{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,4,30]],"date-time":"2026-04-30T04:26:46Z","timestamp":1777523206677,"version":"3.51.4"},"reference-count":15,"publisher":"SAGE Publications","issue":"2","license":[{"start":{"date-parts":[[2019,8,5]],"date-time":"2019-08-05T00:00:00Z","timestamp":1564963200000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["The Cleft Palate Craniofacial Journal"],"published-print":{"date-parts":[[2020,2]]},"abstract":"<jats:p>\n                    Basal cell nevus syndrome (BCNS) is a rare genetic disorder that can be caused by mutation of multiple genes, including\n                    <jats:italic>PTCH1<\/jats:italic>\n                    ,\n                    <jats:italic>PTCH2<\/jats:italic>\n                    , and\n                    <jats:italic>SUFU<\/jats:italic>\n                    , in an autosomal dominant manner. The symptoms include some craniofacial features such as keratocystic odontogenic tumors (KCOTs), macrocephaly, and cleft lip and\/or palate. Although comprehensive orthodontic treatment is frequently required for some of these craniofacial deformities, there are few reports that show the outcomes of comprehensive orthodontic treatment. Here, we report a case of BCNS with multiple KCOTs, macrocephaly, skeletal class III malocclusion, asymmetric dental arch, and mandibular crowding, which was successfully treated with comprehensive orthodontic treatment.\n                  <\/jats:p>","DOI":"10.1177\/1055665619866562","type":"journal-article","created":{"date-parts":[[2019,8,5]],"date-time":"2019-08-05T23:44:15Z","timestamp":1565048655000},"page":"255-262","update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":1,"title":["Multidisciplinary Approach for Treating Malocclusion of Patient With Basal Cell Nevus Syndrome: A Case Report"],"prefix":"10.1177","volume":"57","author":[{"given":"Sayuri","family":"Inoue","sequence":"first","affiliation":[{"name":"Department of Orthodontics and Dentofacial Orthopedics, Osaka University Graduate School of Dentistry, Suita, Osaka, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-8956-5467","authenticated-orcid":false,"given":"Hiroshi","family":"Kurosaka","sequence":"additional","affiliation":[{"name":"Department of Orthodontics and Dentofacial Orthopedics, Osaka University Graduate School of Dentistry, Suita, Osaka, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Donghoon","family":"Lee","sequence":"additional","affiliation":[{"name":"Department of Orthodontics and Dentofacial Orthopedics, Osaka University Graduate School of Dentistry, Suita, Osaka, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Takashi","family":"Yamashiro","sequence":"additional","affiliation":[{"name":"Department of Orthodontics and Dentofacial Orthopedics, Osaka University Graduate School of Dentistry, Suita, Osaka, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"179","published-online":{"date-parts":[[2019,8,5]]},"reference":[{"key":"e_1_3_2_2_1","doi-asserted-by":"publisher","DOI":"10.1007\/s12663-011-0262-5"},{"key":"e_1_3_2_3_1","doi-asserted-by":"publisher","DOI":"10.1563\/AAID-JOI-D-11-00022"},{"key":"e_1_3_2_4_1","doi-asserted-by":"publisher","DOI":"10.1563\/AAID-JOI-D-13-00235"},{"key":"e_1_3_2_5_1","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.a.34421"},{"key":"e_1_3_2_6_1","doi-asserted-by":"publisher","DOI":"10.1056\/NEJM196005052621803"},{"issue":"8","key":"e_1_3_2_7_1","first-page":"140","article-title":"The multiple nevoid basal cell carcinoma syndrome revisited","volume":"7","author":"Gorlin RJ","year":"1971","unstructured":"Gorlin RJ, Sedano HO. The multiple nevoid basal cell carcinoma syndrome revisited. Birth Defects Orig Artic Ser. 1971;7(8):140\u2013148.","journal-title":"Birth Defects Orig Artic Ser"},{"key":"e_1_3_2_8_1","doi-asserted-by":"publisher","DOI":"10.1097\/01.GIM.0000144188.15902.C4"},{"key":"e_1_3_2_9_1","doi-asserted-by":"publisher","DOI":"10.1242\/dev.126.21.4873"},{"key":"e_1_3_2_10_1","doi-asserted-by":"publisher","DOI":"10.1172\/JCI72688"},{"key":"e_1_3_2_11_1","doi-asserted-by":"publisher","DOI":"10.1371\/journal.pone.0120821"},{"key":"e_1_3_2_12_1","doi-asserted-by":"publisher","DOI":"10.1016\/S0889-5406(99)70321-5"},{"key":"e_1_3_2_13_1","doi-asserted-by":"publisher","DOI":"10.1597\/14-323"},{"key":"e_1_3_2_14_1","doi-asserted-by":"publisher","DOI":"10.1177\/1055665618777573"},{"key":"e_1_3_2_15_1","doi-asserted-by":"publisher","DOI":"10.1200\/JCO.2014.58.2569"},{"issue":"9","key":"e_1_3_2_16_1","first-page":"659","article-title":"The origin of keratocysts in the basal cell nevus syndrome","volume":"33","author":"Stoelinga PJ","year":"1975","unstructured":"Stoelinga PJ, Cohen MMJr, Morgan AF. The origin of keratocysts in the basal cell nevus syndrome. J Oral Surg. 1975;33(9):659\u2013663.","journal-title":"J Oral Surg"}],"container-title":["The Cleft Palate Craniofacial Journal"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/1055665619866562","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/full-xml\/10.1177\/1055665619866562","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/1055665619866562","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,4,28]],"date-time":"2026-04-28T16:20:10Z","timestamp":1777393210000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.sagepub.com\/doi\/10.1177\/1055665619866562"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2019,8,5]]},"references-count":15,"journal-issue":{"issue":"2","published-print":{"date-parts":[[2020,2]]}},"alternative-id":["10.1177\/1055665619866562"],"URL":"https:\/\/doi.org\/10.1177\/1055665619866562","relation":{},"ISSN":["1055-6656","1545-1569"],"issn-type":[{"value":"1055-6656","type":"print"},{"value":"1545-1569","type":"electronic"}],"subject":[],"published":{"date-parts":[[2019,8,5]]}}}