{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,26]],"date-time":"2026-06-26T15:51:20Z","timestamp":1782489080091,"version":"3.54.5"},"reference-count":15,"publisher":"BMJ","issue":"4","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2026,3,12]]},"published-print":{"date-parts":[[2026,4]]},"abstract":"<jats:p>Management of bilateral congenital pulmonary airway malformations (CPAM) distributing multiple lobes is challenging since it requires complicated surgical decision-making regarding when and how much abnormal lung parenchyma should be resected with minimal risk of postsurgical respiratory failure.<\/jats:p>\n                  <jats:p>We present a case of antenatally diagnosed bilateral CPAM distributed almost to the entire lungs, which had a favourable outcome with optimised conservative and surgical management. The management was started with maximal ventilatory support, and when and how much of the lesions should be resected was carefully assessed with serial CT and lung perfusion and ventilation scintigraphy. Growth of healthy parenchyma was observed during the conservative management, and then sufficient functioning lung parenchyma could be preserved.<\/jats:p>","DOI":"10.1136\/bcr-2025-270351","type":"journal-article","created":{"date-parts":[[2026,4,15]],"date-time":"2026-04-15T16:25:16Z","timestamp":1776270316000},"page":"e270351","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":0,"title":["Delayed surgical management of extensive bilateral multilobar congenital pulmonary airway malformation"],"prefix":"10.1136","volume":"19","author":[{"given":"Taichi","family":"Hirotani","sequence":"first","affiliation":[{"name":"Pediatric surgery, Kanazawa Medical University, Kahoku-gun, Ishikawa, Japan"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-5387-9635","authenticated-orcid":false,"given":"Ryo","family":"Tamura","sequence":"additional","affiliation":[{"name":"Pediatric surgery, Kanazawa Medical University, Kahoku-gun, Ishikawa, Japan"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Yoshitomo","family":"Yasui","sequence":"additional","affiliation":[{"name":"Pediatric surgery, Kanazawa Medical University, Kahoku-gun, Ishikawa, Japan"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Hideaki","family":"Okajima","sequence":"additional","affiliation":[{"name":"Pediatric surgery, Kanazawa Medical University, Kahoku-gun, Ishikawa, Japan"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"239","published-online":{"date-parts":[[2026,4,15]]},"reference":[{"key":"2026062608154373000_19.4.e270351.1","doi-asserted-by":"publisher","DOI":"10.1053\/j.sempedsurg.2004.10.022"},{"key":"2026062608154373000_19.4.e270351.2","doi-asserted-by":"crossref","first-page":"1001","DOI":"10.1002\/pd.5134","article-title":"Outcome of prenatally diagnosed congenital lung anomalies in the North of England: a review of 228 cases to aid in prenatal counselling","volume":"37","author":"Walker","year":"2017","journal-title":"Prenat Diagn"},{"key":"2026062608154373000_19.4.e270351.3","first-page":"183","article-title":"Bilateral congenital cystic adenomatiod malformation of the lungs: a case report","volume":"35","author":"Atalabi","year":"2006","journal-title":"Afr J Med Med Sci"},{"key":"2026062608154373000_19.4.e270351.4","doi-asserted-by":"crossref","unstructured":"Chandrasekaran P , Goergen S , Robinson A , et al . 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Precise Thoracoscopic Pneumonectomy Using Fluorescence Imaging After Aerosolized Indocyanine Green Inhalation: A Novel Strategy for Treating Congenital Pulmonary Airway Malformation. 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