{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,12,22]],"date-time":"2025-12-22T10:58:11Z","timestamp":1766401091483,"version":"3.44.0"},"reference-count":15,"publisher":"BMJ","issue":"2","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2025,2,11]]},"published-print":{"date-parts":[[2025,2]]},"abstract":"<jats:p>Congenital fusion of jaws is a very rare disorder, with very few cases found in the literature, s since it was first reported 88 years ago. A case with type Id syngnathia with congenital bilateral hemimelia and apodia is presented in this report. The challenges in the diagnosis and management of the patient, along with the postoperative recovery, are discussed in this report.<\/jats:p>","DOI":"10.1136\/bcr-2024-262900","type":"journal-article","created":{"date-parts":[[2025,2,26]],"date-time":"2025-02-26T00:35:12Z","timestamp":1740530112000},"page":"e262900","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":1,"title":["Congenital maxillomandibular fusion (type Id syngnathia) associated with bilateral hemimelia and apodia"],"prefix":"10.1136","volume":"18","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-2865-1978","authenticated-orcid":false,"given":"Johnson Akkarapatty","family":"George","sequence":"first","affiliation":[{"name":"Oral and Maxillofacial Surgery Unit, Christian Medical College and Hospital Vellore, Vellore, Tamil Nadu, India"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-4494-4607","authenticated-orcid":false,"given":"Saurabh","family":"Kumar","sequence":"additional","affiliation":[{"name":"Oral and Maxillofacial Surgery Unit, Christian Medical College and Hospital Vellore, Vellore, Tamil Nadu, India"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-0169-2742","authenticated-orcid":false,"given":"Arun Paul","family":"Charlu","sequence":"additional","affiliation":[{"name":"Oral and Maxillofacial Surgery Unit, Christian Medical College and Hospital Vellore, Vellore, Tamil Nadu, India"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Santosh","family":"Koshy","sequence":"additional","affiliation":[{"name":"Oral and Maxillofacial Surgery Unit, Christian Medical College and Hospital Vellore, Vellore, Tamil Nadu, India"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"239","published-online":{"date-parts":[[2025,2,25]]},"reference":[{"key":"2025082622494585000_18.2.e262900.1","doi-asserted-by":"publisher","DOI":"10.1001\/jama.1936.02770200025009"},{"key":"2025082622494585000_18.2.e262900.2","doi-asserted-by":"crossref","first-page":"19","DOI":"10.1007\/s12663-019-01308-8","article-title":"Congenital Maxillomandibular Syngnathia: Review of Literature and Proposed New Classification System","volume":"20","author":"Kumar","year":"2021","journal-title":"J Maxillofac Oral Surg"},{"key":"2025082622494585000_18.2.e262900.3","doi-asserted-by":"crossref","first-page":"626","DOI":"10.1597\/10-032","article-title":"Congenital zygomatico-mandibular fusion (pseudo-syngnathia?) in conjunction with unilateral anophthalmia: review of terminology and classification","volume":"49","author":"Tauro","year":"2012","journal-title":"Cleft Palate Craniofac J"},{"key":"2025082622494585000_18.2.e262900.4","doi-asserted-by":"publisher","DOI":"10.1001\/archpedi.1966.02090150137019"},{"key":"2025082622494585000_18.2.e262900.5","doi-asserted-by":"publisher","DOI":"10.1016\/0030-4220(73)90070-4"},{"key":"2025082622494585000_18.2.e262900.6","unstructured":"Hegtvedt AK . Diagnosis and management of facial asymmetry. In: Peterson L , ed. Principle of Oral and Maxillofacial Surgery. 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