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We report an exceptional case of a 4-year-old girl with a congenital unilateral solitary lower lip pit, without cleft lip\/palate or any family history of similar conditions. Hyperdontia was also incidentally identified, further emphasizing the rarity of this presentation. The lesion was treated with elliptical excision, resulting in an optimal aesthetic outcome, proving to be an effective and straightforward treatment approach. Although genetic testing was not feasible due to resource limitations, the possibility of recurrence in future generations should still be communicated to the family.<\/jats:p>","DOI":"10.1177\/10556656251382692","type":"journal-article","created":{"date-parts":[[2025,10,17]],"date-time":"2025-10-17T17:47:33Z","timestamp":1760723253000},"page":"2681-2689","update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":0,"title":["A Rare Congenital Unilateral Solitary Lower Lip Pit without Cleft Lip and\/or Palate: Case Report and Structured Review"],"prefix":"10.1177","volume":"63","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-7197-3737","authenticated-orcid":false,"given":"Robertus Arian","family":"Datusanantyo","sequence":"first","affiliation":[{"name":"Universitas Nusa Cendana"},{"name":"Department of Plastic Reconstructive &amp; Aesthetic Surgery, Faculty of Medicine, Universitas Brawijaya, Malang, Indonesia"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0009-0004-7265-7455","authenticated-orcid":false,"given":"Indah","family":"Wulansari","sequence":"additional","affiliation":[{"name":"Naibonat General Hospital"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0009-0003-3679-3049","authenticated-orcid":false,"given":"James","family":"Soewardy","sequence":"additional","affiliation":[{"name":"Emergency Department, Komodo General Hospital"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"179","published-online":{"date-parts":[[2025,10,17]]},"reference":[{"key":"e_1_3_3_2_2","doi-asserted-by":"publisher","DOI":"10.4103\/2321-4848.171923"},{"key":"e_1_3_3_3_2","doi-asserted-by":"publisher","DOI":"10.1016\/S0007-1226(71)80063-2"},{"key":"e_1_3_3_4_2","doi-asserted-by":"publisher","DOI":"10.4103\/0972-1363.170171"},{"key":"e_1_3_3_5_2","doi-asserted-by":"publisher","DOI":"10.4103\/0378-6323.79744"},{"key":"e_1_3_3_6_2","doi-asserted-by":"publisher","DOI":"10.1016\/S0007-1226(51)80043-2"},{"key":"e_1_3_3_7_2","doi-asserted-by":"publisher","DOI":"10.5005\/jp\/books\/11412"},{"key":"e_1_3_3_8_2","doi-asserted-by":"publisher","DOI":"10.1097\/00000637-198904000-00006"},{"issue":"2","key":"e_1_3_3_9_2","first-page":"244","article-title":"Fistula labii inferioris congenita and its association with cleft lip and palate","volume":"6","author":"Van der Woud A","year":"1954","unstructured":"Van der Woud A. 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