{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,18]],"date-time":"2026-08-18T01:38:29Z","timestamp":1787017109207,"version":"build-2736575974"},"reference-count":13,"publisher":"Oxford University Press (OUP)","issue":"819","license":[{"start":{"date-parts":[[1994,1,1]],"date-time":"1994-01-01T00:00:00Z","timestamp":757382400000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/academic.oup.com\/pages\/standard-publication-reuse-rights"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[1994,1,1]]},"abstract":"<jats:title>Summary<\/jats:title>\n                  <jats:p>Clinical, endocrinological and computed tomographic features of three patients with unusual manifestations or complications of craniofacial involvement of fibrous dysplasia are presented. One patient with polyostotic fibrous dysplasia presented in late pregnancy with acute onset of bilateral optic nerve compression and blindness secondary to a rapidly expanding mass of fibrous dysplasia tissue involving the sphenoid, pituitary and optic chiasm regions. A second patient with polyostotic fibrous dysplasia developed thyrotoxicosis and probable gigantism\/acromegaly in keeping with a rare form of McCune-Albright syndrome. Extensive bony distortion of the skull and facial bones by fibrous dysplasia made clinical recognition of these complications more difficult. A third patient had monostotic fibrous dysplasia with marked sclerosis of the sphenoid bone on plain radiographs which mimicked appearances of a meningioma and resulted in a negative craniotomy as computed tomography was not yet available at the time of presentation.<\/jats:p>\n                  <jats:p>Each case demonstrated rare complications of craniofacial fibrous dysplasia and highlighted the wide spectrum of appearances in which it may manifest, often resulting in overlap and diagnostic confusion with other disease processes. The value of computed tomography in assessment is emphasized.<\/jats:p>","DOI":"10.1136\/pgmj.70.819.10","type":"journal-article","created":{"date-parts":[[2008,12,29]],"date-time":"2008-12-29T16:25:21Z","timestamp":1230567921000},"page":"10-16","source":"Crossref","is-referenced-by-count":24,"title":["Unusual manifestations of craniofacial fibrous dysplasia: clinical, endocrinological and computed tomographic features"],"prefix":"10.1093","volume":"70","author":[{"given":"B D","family":"Daly","sequence":"first","affiliation":[{"name":"Department of Diagnostic Radiology and Organ Imaging"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"C C","family":"Chow","sequence":"additional","affiliation":[{"name":"Department of Medicine, Chinese University of Hong Kong, Prince of Wales Hospital , Shatin, N.T. Hong Kong"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"C S","family":"Cockram","sequence":"additional","affiliation":[{"name":"Department of Medicine, Chinese University of Hong Kong, Prince of Wales Hospital , Shatin, N.T. Hong Kong"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"286","published-online":{"date-parts":[[1994,1,1]]},"reference":[{"issue":"52","key":"ref_1","first-page":"743","article-title":"Osteitis fibrosa cystica: the case of a nine year old girl who also exhibits precocious puberty, multiple pigmentation of the skin and hyperthyroidism","volume":"1936","author":"McCune, D.J.","unstructured":"McCune, D.J. Osteitis fibrosa cystica: the case of a nine year old girl who also exhibits precocious puberty, multiple pigmentation of the skin and hyperthyroidism. Am J Dis Child 1936, 52: 743-744.","journal-title":"Am J Dis Child"},{"issue":"216","key":"ref_2","first-page":"727","article-title":"Syndrome characterised by osteitis fibrosa disseminata, areas of pigmentation and endocrine dysfunction, with precocious puberty in females: report of five cases","volume":"1937","author":"Albright, F.; Butler, A.M.; Hampton, A.O.; Smith, P.","unstructured":"Albright, F., Butler, A.M., Hampton, A.O. & Smith, P. Syndrome characterised by osteitis fibrosa disseminata, areas of pigmentation and endocrine dysfunction, with precocious puberty in females: report of five cases. N Engl J Med 1937, 216: 727-746.","journal-title":"N Engl J Med"},{"issue":"11","key":"ref_3","first-page":"30","article-title":"Endocrine features in Albright's syndrome (fibrous dysplasia of bone)","volume":"1962","author":"Benedict, P.H.","unstructured":"Benedict, P.H. Endocrine features in Albright's syndrome (fibrous dysplasia of bone). Metabolism 1962, 11: 30-45.","journal-title":"Metabolism"},{"issue":"279","key":"ref_4","first-page":"207","article-title":"The McCune-Albright syndrome","volume":"1986","author":"Mauras, N.; Blizzard, R.M.","unstructured":"Mauras, N. & Blizzard, R.M. The McCune-Albright syndrome. Acta Endocrinol Suppi (Copenh) 1986, 279, 207-217.","journal-title":"Acta Endocrinol Suppi (Copenh)"},{"key":"ref_5","first-page":"209","article-title":"Fibro-osseous lesions of bone","volume-title":"Joints, International Academy of Pathology, Monograph No. 17","author":"Demner, L.P.","year":"1976","unstructured":"Demner, L.P. Fibro-osseous lesions of bone. In: Ackerman, L.U., Spjut, H.J. & Abell, M.R. (eds) Bone and Joints, International Academy of Pathology, Monograph No. 17. Baltimore, The Williams & Wilkins Co., 1976, pp. 209-235."