{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,15]],"date-time":"2026-06-15T19:49:27Z","timestamp":1781552967939,"version":"3.54.5"},"reference-count":13,"publisher":"BMJ","issue":"1","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2024,12,6]]},"published-print":{"date-parts":[[2025,1]]},"abstract":"<jats:p>Miyazaki syndrome is a rare complication in patients with ventricular shunts, characterised by cervical myelopathy from cerebrospinal fluid overdrainage. Here we report a case of a young woman with a history of hydrocephalus who had a ventricular shunt placed in infancy, presenting to our department with signs and symptoms of myelopathy due to overshunting. This diagnosis is challenging because of the frequent absence of typical signs of intracranial hypotension, leading to delays in treatment, which carries the risk of potentially devastating consequences.<\/jats:p>","DOI":"10.1136\/bcr-2024-263801","type":"journal-article","created":{"date-parts":[[2025,1,19]],"date-time":"2025-01-19T20:50:46Z","timestamp":1737319846000},"page":"e263801","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":1,"title":["Miyazaki syndrome"],"prefix":"10.1136","volume":"18","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-4537-5116","authenticated-orcid":false,"given":"Joana","family":"Tavares","sequence":"first","affiliation":[{"name":"Neurosurgery, Unidade Local de Sa\u00fade de Lisboa Ocidental, Lisboa, Portugal"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Carla","family":"Reizinho","sequence":"additional","affiliation":[{"name":"Neurosurgery, Unidade Local de Sa\u00fade de Lisboa Ocidental, Lisboa, Portugal"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-6160-4516","authenticated-orcid":false,"given":"Ana","family":"Lu\u00eds","sequence":"additional","affiliation":[{"name":"Neurosurgery, Unidade Local de Sa\u00fade de Lisboa Ocidental, Lisboa, Portugal"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"239","published-online":{"date-parts":[[2025,1,19]]},"reference":[{"key":"2025082712183732000_18.1.e263801.1","doi-asserted-by":"crossref","first-page":"1864","DOI":"10.1212\/WNL.50.6.1864","article-title":"Upper cervical myelopathy associated with low CSF pressure: a complication of ventriculoperitoneal shunt","volume":"50","author":"Miyazaki","year":"1998","journal-title":"Neurology (ECronicon)"},{"key":"2025082712183732000_18.1.e263801.2","doi-asserted-by":"crossref","first-page":"274","DOI":"10.1016\/j.wneu.2018.05.175","article-title":"Overshunting-Associated Myelopathy (OSAM) in a Patient with Bilateral Jugular Vein Occlusion","volume":"116","author":"Adib","year":"2018","journal-title":"World Neurosurg"},{"key":"2025082712183732000_18.1.e263801.3","doi-asserted-by":"crossref","first-page":"312","DOI":"10.1159\/000514551","article-title":"Overshunting-Related Cervical Myelopathy Causing Progressive Gait Disturbance: A Case Report","volume":"13","author":"Vister","year":"2021","journal-title":"Case Rep Neurol"},{"key":"2025082712183732000_18.1.e263801.4","doi-asserted-by":"crossref","unstructured":"Ulrich NH , Matthias M , Bernays R , et al . 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