{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,5,9]],"date-time":"2026-05-09T06:36:04Z","timestamp":1778308564293,"version":"3.51.4"},"reference-count":19,"publisher":"Hindawi Limited","license":[{"start":{"date-parts":[[2015,1,1]],"date-time":"2015-01-01T00:00:00Z","timestamp":1420070400000},"content-version":"unspecified","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by\/3.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Case Reports in Endocrinology"],"published-print":{"date-parts":[[2015]]},"abstract":"<jats:p><jats:italic>Objective<\/jats:italic>. To report the unusual case of an adrenal lymphangioma presenting in a patient with an adrenal cystic lesion and biochemical testing concerning for pheochromocytoma. The pertinent diagnostic and imaging features of adrenal lymphangiomas are reviewed.<jats:italic>Methods<\/jats:italic>. We describe a 59-year-old patient who presented with hyperhidrosis and a 2.2 by 2.2\u2009cm left adrenal nodule. Biochemical evaluation revealed elevated plasma-free normetanephrine, urine normetanephrine, urine vanillylmandelic acid, and urine norepinephrine levels. Elevated plasma norepinephrine levels were not suppressed appropriately with clonidine administration.<jats:italic>Results<\/jats:italic>. Given persistent concern for pheochromocytoma, the patient underwent adrenalectomy. The final pathology was consistent with adrenal lymphangioma.<jats:italic>Conclusions<\/jats:italic>. Lymphangiomas are benign vascular lesions that can very rarely occur in the adrenal gland. Imaging findings are generally consistent with a cyst but are nonspecific. Excluding malignancy in patients presenting with adrenal cysts can be difficult. Despite its benign nature, the diagnosis of adrenal lymphangioma may ultimately require pathology.<\/jats:p>","DOI":"10.1155\/2015\/380151","type":"journal-article","created":{"date-parts":[[2015,11,5]],"date-time":"2015-11-05T21:01:39Z","timestamp":1446757299000},"page":"1-4","source":"Crossref","is-referenced-by-count":3,"title":["Adrenal Lymphangioma Masquerading as a Catecholamine Producing Tumor"],"prefix":"10.1155","volume":"2015","author":[{"given":"Israel","family":"Hodish","sequence":"first","affiliation":[{"name":"Division of Internal Medicine, University of Michigan Medical Center, Ann Arbor, MI 48109, USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Lindsay","family":"Schmidt","sequence":"additional","affiliation":[{"name":"Department of Pathology, University of Michigan, Ann Arbor, MI 48109, USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Andreas G.","family":"Moraitis","sequence":"additional","affiliation":[{"name":"Corcept Therapeutics, Menlo Park, CA 94025, USA"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"98","reference":[{"key":"1","year":"2001"},{"issue":"4","key":"2","first-page":"758","volume":"27","year":"1951","journal-title":"The American Journal of Pathology"},{"key":"3","doi-asserted-by":"publisher","DOI":"10.1002\/cncr.20555"},{"key":"4","doi-asserted-by":"publisher","DOI":"10.1001\/archsurg.1966.01320190133032"},{"issue":"2","key":"5","doi-asserted-by":"crossref","first-page":"151","DOI":"10.1177\/000313489906500213","volume":"65","year":"1999","journal-title":"American Surgeon"},{"key":"6","doi-asserted-by":"publisher","DOI":"10.1007\/s00428-008-0611-z"},{"issue":"3","key":"7","first-page":"239","volume":"78","year":"1993","journal-title":"International Surgery"},{"key":"8","doi-asserted-by":"publisher","DOI":"10.1148\/radiology.201.2.8888255"},{"key":"9","doi-asserted-by":"publisher","DOI":"10.1016\/0720-048X(95)00604-O"},{"key":"10","doi-asserted-by":"publisher","DOI":"10.1148\/radiology.175.2.2183287"},{"key":"11","doi-asserted-by":"publisher","DOI":"10.1016\/j.ejrad.2006.12.011"},{"key":"13","doi-asserted-by":"publisher","DOI":"10.1210\/jc.2002-030005"},{"issue":"11","key":"14","first-page":"1427","volume":"287","year":"2002","journal-title":"The Journal of the American Medical Association"},{"key":"15","doi-asserted-by":"publisher","DOI":"10.1210\/jc.2003-030720"},{"key":"16","doi-asserted-by":"publisher","DOI":"10.1016\/s0140-6736(05)67139-5"},{"key":"17","doi-asserted-by":"publisher","DOI":"10.1056\/nejm198109103051107"},{"key":"18","doi-asserted-by":"publisher","DOI":"10.1001\/archinte.152.6.1193"},{"key":"19","doi-asserted-by":"publisher","DOI":"10.1016\/0002-9343(88)90261-6"},{"key":"20","doi-asserted-by":"publisher","DOI":"10.1186\/s12957-015-0490-0"}],"container-title":["Case Reports in Endocrinology"],"original-title":[],"language":"en","link":[{"URL":"http:\/\/downloads.hindawi.com\/journals\/crie\/2015\/380151.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"http:\/\/downloads.hindawi.com\/journals\/crie\/2015\/380151.xml","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"http:\/\/downloads.hindawi.com\/journals\/crie\/2015\/380151.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2023,8,15]],"date-time":"2023-08-15T19:23:41Z","timestamp":1692127421000},"score":1,"resource":{"primary":{"URL":"http:\/\/www.hindawi.com\/journals\/crie\/2015\/380151\/"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2015]]},"references-count":19,"alternative-id":["380151","380151"],"URL":"https:\/\/doi.org\/10.1155\/2015\/380151","relation":{},"ISSN":["2090-6501","2090-651X"],"issn-type":[{"value":"2090-6501","type":"print"},{"value":"2090-651X","type":"electronic"}],"subject":[],"published":{"date-parts":[[2015]]}}}