{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,7,30]],"date-time":"2026-07-30T22:03:52Z","timestamp":1785449032193,"version":"3.56.0"},"reference-count":46,"publisher":"SAGE Publications","license":[{"start":{"date-parts":[[2026,7,29]],"date-time":"2026-07-29T00:00:00Z","timestamp":1785283200000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"},{"start":{"date-parts":[[2026,7,29]],"date-time":"2026-07-29T00:00:00Z","timestamp":1785283200000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"funder":[{"DOI":"10.13039\/100000072","name":"National Institute of Dental and Craniofacial Research","doi-asserted-by":"publisher","award":["R01DE029510"],"award-info":[{"award-number":["R01DE029510"]}],"id":[{"id":"10.13039\/100000072","id-type":"DOI","asserted-by":"publisher"}]}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["The Cleft Palate Craniofacial Journal"],"abstract":"<jats:sec>\n                    <jats:title>Objective<\/jats:title>\n                    <jats:p>To explore factors associated with caregiver psychological distress and family quality of life (QoL) in craniofacial microsomia (CFM).<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Design<\/jats:title>\n                    <jats:p>Online cross-sectional survey.<\/jats:p>\n                    <jats:p>\n                      <jats:bold>Participants:<\/jats:bold>\n                      Forty caregivers (38 mothers) of children with CFM.\n                    <\/jats:p>\n                    <jats:p>\n                      <jats:bold>Outcome Measures:<\/jats:bold>\n                      Pediatric Quality of Life Inventory (Family Impact Module), Perceived Stress Scale, Hospital Anxiety and Depression Scale, and PTSD Checklist.\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Results<\/jats:title>\n                    <jats:p>Most caregivers (75%) were in \u201cborderline\u201d or \u201cconcern\u201d risk categories for QoL. Caregivers reported significantly more symptoms of anxiety, depression, stress, and PTSD than norms. Factors associated with caregiver distress and family QoL included the number of child CFM characteristics and prior surgeries, and caregivers\u2019 healthcare satisfaction, life orientation, resilience, and relationship satisfaction.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusions<\/jats:title>\n                    <jats:p>This study represents a small, self-selected, clinically impacted group of caregivers. Yet, findings align with similar studies and highlight a subset of families in need of psychological support. The findings can be tentatively used to inform larger studies, screening practices, and intervention targets.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.1177\/10556656261470559","type":"journal-article","created":{"date-parts":[[2026,7,29]],"date-time":"2026-07-29T13:46:06Z","timestamp":1785332766000},"update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":0,"title":["Psychological Health in Caregivers of Children With Craniofacial Microsomia: Exploring Factors Associated With Distress and Family Quality of Life"],"prefix":"10.1177","author":[{"given":"Debora","family":"Blaso","sequence":"first","affiliation":[{"name":"University of the West of England"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Paul","family":"White","sequence":"additional","affiliation":[{"name":"University of the West of England"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-2029-5873","authenticated-orcid":false,"given":"Alexis L.","family":"Johns","sequence":"additional","affiliation":[{"name":"Children's Hospital Los Angeles"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-0040-6396","authenticated-orcid":false,"given":"Canice E.","family":"Crerand","sequence":"additional","affiliation":[{"name":"Nationwide Children's Hospital"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Leanne","family":"Magee","sequence":"additional","affiliation":[{"name":"Children's Hospital of Philadelphia"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-0329-5671","authenticated-orcid":false,"given":"Kristin","family":"B. Feragen","sequence":"additional","affiliation":[{"name":"Centre for Rare Disorders, Oslo University Hospital, Oslo, Norway"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Matthew","family":"Hotton","sequence":"additional","affiliation":[{"name":"University of Oxford"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Laura P.","family":"Stueckle","sequence":"additional","affiliation":[{"name":"Seattle Children's Research Institute"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Angela","family":"Mills","sequence":"additional","affiliation":[{"name":"Seattle Children's Research Institute"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Melissa","family":"Tumblin","sequence":"additional","affiliation":[{"name":"Seattle Children's Research Institute"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Amy","family":"Schefer","sequence":"additional","affiliation":[{"name":"Seattle Children's Research Institute"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Amelia F.","family":"Drake","sequence":"additional","affiliation":[{"name":"University of North Carolina at Chapel Hill School of Medicine"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-2178-7730","authenticated-orcid":false,"given":"Carrie L.","family":"Heike","sequence":"additional","affiliation":[{"name":"Seattle Children's Research Institute"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-1285-691X","authenticated-orcid":false,"given":"Nicola