{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,4,14]],"date-time":"2026-04-14T15:28:54Z","timestamp":1776180534380,"version":"3.50.1"},"reference-count":35,"publisher":"Wiley","issue":"1","license":[{"start":{"date-parts":[[2023,4,11]],"date-time":"2023-04-11T00:00:00Z","timestamp":1681171200000},"content-version":"vor","delay-in-days":100,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Case Reports in Dentistry"],"published-print":{"date-parts":[[2023,1]]},"abstract":"<jats:p>\n                    This report presents an extremely rare case of\n                    <jats:italic>MAML2<\/jats:italic>\n                    \u2010rearranged primary central mucoepidermoid carcinoma (MEC) of the mandible that was discovered as an incidental finding. Our review of the literature identified 36 cases of\n                    <jats:italic>MAML2-<\/jats:italic>\n                    rearranged intraosseous lesions of the jaw (30 central MECs, 5 odontogenic cysts with mucous prosoplasia, and 1 glandular odontogenic cyst). Given the therapeutic indications for a diagnosis of MEC (a malignant neoplasm),\n                    <jats:italic>MAML2<\/jats:italic>\n                    rearrangement should be confirmed in suspected cases of central MEC.\n                  <\/jats:p>","DOI":"10.1155\/2023\/7764292","type":"journal-article","created":{"date-parts":[[2023,4,11]],"date-time":"2023-04-11T21:20:07Z","timestamp":1681248007000},"update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":1,"title":["<i>MAML2<\/i>\n                    \u2010Rearranged Primary Central Mucoepidermoid Carcinoma of the Mandible as an Incidental Finding: A Case Report and Review of the Literature of Molecularly Confirmed Cases"],"prefix":"10.1155","volume":"2023","author":[{"given":"Sarah E.","family":"Aguirre","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"suffix":"Jr.","given":"Donald","family":"Tyler","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-4602-9469","authenticated-orcid":false,"given":"Adepitan A.","family":"Owosho","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"311","published-online":{"date-parts":[[2023,4,11]]},"reference":[{"key":"e_1_2_8_1_2","doi-asserted-by":"publisher","DOI":"10.1002\/1097-0142(197501)35:1<270::AID-CNCR2820350134>3.0.CO;2-Y"},{"key":"e_1_2_8_2_2","doi-asserted-by":"publisher","DOI":"10.1016\/0030-4220(84)90165-8"},{"key":"e_1_2_8_3_2","doi-asserted-by":"publisher","DOI":"10.1016\/0278-2391(92)90317-S"},{"key":"e_1_2_8_4_2","doi-asserted-by":"publisher","DOI":"10.1016\/0278-2391(90)90245-W"},{"key":"e_1_2_8_5_2","doi-asserted-by":"publisher","DOI":"10.1097\/00000658-194511000-00005"},{"key":"e_1_2_8_6_2","doi-asserted-by":"publisher","DOI":"10.1054\/ijom.2002.0374"},{"key":"e_1_2_8_7_2","doi-asserted-by":"publisher","DOI":"10.1007\/s00428-021-03146-x"},{"key":"e_1_2_8_8_2","doi-asserted-by":"publisher","DOI":"10.1038\/modpathol.2009.126"},{"key":"e_1_2_8_9_2","doi-asserted-by":"publisher","DOI":"10.1097\/PAS.0b013e3181de3021"},{"key":"e_1_2_8_10_2","doi-asserted-by":"publisher","DOI":"10.1007\/s12105-010-0191-5"},{"key":"e_1_2_8_11_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.anndiagpath.2010.05.009"},{"key":"e_1_2_8_12_2","doi-asserted-by":"publisher","DOI":"10.1007\/s12105-014-0534-8"},{"key":"e_1_2_8_13_2","doi-asserted-by":"publisher","DOI":"10.1111\/his.12526"},{"key":"e_1_2_8_14_2","doi-asserted-by":"publisher","DOI":"10.1002\/hed.24219"},{"key":"e_1_2_8_15_2","doi-asserted-by":"publisher","DOI":"10.1111\/pin.12609"},{"key":"e_1_2_8_16_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.oooo.2018.12.003"},{"key":"e_1_2_8_17_2","doi-asserted-by":"publisher","DOI":"10.1186\/s13000-021-01124-0"},{"key":"e_1_2_8_18_2","article-title":"Unicystic mucoepidermoid carcinoma: a pitfall for clinical and pathologic diagnosis","volume":"2022","author":"Wang X.","year":"2022","journal-title":"Journal of Oncology"},{"key":"e_1_2_8_19_2","doi-asserted-by":"publisher","DOI":"10.1097\/MD.0000000000013691"},{"key":"e_1_2_8_20_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.oooo.2011.12.021"},{"key":"e_1_2_8_21_2","doi-asserted-by":"publisher","DOI":"10.1016\/0030-4220(75)90373-4"},{"key":"e_1_2_8_22_2","doi-asserted-by":"publisher","DOI":"10.1016\/0278-2391(90)90349-7"},{"key":"e_1_2_8_23_2","doi-asserted-by":"publisher","DOI":"10.1053\/adpa.2000.19395"},{"key":"e_1_2_8_24_2","doi-asserted-by":"publisher","DOI":"10.1053\/joms.2002.29827"},{"key":"e_1_2_8_25_2","doi-asserted-by":"publisher","DOI":"10.1097\/PAS.0000000000001886"},{"key":"e_1_2_8_26_2","doi-asserted-by":"publisher","DOI":"10.1111\/1759-7714.14536"},{"key":"e_1_2_8_27_2","first-page":"1413","article-title":"CRTC1-MAML2 gene fusion in mucoepidermoid carcinoma of the lacrimal gland","volume":"27","author":"Von Holstein S. 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