{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,4,30]],"date-time":"2026-04-30T04:25:38Z","timestamp":1777523138236,"version":"3.51.4"},"reference-count":17,"publisher":"SAGE Publications","issue":"7","license":[{"start":{"date-parts":[[2019,1,17]],"date-time":"2019-01-17T00:00:00Z","timestamp":1547683200000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["The Cleft Palate Craniofacial Journal"],"published-print":{"date-parts":[[2019,8]]},"abstract":"<jats:p>This case report intends to provide the facial characteristics of Escobar syndrome and to describe the orthodontic treatment of a 12-year-old female patient diagnosed with it. Escobar syndrome, a variant of the multiple pterygium syndrome, is a rare disorder with many systemic, facial, and oral manifestations.The patient presented with mixed dentition, severe dolichofacial pattern, increased lower facial height, convex profile, severe anterior open bite, maxillary hypoplasia, and mandibular retrognatism. The multidisciplinary approach included soft cleft palate repair, orthodontic treatment, orthognathic surgery, restorative cosmetic dentistry, speech therapy, and physiotherapy. Despite the limitations imposed by the syndrome, this report illustrates how the multidisciplinary treatment approach aided in the correction of occlusal function and facial esthetics and improvement in the quality of life of the patient with Escobar syndrome.<\/jats:p>","DOI":"10.1177\/1055665618823416","type":"journal-article","created":{"date-parts":[[2019,1,17]],"date-time":"2019-01-17T21:21:02Z","timestamp":1547760062000},"page":"970-977","update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":3,"title":["Escobar Syndrome\u2014An Multidisciplinary Approach for an Excellent Outcome With 3 Years of Follow-Up"],"prefix":"10.1177","volume":"56","author":[{"given":"Fernanda Blaudt C.","family":"Marques","sequence":"first","affiliation":[{"name":"Department of Pedodontics and Orthodontics, Dental School, Federal University of Rio de Janeiro, Rio de Janeiro, Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Liliane Siqueira","family":"de Morais","sequence":"additional","affiliation":[{"name":"Department of Pediatric Dentistry and Orthodontics, Dental School, Federal University of Rio de Janeiro, Rio de Janeiro, Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Luciana Rougemont","family":"Squeff","sequence":"additional","affiliation":[{"name":"Department of Pediatric Dentistry and Orthodontics, Dental School, Federal University of Rio de Janeiro, Rio de Janeiro, Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Margareth Maria Gomes","family":"de Souza","sequence":"additional","affiliation":[{"name":"Department of Pediatric Dentistry and Orthodontics, Dental School, Federal University of Rio de Janeiro, Rio de Janeiro, Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ana Maria","family":"Bolognese","sequence":"additional","affiliation":[{"name":"Department of Pediatric Dentistry and Orthodontics, Dental School, Federal University of Rio de Janeiro, Rio de Janeiro, Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"179","published-online":{"date-parts":[[2019,1,17]]},"reference":[{"key":"e_1_3_2_2_1","doi-asserted-by":"publisher","DOI":"10.1097\/ANC.0000000000000039"},{"key":"e_1_3_2_3_1","doi-asserted-by":"publisher","DOI":"10.1007\/s00431-014-2324-4"},{"key":"e_1_3_2_4_1","first-page":"59","volume-title":"Rev Mex Ortop Ped","author":"Camarena CA","year":"2010","unstructured":"Camarena CA, Vernis AM, Martinez AC, Ramirez AI. Sindrome de Escobar. Rev Mex Ortop Ped. 2010;12(1):59\u201362."},{"key":"e_1_3_2_5_1","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.1320070203"},{"key":"e_1_3_2_6_1","doi-asserted-by":"publisher","DOI":"10.1590\/S1678-77572008000300012"},{"key":"e_1_3_2_7_1","doi-asserted-by":"publisher","DOI":"10.3109\/14767058.2010.482615"},{"issue":"6","key":"e_1_3_2_8_1","first-page":"609","article-title":"Multiple pterygium syndrome","volume":"132","author":"Escobar V","year":"1978","unstructured":"Escobar V, Gleiser S, Weaver DD, Gibbs T. Multiple pterygium syndrome. Am J Dis Child. 1978;132(6):609\u2013611.","journal-title":"Am J Dis Child"},{"key":"e_1_3_2_9_1","doi-asserted-by":"publisher","DOI":"10.1136\/jmg.15.1.35"},{"key":"e_1_3_2_10_1","doi-asserted-by":"publisher","DOI":"10.1515\/JPEM.2011.367"},{"key":"e_1_3_2_11_1","doi-asserted-by":"publisher","DOI":"10.1086\/506257"},{"key":"e_1_3_2_12_1","doi-asserted-by":"publisher","DOI":"10.1097\/BPO.0b013e31823ab359"},{"key":"e_1_3_2_13_1","doi-asserted-by":"publisher","DOI":"10.1007\/978-3-540-95928-1"},{"issue":"5","key":"e_1_3_2_14_1","first-page":"559","article-title":"The association of Klinefelter syndrome and multiple pterygium syndrome: an unusual presentation","volume":"55","author":"Nur BG","year":"2013","unstructured":"Nur BG, Altiok-Clark \u00d6, Toylu A, L\u00fcleci G, Mih\u00e7i E. The association of Klinefelter syndrome and multiple pterygium syndrome: an unusual presentation. Turk J Pediatr. 2013;55(5):559\u2013563.","journal-title":"Turk J Pediatr"},{"key":"e_1_3_2_15_1","doi-asserted-by":"publisher","DOI":"10.1016\/S1015-9584(09)60118-4"},{"key":"e_1_3_2_16_1","doi-asserted-by":"publisher","DOI":"10.14219\/jada.archive.1999.0032"},{"key":"e_1_3_2_17_1","doi-asserted-by":"publisher","DOI":"10.1038\/jhg.2015.2"},{"key":"e_1_3_2_18_1","doi-asserted-by":"publisher","DOI":"10.1159\/000365330"}],"container-title":["The Cleft Palate Craniofacial Journal"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/1055665618823416","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/full-xml\/10.1177\/1055665618823416","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/1055665618823416","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,4,28]],"date-time":"2026-04-28T16:19:50Z","timestamp":1777393190000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.sagepub.com\/doi\/10.1177\/1055665618823416"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2019,1,17]]},"references-count":17,"journal-issue":{"issue":"7","published-print":{"date-parts":[[2019,8]]}},"alternative-id":["10.1177\/1055665618823416"],"URL":"https:\/\/doi.org\/10.1177\/1055665618823416","relation":{},"ISSN":["1055-6656","1545-1569"],"issn-type":[{"value":"1055-6656","type":"print"},{"value":"1545-1569","type":"electronic"}],"subject":[],"published":{"date-parts":[[2019,1,17]]}}}