M.","family":"Stock","sequence":"additional","affiliation":[{"name":"University of the West of England"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"179","published-online":{"date-parts":[[2026,7,29]]},"reference":[{"key":"e_1_3_3_2_2","doi-asserted-by":"publisher","DOI":"10.1177\/10556656241245284"},{"key":"e_1_3_3_3_2","doi-asserted-by":"publisher","DOI":"10.1177\/10556656221091699"},{"key":"e_1_3_3_4_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.ijporl.2018.02.007"},{"key":"e_1_3_3_5_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.jogn.2024.01.001"},{"key":"e_1_3_3_6_2","doi-asserted-by":"publisher","DOI":"10.1097\/SCS.0000000000004867"},{"key":"e_1_3_3_7_2","doi-asserted-by":"publisher","DOI":"10.5014\/ajot.2021.041277"},{"key":"e_1_3_3_8_2","doi-asserted-by":"publisher","DOI":"10.1177\/1055665618821014"},{"key":"e_1_3_3_9_2","doi-asserted-by":"publisher","DOI":"10.1097\/SCS.0000000000011643"},{"key":"e_1_3_3_10_2","doi-asserted-by":"publisher","DOI":"10.1097\/PRS.0b013e31819e5bea"},{"key":"e_1_3_3_11_2","doi-asserted-by":"publisher","DOI":"10.1177\/1055665619869146"},{"key":"e_1_3_3_12_2","doi-asserted-by":"publisher","DOI":"10.1177\/10556656241305889"},{"key":"e_1_3_3_13_2","doi-asserted-by":"publisher","DOI":"10.1177\/10556656231176904"},{"key":"e_1_3_3_14_2","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.c.31373"},{"key":"e_1_3_3_15_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.cps.2018.12.001"},{"key":"e_1_3_3_16_2","doi-asserted-by":"publisher","DOI":"10.1186\/1477-7525-2-55"},{"key":"e_1_3_3_17_2","doi-asserted-by":"publisher","DOI":"10.1111\/j.1600-0447.1983.tb09716.x"},{"key":"e_1_3_3_18_2","doi-asserted-by":"publisher","DOI":"10.2307\/2136404"},{"key":"e_1_3_3_19_2","unstructured":"Weathers FW Litz BT Keane TM. The PTSD Checklist for DSM-5 (PCL-5). Accessed July 5 2023. Available at: www.ptsd.va.gov"},{"key":"e_1_3_3_20_2","doi-asserted-by":"publisher","DOI":"10.1097\/00004583-200111000-00015"},{"key":"e_1_3_3_21_2","doi-asserted-by":"publisher","DOI":"10.1097\/00004703-200402000-00002"},{"key":"e_1_3_3_22_2","doi-asserted-by":"publisher","DOI":"10.1037\/\/0022-3514.67.6.1063"},{"key":"e_1_3_3_23_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.psychres.2007.01.006"},{"key":"e_1_3_3_24_2","doi-asserted-by":"publisher","DOI":"10.5324\/nje.v24i1-2.1821"},{"key":"e_1_3_3_25_2","doi-asserted-by":"publisher","DOI":"10.1007\/s11136-013-0422-9"},{"key":"e_1_3_3_26_2","doi-asserted-by":"publisher","DOI":"10.1348\/014466501163904"},{"key":"e_1_3_3_27_2","unstructured":"Cohen S. Perceived stress in a probability sample of the United States. In: Spacapan S. ed. The Social Psychology of Health. Thousand Oaks CA: Sage; 1988:31-67."},{"key":"e_1_3_3_28_2","doi-asserted-by":"publisher","DOI":"10.1192\/bjp.177.6.534"},{"key":"e_1_3_3_29_2","unstructured":"Cohen J. Statistical Power Analysis for the Behavioural Sciences. 2nd ed. Erlbaum. 1988."},{"key":"e_1_3_3_30_2","doi-asserted-by":"publisher","DOI":"10.1177\/1055665619862457"},{"key":"e_1_3_3_31_2","doi-asserted-by":"publisher","DOI":"10.1597\/14-062"},{"key":"e_1_3_3_32_2","doi-asserted-by":"publisher","DOI":"10.1111\/j.1469-7610.2008.01942.x"},{"key":"e_1_3_3_33_2","doi-asserted-by":"publisher","DOI":"10.1007\/s00127-016-1208-5"},{"key":"e_1_3_3_34_2","doi-asserted-by":"publisher","DOI":"10.1177\/10556656221102043"},{"key":"e_1_3_3_35_2","doi-asserted-by":"publisher","DOI":"10.1097\/SCS.0000000000003955"},{"key":"e_1_3_3_36_2","doi-asserted-by":"publisher","DOI":"10.1177\/10556656231219579"},{"key":"e_1_3_3_37_2","doi-asserted-by":"publisher","DOI":"10.1097\/SCS.0000000000008454"},{"key":"e_1_3_3_38_2","doi-asserted-by":"publisher","DOI":"10.1097\/NUR.0000000000000371"},{"key":"e_1_3_3_39_2","doi-asserted-by":"publisher","DOI":"10.1080\/01609513.2017.1333480"},{"key":"e_1_3_3_40_2","unstructured":"Article in preparation."},{"key":"e_1_3_3_41_2","doi-asserted-by":"publisher","DOI":"10.1177\/10556656241280071"},{"key":"e_1_3_3_42_2","doi-asserted-by":"publisher","DOI":"10.1097\/SCS.0000000000006033"},{"key":"e_1_3_3_43_2","doi-asserted-by":"publisher","DOI":"10.1097\/SCS.0000000000006691"},{"key":"e_1_3_3_44_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.jcms.2025.01.019"},{"key":"e_1_3_3_45_2","doi-asserted-by":"publisher","DOI":"10.1093\/jpepsy\/jsaf029"},{"key":"e_1_3_3_46_2","doi-asserted-by":"publisher","DOI":"10.1177\/1055665618770183"},{"key":"e_1_3_3_47_2","doi-asserted-by":"publisher","DOI":"10.3389\/fsurg.2021.690680"}],"container-title":["The Cleft Palate Craniofacial Journal"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/10556656261470559","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/full-xml\/10.1177\/10556656261470559","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/10556656261470559","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,7,30]],"date-time":"2026-07-30T21:46:23Z","timestamp":1785447983000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.sagepub.com\/doi\/10.1177\/10556656261470559"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2026,7,29]]},"references-count":46,"alternative-id":["10.1177\/10556656261470559"],"URL":"https:\/\/doi.org\/10.1177\/10556656261470559","relation":{},"ISSN":["1055-6656","1545-1569"],"issn-type":[{"value":"1055-6656","type":"print"},{"value":"1545-1569","type":"electronic"}],"subject":[],"published":{"date-parts":[[2026,7,29]]},"article-number":"10556656261470559"}}