{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,25]],"date-time":"2026-06-25T14:51:20Z","timestamp":1782399080535,"version":"3.54.5"},"reference-count":8,"publisher":"BMJ","issue":"6","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2026,6,16]]},"published-print":{"date-parts":[[2026,6]]},"abstract":"<jats:p>Urinary bladder agenesis is an extraordinarily rare congenital anomaly, often associated with complex genitourinary malformations and poses significant diagnostic challenges in infancy. We report an infant girl with progressive abdominal distension, continuous urinary dribbling and bilateral hydronephrosis, ultimately found to have bladder agenesis with bilateral pelviureteric junction obstruction, ectopic ureteric insertion into the vagina and malrotated kidneys. Multimodality imaging, including ultrasonography, radionuclide diuretic renography with single-photon emission CT\/CT and contrast-enhanced CT, was essential for establishing the diagnosis when the bladder was not visualised on initial evaluation. The child underwent staged management with initial decompression by percutaneous nephrostomy followed by left pyeloplasty, and was planned for delayed bladder reconstruction, but was lost to follow-up. This case highlights the need for high index of suspicion when the bladder is not visualised on imaging in infants with continuous dribbling and upper tract dilatation. It underscores the need to prioritise relief of obstruction before definitive reconstruction.<\/jats:p>","DOI":"10.1136\/bcr-2026-272734","type":"journal-article","created":{"date-parts":[[2026,6,25]],"date-time":"2026-06-25T14:25:20Z","timestamp":1782397520000},"page":"e272734","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":0,"title":["Urinary bladder agenesis presenting with bilateral pelviureteric junction obstruction in an infant: a rare urological anomaly"],"prefix":"10.1136","volume":"19","author":[{"given":"Anandit","family":"Bal","sequence":"first","affiliation":[{"name":"Paediatric Surgery, All India Institute of Medical Sciences Bhubaneswar, Bhubaneswar, Odisha, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Manita","family":"Tamang","sequence":"additional","affiliation":[{"name":"Paediatric Surgery, All India Institute of Medical Sciences Bhubaneswar, Bhubaneswar, Odisha, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Biswajit","family":"Sahoo","sequence":"additional","affiliation":[{"name":"Radiodiagnosis, All India Institute of Medical Sciences Bhubaneswar, Bhubaneswar, Odisha, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"P Saisradha","family":"Patro","sequence":"additional","affiliation":[{"name":"Nuclear Medicine, All India Institute of Medical Sciences Bhubaneswar, Bhubaneswar, OD, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-8147-3966","authenticated-orcid":false,"given":"Santosh Kumar","family":"Mahalik","sequence":"additional","affiliation":[{"name":"Paediatric Surgery, All India Institute of Medical Sciences Bhubaneswar, Bhubaneswar, Odisha, India"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"239","published-online":{"date-parts":[[2026,6,25]]},"reference":[{"key":"2026062507251316000_19.6.e272734.1","doi-asserted-by":"crossref","first-page":"777","DOI":"10.1007\/s12098-025-05539-1","article-title":"Urinary Bladder Agenesis in a Child: An Uncommon Congenital Anomaly of the Urinary Tract","volume":"92","author":"Rathi","year":"2025","journal-title":"Indian J Pediatr"},{"key":"2026062507251316000_19.6.e272734.2","article-title":"Bladder Agenesis: A Systematic Review","volume":"15","author":"Yahya","year":"2023","journal-title":"Cureus"},{"key":"2026062507251316000_19.6.e272734.3","doi-asserted-by":"crossref","first-page":"2782783","DOI":"10.1155\/2020\/2782783","article-title":"Congenital Bladder and Urethral Agenesis: Two Case Reports and Management","volume":"2020","author":"Delshad","year":"2020","journal-title":"Adv 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Solitary Kidney, Ectopic Ureter, and Unicornuate Uterus in an Adult Patient","volume":"02","author":"Gowtham","year":"2019","journal-title":"Journal of Gastrointestinal and Abdominal Radiology"},{"key":"2026062507251316000_19.6.e272734.8","doi-asserted-by":"crossref","first-page":"256","DOI":"10.1016\/j.urology.2021.02.032","article-title":"Bladder Agenesis and Bilateral Ectopic Ureters in an Infant Male With Cystic Renal Dysplasia, Imperforate Anus, and Penoscrotal Transposition","volume":"156","author":"Omil-Lima","year":"2021","journal-title":"Urology"}],"container-title":["BMJ Case 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