{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,7,17]],"date-time":"2026-07-17T12:43:21Z","timestamp":1784292201801,"version":"3.55.0"},"reference-count":17,"publisher":"S. Karger AG","issue":"3","license":[{"start":{"date-parts":[[2025,5,30]],"date-time":"2025-05-30T00:00:00Z","timestamp":1748563200000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by-nc\/4.0\/"},{"start":{"date-parts":[[2025,5,30]],"date-time":"2025-05-30T00:00:00Z","timestamp":1748563200000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by-nc\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Neuroepidemiology"],"abstract":"<jats:p>&lt;p&gt;Introduction: Screening questions are important in identifying subgroups of individuals within a target population. Dystonic movements and postures are not uncommon in patients with essential tremor (ET). There is a gap in knowledge \u2013 no studies have assessed the validity of a self-report of dystonia in ET patients. We assessed the concordance between self-reported dystonia and the presence or absence of dystonia on examination (DOE). Methods: We obtained self-report data from 274 ET cases in a serial study with up to five follow-up evaluations. At each assessment, participants could self-report dystonia, and they underwent a detailed neurological examination, from which a movement disorders neurologist assessed for the presence of DOE. Results: Across time, the prevalence of self-reported dystonia and DOE ranged from 0.0% to 4.3% and 8.6% to 17.5%, respectively. There were 74 cases with either self-reported dystonia or DOE; in only 3 (4.1%) was there a positive concordance between the two at each of their evaluations. Values for sensitivity ranged from 0.0% to 40%; specificity from 96.1% to 100%; positive predictive value from 0.0% to 67.0% (median 30.0%); and negative predictive value from 83.1% to 94.4%. Conclusion: Our study provides important insights into the validity of self-report data on dystonia in ET and the prevalence of DOE in ET. Our findings suggest that self-reported dystonia was not a valid means to identify DOE in ET. &lt;\/p&gt;<\/jats:p>","DOI":"10.1159\/000546428","type":"journal-article","created":{"date-parts":[[2025,5,30]],"date-time":"2025-05-30T12:02:04Z","timestamp":1748606524000},"page":"463-472","source":"Crossref","is-referenced-by-count":2,"title":["Self-Reported Dystonia and Dystonia on Neurological Examination: Prevalence and Concordance across Time in a Prospectively Followed Essential Tremor Cohort"],"prefix":"10.1159","volume":"60","author":[{"given":"Tomer O.","family":"Guy","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Diane S.","family":"Berry","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Vibhash D.","family":"Sharma","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Elan D.","family":"Louis","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"127","published-online":{"date-parts":[[2025,5,30]]},"reference":[{"key":"ref1","doi-asserted-by":"publisher","DOI":"10.5334\/tohm.690"},{"key":"ref2","doi-asserted-by":"publisher","DOI":"10.1159\/000502455"},{"key":"ref3","doi-asserted-by":"publisher","DOI":"10.1002\/ana.26927"},{"key":"ref4","doi-asserted-by":"publisher","DOI":"10.1159\/000109681"},{"key":"ref5","doi-asserted-by":"publisher","DOI":"10.1002\/ana.410350613"},{"key":"ref6","doi-asserted-by":"publisher","DOI":"10.1212\/wnl.41.2_part_1.234"},{"key":"ref7","doi-asserted-by":"publisher","DOI":"10.1093\/jnci\/92.16.1280"},{"key":"ref8","doi-asserted-by":"publisher","DOI":"10.1016\/j.jns.2021.117563"},{"key":"ref9","doi-asserted-by":"publisher","DOI":"10.7916\/D8B00NRV"},{"key":"ref10","doi-asserted-by":"publisher","DOI":"10.5858\/2007-131-702-CROTAA"},{"key":"ref11","doi-asserted-by":"publisher","DOI":"10.1016\/j.jns.2018.08.006"},{"key":"ref12","doi-asserted-by":"publisher","DOI":"10.1002\/mds.870130215"},{"key":"ref13","doi-asserted-by":"publisher","DOI":"10.1002\/mds.1144"},{"key":"ref14","doi-asserted-by":"publisher","DOI":"10.3109\/08958378.2014.955932"},{"key":"ref15","doi-asserted-by":"publisher","DOI":"10.1016\/j.jns.2023.120550"},{"key":"ref16","doi-asserted-by":"publisher","DOI":"10.1016\/j.jns.2023.120854"},{"key":"ref17","doi-asserted-by":"publisher","DOI":"10.1212\/wnl.43.11.2382"}],"container-title":["Neuroepidemiology"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/karger.com\/article-pdf\/doi\/10.1159\/000546428","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/karger.com\/article-pdf\/doi\/10.1159\/000546428","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,6,1]],"date-time":"2026-06-01T16:04:31Z","timestamp":1780329871000},"score":1,"resource":{"primary":{"URL":"https:\/\/karger.com\/article\/doi\/10.1159\/000546428"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2025,5,30]]},"references-count":17,"journal-issue":{"issue":"3","published-online":{"date-parts":[[2026,6,1]]},"published-print":{"date-parts":[[2026,6,3]]}},"URL":"https:\/\/doi.org\/10.1159\/000546428","archive":["Portico"],"relation":{"is-supplemented-by":[{"id-type":"doi","id":"10.6084\/m9.figshare.29092394","asserted-by":"subject"}]},"ISSN":["0251-5350","1423-0208"],"issn-type":[{"value":"0251-5350","type":"print"},{"value":"1423-0208","type":"electronic"}],"subject":[],"published":{"date-parts":[[2025,5,30]]}}}