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Intraoperative findings were consistent with intrapulmonary teratoma and this was confirmed by a histopathological diagnosis of mature teratoma. Four years later, the patient presented again with recurrence of haemoptysis and a right middle lobectomy was performed. We present a report of successful management of this patient with 20-year follow-up since the first surgery, describe the pathology of this rare condition and the procedures used to treat it. We also discuss the social and economic factors that affect decision making in the management of rare conditions in remote rural areas among poor communities that are usually referred to tertiary hospitals and suggest modifications to protocols to provide effective treatment in spite of resource constraints.<\/jats:p>","DOI":"10.1136\/bcr-2021-248221","type":"journal-article","created":{"date-parts":[[2022,7,14]],"date-time":"2022-07-14T10:56:34Z","timestamp":1657796194000},"page":"e248221","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":3,"title":["Intrapulmonary mature cystic teratoma presenting with haemoptysis treated with right middle lobectomy in a low-resource setting"],"prefix":"10.1136","volume":"15","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-2329-596X","authenticated-orcid":false,"given":"Vijay Anand","family":"Ismavel","sequence":"first","affiliation":[{"name":"Surgery, Makunda Christian Leprosy and General Hospital, Karimganj, Assam, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Ann","family":"Miriam","sequence":"additional","affiliation":[{"name":"Anaesthesia, Makunda Christian Leprosy and General Hospital, Karimganj, Assam, India"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"239","published-online":{"date-parts":[[2022,7,14]]},"reference":[{"key":"2025082711095732000_15.7.e248221.1","doi-asserted-by":"crossref","first-page":"e129","DOI":"10.1016\/j.jtcvs.2016.07.056","article-title":"Isolated intrapulmonary teratoma","volume":"152","author":"Ditah","year":"2016","journal-title":"J Thorac Cardiovasc Surg"},{"key":"2025082711095732000_15.7.e248221.2","doi-asserted-by":"crossref","first-page":"71","DOI":"10.1007\/s12055-018-0701-8","article-title":"Intrapulmonary teratoma masquerading as hydatid cyst of the lung","volume":"35","author":"Ram","year":"2019","journal-title":"Indian J Thorac Cardiovasc Surg"},{"key":"2025082711095732000_15.7.e248221.3","doi-asserted-by":"publisher","DOI":"10.1136\/thx.38.8.632"},{"key":"2025082711095732000_15.7.e248221.4","first-page":"1779","article-title":"Trichoptysis due to an intrapulmonary teratoma","volume":"53","author":"Agarwal","year":"2007","journal-title":"Respiratory Care"},{"key":"2025082711095732000_15.7.e248221.5","doi-asserted-by":"crossref","first-page":"368","DOI":"10.1016\/j.arbres.2015.12.002","article-title":"Diagnosis and treatment of hemoptysis","volume":"52","author":"Cordovilla","year":"2016","journal-title":"Arch Bronconeumol"},{"key":"2025082711095732000_15.7.e248221.6","doi-asserted-by":"crossref","first-page":"29","DOI":"10.1007\/s003830000439","article-title":"Pneumonostomy in the surgical management of bilateral hydatid cysts of the lung","volume":"17","author":"Anand","year":"2001","journal-title":"Pediatr Surg Int"},{"key":"2025082711095732000_15.7.e248221.7","doi-asserted-by":"crossref","first-page":"358","DOI":"10.12809\/hkmj-hkmms202008","article-title":"Epstein-Macintosh-Oxford inhaler (EMO anaesthetic apparatus)","volume":"26","author":"Lo","year":"2020","journal-title":"Hong Kong Med J"},{"key":"2025082711095732000_15.7.e248221.8","doi-asserted-by":"crossref","first-page":"2","DOI":"10.1186\/s12871-015-0128-3","article-title":"Ether in the developing world: rethinking an abandoned agent","volume":"15","author":"Chang","year":"2015","journal-title":"BMC Anesthesiol"},{"key":"2025082711095732000_15.7.e248221.9","doi-asserted-by":"publisher","DOI":"10.1093\/heapol\/czn043"},{"key":"2025082711095732000_15.7.e248221.10","unstructured":"Kumar S , Sahu D . 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