{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,11,5]],"date-time":"2026-11-05T11:42:11Z","timestamp":1793878931638,"version":"4.7.0"},"reference-count":63,"publisher":"S. Karger AG","issue":"2-3","license":[{"start":{"date-parts":[[2019,1,1]],"date-time":"2019-01-01T00:00:00Z","timestamp":1546300800000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/www.karger.com\/Services\/SiteLicenses"},{"start":{"date-parts":[[2019,1,1]],"date-time":"2019-01-01T00:00:00Z","timestamp":1546300800000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.karger.com\/Services\/SiteLicenses"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["ORL"],"published-print":{"date-parts":[[2019]]},"abstract":"<jats:p>&lt;b&gt;&lt;i&gt;Background\/Aims:&lt;\/i&gt;&lt;\/b&gt; To review the existing literature on pigmented villonodular synovitis (PVNS) of the temporomandibular joint (TMJ) and report a rare case of PVNS of the TMJ presenting with unilateral hearing loss. &lt;b&gt;&lt;i&gt;Methods:&lt;\/i&gt;&lt;\/b&gt; Review of the existing literature and a description of personal experience with PVNS of the TMJ presenting with unilateral hearing loss. &lt;b&gt;&lt;i&gt;Results:&lt;\/i&gt;&lt;\/b&gt; Review of the existing literature revealed 76 reported cases of PVNS of the TMJ. The most common presenting symptom was of a slowly enlarging mass or swelling of the preauricular area, with dysfunctional TMJ also frequently reported. All patients underwent surgical excision with some pursuing radiation as adjuvant therapy. &lt;b&gt;&lt;i&gt;Presented Patient:&lt;\/i&gt;&lt;\/b&gt; A 46-year-old man presented with several months of unilateral subjective hearing loss and aural fullness. Imaging revealed a mass centered along the superior TMJ with expansion through the squamous temporal bone and extra-axial intracranial extension into the middle cranial fossa. Imaging characteristics and fine-needle aspiration biopsy were consistent with PVNS. &lt;b&gt;&lt;i&gt;Intervention:&lt;\/i&gt;&lt;\/b&gt; The patient underwent near-total excision of the mass via frontotemporal craniectomy and lateral temporal bone resection. &lt;b&gt;&lt;i&gt;Follow-Up:&lt;\/i&gt;&lt;\/b&gt; At the 16-month follow-up there was no evidence of disease recurrence. &lt;b&gt;&lt;i&gt;Conclusion:&lt;\/i&gt;&lt;\/b&gt; PVNS of the TMJ represents a rare entity that can present with a variety of symptoms including unilateral hearing loss.<\/jats:p>","DOI":"10.1159\/000499473","type":"journal-article","created":{"date-parts":[[2019,7,17]],"date-time":"2019-07-17T21:00:30Z","timestamp":1563397230000},"page":"171-182","source":"Crossref","is-referenced-by-count":8,"title":["Pigmented Villonodular Synovitis Presenting as Unilateral Hearing Loss: Review of the Literature and Case 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