{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,8,5]],"date-time":"2025-08-05T13:02:57Z","timestamp":1754398977369},"reference-count":20,"publisher":"World Scientific Pub Co Pte Lt","issue":"02","content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Hand Surg."],"published-print":{"date-parts":[[2013,1]]},"abstract":"<jats:p> Macrodystrophia lipomatosa is a rare, non-hereditary form of congenital local gigantism characterised by enlargement and hypertrophy of all mesenchymal tissue components with a disproportionate increase in adipose tissue. This form of macrodactyly has been reported in association with other anomalies including polydactyly, brachydactyly, syndactyly, and symphalangism. We describe a previously unreported case of bilateral upper extremity macrodystrophia lipomatosa with syndactyly in a 23-month-old boy. In this report, we emphasise the importance of establishing a diagnosis with imaging and review the described surgical approaches to treating this difficult condition. <\/jats:p>","DOI":"10.1142\/s0218810413720180","type":"journal-article","created":{"date-parts":[[2013,7,3]],"date-time":"2013-07-03T04:04:59Z","timestamp":1372824299000},"page":"267-272","source":"Crossref","is-referenced-by-count":3,"title":["BILATERAL MACRODYSTROPHIA LIPOMATOSA WITH SYNDACTYLY: A CASE REPORT AND LITERATURE REVIEW"],"prefix":"10.1142","volume":"18","author":[{"given":"Steven B.","family":"Albright","sequence":"first","affiliation":[{"name":"Division of Plastic Surgery, Michael E. Debakey Department of Surgery, Baylor College of Medicine, Houston, TX 77030, USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Erik M.","family":"Wolfswinkel","sequence":"additional","affiliation":[{"name":"Division of Plastic Surgery, Michael E. 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