{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,5,4]],"date-time":"2026-05-04T23:29:29Z","timestamp":1777937369285,"version":"3.51.4"},"reference-count":16,"publisher":"SAGE Publications","issue":"1","license":[{"start":{"date-parts":[[2017,2,1]],"date-time":"2017-02-01T00:00:00Z","timestamp":1485907200000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["Pediatr Dev Pathol"],"published-print":{"date-parts":[[2017,2]]},"abstract":"<jats:p>Abnormal muscularization of acinar arteries is the hallmark of persistent pulmonary hypertension of newborn (PPHN), an uncommon disease with high rate of morbidity and mortality. PPHN presents with signs of respiratory distress immediately following birth. We herein report 2 cases presenting as a witnessed sudden unexpected death in the late neonatal period, preceded by respiratory deterioration and in whom the presence of abnormal muscularization of the acinar pulmonary arteries was reminiscent of PPHN. The significance of this report is twofold: to increase the awareness among pediatricians and pathologists of this feature that can present in some cases of Sudden Unexpected Death in Infancy\/Sudden Infant Death Syndrome, and to highlight the importance of performing a thorough autopsy in order to identify the abnormality.<\/jats:p>","DOI":"10.1177\/1093526616689311","type":"journal-article","created":{"date-parts":[[2017,7,18]],"date-time":"2017-07-18T06:37:22Z","timestamp":1500359842000},"page":"49-53","update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":4,"title":["Abnormal Muscularization of Intra-acinar Pulmonary Arteries in Two Cases Presenting as Sudden Infant Death"],"prefix":"10.1177","volume":"20","author":[{"given":"Khairul","family":"Zainun","sequence":"first","affiliation":[{"name":"Department of Histopathology, Sheffield Children\u2019s Hospital Foundation Trust, Western Bank, Sheffield, UK"},{"name":"Department of Forensic Medicine, Hospital Sultanah Aminah, Johor Bharu, Johore, Malaysia"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Kirsten","family":"Hope","sequence":"additional","affiliation":[{"name":"Department of Histopathology, Sheffield Children\u2019s Hospital Foundation Trust, Western Bank, Sheffield, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Andrew G","family":"Nicholson","sequence":"additional","affiliation":[{"name":"Department of Histopathology, Royal Brompton and Harefield Hospitals NHS Foundation Trust, and National Heart and Lung Division, Imperial College, London, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Marta C","family":"Cohen","sequence":"additional","affiliation":[{"name":"Department of Histopathology, Sheffield Children\u2019s Hospital Foundation Trust, Western Bank, Sheffield, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"179","published-online":{"date-parts":[[2017,2,7]]},"reference":[{"key":"bibr1-1093526616689311","doi-asserted-by":"publisher","DOI":"10.1053\/j.semperi.2013.11.004"},{"key":"bibr2-1093526616689311","doi-asserted-by":"publisher","DOI":"10.2350\/07-12-0398.1"},{"key":"bibr3-1093526616689311","first-page":"187","volume-title":"Essentials of Surgical Pediatric Pathology","author":"Deutsch G","year":"2014"},{"key":"bibr4-1093526616689311","doi-asserted-by":"publisher","DOI":"10.1016\/S1084-2756(02)00195-1"},{"key":"bibr5-1093526616689311","first-page":"398","volume":"66","author":"Raine J","year":"1991","journal-title":"ADC"},{"key":"bibr6-1093526616689311","volume-title":"Sudden unexpected death in infancy. 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