{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,10,9]],"date-time":"2025-10-09T00:22:22Z","timestamp":1759969342878,"version":"build-2065373602"},"reference-count":9,"publisher":"BMJ","issue":"10","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2025,9,22]]},"published-print":{"date-parts":[[2025,10]]},"abstract":"<jats:p>A woman in her 60s reported \u2018cramping\u2019 of her tongue, and examination showed continuous undulating movements of the right tongue typical of myokymia. MRI demonstrated compression of the right hypoglossal nerve and the right internal carotid artery by a soft tissue mass involving the right carotid space and hypoglossal canal. A biopsy of the mass was considered too dangerous, but anti-MPO-ANCA (myeloperoxidase specific antineutrophil cytoplasmic) antibodies were found positive, and a tentative diagnosis of MPO-ANCA-associated vasculitis (i.e., microscopic polyangiitis\u2014MPA) was made. She was treated with intravenous corticosteroids and then oral prednisone. She did not tolerate rituximab, so was treated with cyclophosphamide, followed by azathioprine. Eight months later, MRI showed complete resolution of the lesion, and her anti-MPO antibodies became negative. Her tongue myokymia was greatly decreased, but had not completely resolved.<\/jats:p>","DOI":"10.1136\/bcr-2025-267957","type":"journal-article","created":{"date-parts":[[2025,10,8]],"date-time":"2025-10-08T05:20:29Z","timestamp":1759900829000},"page":"e267957","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":0,"title":["Tongue myokymia due to microscopic polyangiitis"],"prefix":"10.1136","volume":"18","author":[{"given":"Alfiya","family":"Gali","sequence":"first","affiliation":[{"name":"Department of Medicine, McGill University Faculty of Medicine, Montreal, Quebec, Canada"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Tasnia","family":"Rahman","sequence":"additional","affiliation":[{"name":"Department of Neurology & Neurosurgery, McGill University Faculty of Medicine, Montreal, Quebec, Canada"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Pia","family":"Sumbly","sequence":"additional","affiliation":[{"name":"McGill University Faculty of Medicine, Montreal, Quebec, Canada"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Colin","family":"Chalk","sequence":"additional","affiliation":[{"name":"Department of Neurology & Neurosurgery, McGill University Faculty of Medicine, Montreal, Quebec, Canada"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"239","published-online":{"date-parts":[[2025,10,7]]},"reference":[{"key":"2025100722201888000_18.10.e267957.1","doi-asserted-by":"publisher","DOI":"10.1136\/ard-2022-223480"},{"key":"2025100722201888000_18.10.e267957.2","doi-asserted-by":"publisher","DOI":"10.1136\/annrheumdis-2021-221796"},{"key":"2025100722201888000_18.10.e267957.3","doi-asserted-by":"crossref","first-page":"132","DOI":"10.1016\/j.jocn.2017.07.013","article-title":"Unilateral tongue myokymia - A rare topodiagnostic sign of different clinical conditions","volume":"45","author":"Leupold","year":"2017","journal-title":"J Clin Neurosci"},{"key":"2025100722201888000_18.10.e267957.4","doi-asserted-by":"crossref","first-page":"1056","DOI":"10.1002\/ccr3.965","article-title":"Radiation-induced tongue myokymia with hypoglossal nerve damage, mimicker of motor neuron disease","volume":"5","author":"Memon","year":"2017","journal-title":"Clin Case Rep"},{"key":"2025100722201888000_18.10.e267957.5","doi-asserted-by":"crossref","first-page":"494","DOI":"10.5694\/j.1326-5377.1988.tb120738.x","article-title":"Myokymia of the tongue in a case of brainstem tumour that simulated motor-neuron disease","volume":"149","author":"Adams","year":"1988","journal-title":"Med J Aust"},{"key":"2025100722201888000_18.10.e267957.6","doi-asserted-by":"publisher","DOI":"10.1136\/ard-2022-223764"},{"key":"2025100722201888000_18.10.e267957.7","doi-asserted-by":"crossref","first-page":"337","DOI":"10.1080\/24725625.2021.1893944","article-title":"Temporal arteritis as an initial manifestation of eosinophilic granulomatosis with polyangiitis: a case report and a literature review","volume":"5","author":"Nishimura","year":"2021","journal-title":"Mod Rheumatol Case Rep"},{"key":"2025100722201888000_18.10.e267957.8","doi-asserted-by":"crossref","first-page":"412","DOI":"10.31138\/mjr.31.4.412","article-title":"A Case of Microscopic Polyangiitis Presenting as Cranial Giant Cell Arteritis","volume":"31","author":"Evangelatos","year":"2020","journal-title":"Mediterr J Rheumatol"},{"key":"2025100722201888000_18.10.e267957.9","doi-asserted-by":"crossref","first-page":"339","DOI":"10.4103\/aian.AIAN_83_18","article-title":"Antineutrophil Cytoplasmic Antibody Vasculitis Causing Skull Base Inflammation and Aortitis","volume":"21","author":"Maramattom","year":"2018","journal-title":"Ann Indian Acad Neurol"}],"container-title":["BMJ Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/syndication.highwire.org\/content\/doi\/10.1136\/bcr-2025-267957","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2025,10,8]],"date-time":"2025-10-08T05:20:30Z","timestamp":1759900830000},"score":1,"resource":{"primary":{"URL":"https:\/\/casereports.bmj.com\/lookup\/doi\/10.1136\/bcr-2025-267957"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2025,10]]},"references-count":9,"journal-issue":{"issue":"10","published-online":{"date-parts":[[2025,10,7]]},"published-print":{"date-parts":[[2025,10]]}},"alternative-id":["10.1136\/bcr-2025-267957"],"URL":"https:\/\/doi.org\/10.1136\/bcr-2025-267957","relation":{},"ISSN":["1757-790X"],"issn-type":[{"value":"1757-790X","type":"electronic"}],"subject":[],"published":{"date-parts":[[2025,10]]}}}