},{"key":"ref_6","first-page":"208","article-title":"Fibrous dysplasia","volume-title":"Neck Imaging","author":"Som, P.","year":"1991","unstructured":"Som, P. Fibrous dysplasia. In: Som, P.M. & Bergeron, R.T. (eds.) Head and Neck Imaging, 2nd ed. St Louis, Mosby, 1991, pp. 208-210.","edition":"2nd ed"},{"key":"ref_7","first-page":"170","article-title":"Otosclerosis and bone dystrophies","volume-title":"Neck Imaging","author":"Valvassoni, G.E.; Buckingham, R.A.","year":"1988","unstructured":"Valvassoni, G.E. & Buckingham, R.A. Otosclerosis and bone dystrophies. In: Valvassoni, G.E., Buckingham, R.A., Carter, B.L., Hanafee, W.N. & Mafee, M.F. (eds) Head and Neck Imaging. New York, Thieme, 1988, pp. 170-171."},{"key":"ref_8","first-page":"397","article-title":"Fibro-osseous lesions","volume-title":"Neck Imaging","author":"Weber, A.L.","year":"1991","unstructured":"Weber, A.L. Fibro-osseous lesions. In: Som, P.M. & Bergeron, R.T. (eds) Head and Neck Imaging, 2nd edn. St Louis, Mosby, 1991, pp. 397-398.","edition":"2nd edn"},{"key":"ref_9","first-page":"727","article-title":"Monostotic fibrous dysplasia of the sphenoid bone presenting with visual disturbance during pregnancy. No To Shinkei","volume":"40","author":"Okudera, H.; Toba, Y.; Kyoshima, K.; Kobayashi, S.","year":"1988","unstructured":"Okudera, H., Toba, Y., Kyoshima, K. & Kobayashi, S. Monostotic fibrous dysplasia of the sphenoid bone presenting with visual disturbance during pregnancy. No To Shinkei 1988, 40: 727-732 (English abstract)."},{"issue":"149","key":"ref_10","first-page":"10","article-title":"McCune-Albright syndrome associated with acromegaly: report of a case and review of literature","volume":"1981","author":"Lipson, A.; Hsu, T.","unstructured":"Lipson, A. & Hsu, T. McCune-Albright syndrome associated with acromegaly: report of a case and review of literature. Johns Hopkins Med J 1981, 149: 10-14.","journal-title":"Johns Hopkins Med J"},{"key":"ref_11","doi-asserted-by":"crossref","first-page":"1148","DOI":"10.1210\/jcem-68-6-1148","article-title":"Hypersecretion of growth hormone and prolactin in McCune-Albright syndrome","volume":"68","author":"Cuttler, L.; Jackson, J.A.; Uz-Zafar, M.S.; Levitsky, L.L.; Meltinger, R.C.; Frohman, L.A.","year":"1989","unstructured":"Cuttler, L., Jackson, J.A., Uz-Zafar, M.S., Levitsky, L.L., Meltinger, R.C. & Frohman, L.A. Hypersecretion of growth hormone and prolactin in McCune-Albright syndrome. J Clin Endocrinol Metabol 1989, 68: 1148-1154.","journal-title":"J Clin Endocrinol Metabol"},{"issue":"2","key":"ref_12","first-page":"480","article-title":"Fibrous dysplasia of the skull","volume":"1955","author":"Ameli, N.","unstructured":"Ameli, N. Fibrous dysplasia of the skull. Lancet 1955, 2: 480-482.","journal-title":"Lancet"},{"key":"ref_13","doi-asserted-by":"crossref","first-page":"1017","DOI":"10.2214\/ajr.149.5.1017","article-title":"CT features of hyperostosing meningioma en plaque","volume":"149","author":"Kim, K.S.; Rogers, L.F.; Goldblatt, D.","year":"1987","unstructured":"Kim, K.S., Rogers, L.F. & Goldblatt, D. CT features of hyperostosing meningioma en plaque. Am J Roentgenol 1987, 149: 1017-1023.","journal-title":"Am J Roentgenol"}],"container-title":["Postgraduate Medical Journal"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/academic.oup.com\/pmj\/article-pdf\/70\/819\/10\/50217573\/postgradmedj-70-10.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/academic.oup.com\/pmj\/article-pdf\/70\/819\/10\/50217573\/postgradmedj-70-10.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2023,5,15]],"date-time":"2023-05-15T06:45:43Z","timestamp":1684133143000},"score":1,"resource":{"primary":{"URL":"https:\/\/academic.oup.com\/pmj\/article\/70\/819\/10\/7042416"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[1994,1,1]]},"references-count":13,"journal-issue":{"issue":"819","published-online":{"date-parts":[[1994,1,1]]},"published-print":{"date-parts":[[1994,1,1]]}},"URL":"https:\/\/doi.org\/10.1136\/pgmj.70.819.10","relation":{},"ISSN":["0032-5473","1469-0756"],"issn-type":[{"value":"0032-5473","type":"print"},{"value":"1469-0756","type":"electronic"}],"subject":[],"published-other":{"date-parts":[[1994,1]]},"published":{"date-parts":[[1994,1,1]]}}}