{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,8,28]],"date-time":"2025-08-28T00:02:21Z","timestamp":1756339341889,"version":"3.44.0"},"reference-count":38,"publisher":"BMJ","issue":"6","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2024,6,4]]},"published-print":{"date-parts":[[2024,6]]},"abstract":"<jats:p>Spontaneous pampiniform plexus thrombosis is an extremely rare condition. Its aetiology and pathophysiology are unknown, and its diagnosis remains challenging. We present the first case of an adolescent patient with bilateral spontaneous pampiniform plexus thrombosis. He presented with a 2-day history of bilateral testicular pain. Biochemical investigations were unremarkable, and the patient did not have any risk factors. Ultrasound of the scrotum demonstrated bilateral pampiniform plexus thrombosis. He was managed conservatively and repeat scrotal ultrasound 3\u2009months later revealed complete resolution. This case adds to the minimal literature on spontaneous pampiniform plexus thrombosis, supporting diagnosis via scrotal ultrasound while recommending conservative management without the use of anticoagulation for patients with no pre-existing coagulopathy.<\/jats:p>","DOI":"10.1136\/bcr-2023-259222","type":"journal-article","created":{"date-parts":[[2024,6,13]],"date-time":"2024-06-13T22:41:14Z","timestamp":1718318474000},"page":"e259222","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":0,"title":["Spontaneous bilateral pampiniform plexus thrombosis in a teenager"],"prefix":"10.1136","volume":"17","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-7183-5791","authenticated-orcid":false,"given":"Esther Ern Hwei","family":"Chan","sequence":"first","affiliation":[{"name":"Department of Paediatric Surgery, KK Women's and Children's Hospital, Singapore"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Fay Xiangzhen","family":"Li","sequence":"additional","affiliation":[{"name":"Department of Paediatric Surgery, KK Women's and Children's Hospital, Singapore"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Matthew Chien Ern","family":"Goh","sequence":"additional","affiliation":[{"name":"Naval Medical Service, Singapore"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-1934-0502","authenticated-orcid":false,"given":"Siam Wee","family":"Sim","sequence":"additional","affiliation":[{"name":"Department of Paediatric Surgery, KK Women's and Children's Hospital, Singapore"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"239","published-online":{"date-parts":[[2024,6,13]]},"reference":[{"key":"2025082623501681000_17.6.e259222.1","first-page":"2415","article-title":"Surgical clinic","volume":"4","author":"Senn","year":"1903","journal-title":"Clin Rev"},{"key":"2025082623501681000_17.6.e259222.2","doi-asserted-by":"crossref","first-page":"368","DOI":"10.1016\/S0140-6736(00)77242-4","article-title":"Thrombosis of the pampiniform plexus","volume":"226","author":"Mcgavin","year":"1935","journal-title":"Lancet"},{"key":"2025082623501681000_17.6.e259222.3","doi-asserted-by":"publisher","DOI":"10.1097\/MOU.0b013e32834b8698"},{"key":"2025082623501681000_17.6.e259222.4","doi-asserted-by":"crossref","first-page":"252","DOI":"10.1080\/00365590600589823","article-title":"Spontaneous thrombosis of the pampiniform plexus","volume":"40","author":"Hashimoto","year":"2006","journal-title":"Scand J Urol Nephrol"},{"key":"2025082623501681000_17.6.e259222.5","doi-asserted-by":"crossref","DOI":"10.1016\/S0022-5347(17)39395-3","article-title":"Effort-induced spontaneous thrombosis of the left spermatic vein presenting clinically as a left Inguinal hernia","volume":"144","author":"Isenberg","year":"1990","journal-title":"J Urol"},{"key":"2025082623501681000_17.6.e259222.6","doi-asserted-by":"crossref","first-page":"117","DOI":"10.1159\/000486287","article-title":"Deep vein thrombosis: a rare cause of acute testicular pain. case report: literature review.","volume":"101","author":"Amador Robayna","year":"2018","journal-title":"Urol Int"},{"key":"2025082623501681000_17.6.e259222.7","unstructured":"Kushner A , West WP , Khan Suheb MZ , et al . 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