{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,7,13]],"date-time":"2026-07-13T12:12:20Z","timestamp":1783944740270,"version":"3.55.0"},"reference-count":35,"publisher":"BMJ","issue":"7","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2026,6,25]]},"published-print":{"date-parts":[[2026,7]]},"abstract":"<jats:p>We report a rare case of a dural angioleiomyoma (ALM) in a woman in her 50s presenting with a progressive right-sided tremor. MRI revealed a left-sided infratentorial extra-axial lesion, initially suspected to be a posterior fossa meningioma. The patient underwent supracerebellar infratentorial gross total resection without complications. Histopathology demonstrated well-differentiated spindle-shaped smooth muscle cells arranged around blood vessels, with strong smooth muscle actin positivity and a Ki-67 index &lt;1%, confirming the diagnosis of dural ALM. At the 1-year follow-up, the patient remained neurologically intact and imaging showed no recurrence.<\/jats:p>\n                  <jats:p>Intracranial ALMs are exceedingly rare and often misdiagnosed preoperatively due to non-specific imaging characteristics. This case highlights the importance of considering ALM in the differential diagnosis of extra-axial posterior fossa lesions and emphasises that complete surgical excision provides excellent disease control with favourable functional outcomes.<\/jats:p>","DOI":"10.1136\/bcr-2026-272824","type":"journal-article","created":{"date-parts":[[2026,7,13]],"date-time":"2026-07-13T11:35:17Z","timestamp":1783942517000},"page":"e272824","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":0,"title":["Intracranial infratentorial angioleiomyoma, an unusual localisation"],"prefix":"10.1136","volume":"19","author":[{"given":"Lorenzo","family":"Dolci","sequence":"first","affiliation":[{"name":"University of Turin Department of Neurosciences Rita Levi Montalcini, Turin, Piedmont, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Carmen","family":"Ungaro","sequence":"additional","affiliation":[{"name":"University of Turin Department of Neurosciences Rita Levi Montalcini, Turin, Piedmont, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Ignazio","family":"Digirolamo","sequence":"additional","affiliation":[{"name":"University of Turin Department of Neurosciences Rita Levi Montalcini, Turin, Piedmont, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Antonio","family":"Melcarne","sequence":"additional","affiliation":[{"name":"University of Turin Department of Neurosciences Rita Levi Montalcini, Turin, Piedmont, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"239","published-online":{"date-parts":[[2026,7,13]]},"reference":[{"key":"2026071304351207000_19.7.e272824.1","doi-asserted-by":"crossref","first-page":"842","DOI":"10.1007\/s10143-024-03079-4","article-title":"Intracranial angioleiomyoma mimicking meningioma: an uncommon tumor with favorable outcome and frequent GJA4 mutation","volume":"47","author":"Ren","year":"2024","journal-title":"Neurosurg Rev"},{"key":"2026071304351207000_19.7.e272824.2","doi-asserted-by":"publisher","DOI":"10.1007\/s11060-024-04734-y"},{"key":"2026071304351207000_19.7.e272824.3","doi-asserted-by":"publisher","DOI":"10.1002\/1097-0142(19840701)54:1<126::AID-CNCR2820540125>3.0.CO;2-F"},{"key":"2026071304351207000_19.7.e272824.4","doi-asserted-by":"publisher","DOI":"10.32074\/1591-951X-213"},{"key":"2026071304351207000_19.7.e272824.5","doi-asserted-by":"crossref","first-page":"1915","DOI":"10.1002\/1097-0142(19941001)74:7<1915::AID-CNCR2820740715>3.0.CO;2-1","article-title":"Primary intracranial pleomorphic angioleiomyoma\u2014A New Morphologic Variant. 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