{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,19]],"date-time":"2026-06-19T22:35:28Z","timestamp":1781908528006,"version":"3.54.5"},"reference-count":11,"publisher":"Wiley","license":[{"start":{"date-parts":[[2023,2,28]],"date-time":"2023-02-28T00:00:00Z","timestamp":1677542400000},"content-version":"unspecified","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Case Reports in Endocrinology"],"published-print":{"date-parts":[[2023,2,28]]},"abstract":"<jats:p>Brachymetacarpia and brachymetatarsia are unique clinical entities associated with numerous rare conditions. Primary hypoparathyroidism is distinct from pseudohypoparathyroidism and pseudopseudohypoparathyroidism by lacking skeletal changes such as short metacarpals or metatarsals. Here, we present a case of a 64-year-old patient with brachymetacarpia and brachymetatarsia presented with hypocalcemic symptoms and signs, bilateral cataracts, and basal ganglia calcifications, subsequently diagnosed with idiopathic primary hypoparathyroidism. This is a rare case describing such an infrequent observation of brachymetacarpia and brachymetatarsia in primary idiopathic hypoparathyroidism.<\/jats:p>","DOI":"10.1155\/2023\/4149677","type":"journal-article","created":{"date-parts":[[2023,2,28]],"date-time":"2023-02-28T20:35:09Z","timestamp":1677616509000},"page":"1-4","source":"Crossref","is-referenced-by-count":3,"title":["A Rare Observation of Brachymetacarpia and Brachymetatarsia in a Patient with Primary Idiopathic Hypoparathyroidism"],"prefix":"10.1155","volume":"2023","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-7029-7781","authenticated-orcid":true,"given":"Parackrama","family":"Karunathilake","sequence":"first","affiliation":[{"name":"National Hospital Kandy, Kandy 20000, Sri Lanka"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-5849-8962","authenticated-orcid":true,"given":"Arun","family":"Rajaratnam","sequence":"additional","affiliation":[{"name":"National Hospital Kandy, Kandy 20000, Sri Lanka"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0009-0008-2902-3077","authenticated-orcid":true,"given":"W. K. S.","family":"Kularatne","sequence":"additional","affiliation":[{"name":"National Hospital Kandy, Kandy 20000, Sri Lanka"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"311","reference":[{"issue":"2","key":"1","first-page":"162","article-title":"A rare case of bilateral idiopathic brachymetacarpia and brachymetatarsia","volume":"1","author":"B. Aski","year":"2022","journal-title":"International Journal of Advances in Medicine"},{"issue":"1","key":"2","first-page":"15","article-title":"Brachymetacarpia and brachymetatarsia: do we need to operate?","volume":"6","author":"S. Barik","year":"2021","journal-title":"EFORT Open Reviews"},{"issue":"5","key":"3","doi-asserted-by":"crossref","first-page":"735","DOI":"10.1016\/S0363-5023(86)80023-5","article-title":"Idiopathic bilaterally symmetrical brachymetacarpia of the fourth and fifth metacarpals","volume":"11","author":"B. T. Cohn","year":"1986","journal-title":"Journal of Hand Surgery"},{"key":"4","doi-asserted-by":"crossref","first-page":"924","DOI":"10.4103\/2230-8210.117221","article-title":"Short fourth and fifth metacarpals in a case of idiopathic primary hypoparathyroidism","volume":"17","author":"N. Valizadeh","year":"2013","journal-title":"Indian Journal of Endocrinology and Metabolism"},{"issue":"3","key":"5","doi-asserted-by":"crossref","first-page":"339","DOI":"10.1177\/1558944717736859","article-title":"Metacarpal lengthening in adults with brachymetacarpia","volume":"14","author":"A. Lam","year":"2019","journal-title":"Hand"},{"key":"6","doi-asserted-by":"publisher","DOI":"10.1186\/1750-1172-3-15"},{"issue":"3","key":"7","doi-asserted-by":"crossref","first-page":"555","DOI":"10.1016\/j.fcl.2004.05.002","article-title":"Brachymetatarsia","volume":"9","author":"A. Schimizzi","year":"2004","journal-title":"Foot and Ankle Clinics"},{"key":"8","article-title":"Hypoparathyroidism and pseudohypoparathyroidism","volume-title":"Diseases of the Parathyroid Glands","author":"G. N. Hendy","year":"2022"},{"issue":"3","key":"9","doi-asserted-by":"crossref","first-page":"363","DOI":"10.1507\/endocrj1954.31.363","article-title":"A patient of short stature with idiopathic hypoparathyroidism round face and metacarpal signs","volume":"31","author":"O. Isozaki","year":"1984","journal-title":"Endocrinologia Japonica"},{"key":"10","first-page":"262","article-title":"A rare case report of idiopathic primary hypoparathyroidism coexisting with shortening of third to fifth metacarpal bones","volume":"5","author":"S. S. Ali","year":"2018","journal-title":"Crescent Journal of Medical and Biological Sciences"},{"issue":"3","key":"11","first-page":"300","article-title":"Bilateral short fourth metacarpal and metatarsal in a case of idiopathic primary hypoparathyroidism","volume":"2","author":"C. Nayak","year":"2017","journal-title":"International Journal of Advances in Medicine"}],"container-title":["Case Reports in Endocrinology"],"original-title":[],"language":"en","link":[{"URL":"http:\/\/downloads.hindawi.com\/journals\/crie\/2023\/4149677.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"http:\/\/downloads.hindawi.com\/journals\/crie\/2023\/4149677.xml","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"http:\/\/downloads.hindawi.com\/journals\/crie\/2023\/4149677.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2023,2,28]],"date-time":"2023-02-28T20:35:15Z","timestamp":1677616515000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.hindawi.com\/journals\/crie\/2023\/4149677\/"}},"subtitle":[],"editor":[{"given":"Micha\u00ebl R.","family":"Laurent","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"editor"}]}],"short-title":[],"issued":{"date-parts":[[2023,2,28]]},"references-count":11,"alternative-id":["4149677","4149677"],"URL":"https:\/\/doi.org\/10.1155\/2023\/4149677","relation":{},"ISSN":["2090-651X","2090-6501"],"issn-type":[{"value":"2090-651X","type":"electronic"},{"value":"2090-6501","type":"print"}],"subject":[],"published":{"date-parts":[[2023,2,28]]}}}