{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,26]],"date-time":"2026-06-26T13:47:17Z","timestamp":1782481637929,"version":"3.54.5"},"reference-count":65,"publisher":"SAGE Publications","license":[{"start":{"date-parts":[[2026,6,23]],"date-time":"2026-06-23T00:00:00Z","timestamp":1782172800000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"},{"start":{"date-parts":[[2026,6,23]],"date-time":"2026-06-23T00:00:00Z","timestamp":1782172800000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"funder":[{"DOI":"10.13039\/100009633","name":"Eunice Kennedy Shriver National Institute of Child Health and Human Development","doi-asserted-by":"publisher","award":["P50HD103555"],"award-info":[{"award-number":["P50HD103555"]}],"id":[{"id":"10.13039\/100009633","id-type":"DOI","asserted-by":"publisher"}]},{"DOI":"10.13039\/100000025","name":"National Institute of Mental Health","doi-asserted-by":"publisher","award":["U54AR068069-S1"],"award-info":[{"award-number":["U54AR068069-S1"]}],"id":[{"id":"10.13039\/100000025","id-type":"DOI","asserted-by":"publisher"}]},{"DOI":"10.13039\/100000069","name":"National Institute of Arthritis and Musculoskeletal and Skin Diseases","doi-asserted-by":"publisher","award":["U54AR068069-S1"],"award-info":[{"award-number":["U54AR068069-S1"]}],"id":[{"id":"10.13039\/100000069","id-type":"DOI","asserted-by":"publisher"}]},{"DOI":"10.13039\/100006108","name":"national center for advancing translational sciences","doi-asserted-by":"publisher","award":["1U54AR068069-0"],"award-info":[{"award-number":["1U54AR068069-0"]}],"id":[{"id":"10.13039\/100006108","id-type":"DOI","asserted-by":"publisher"}]}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["J Health Psychol"],"abstract":"<jats:p>\n                    Osteogenesis Imperfecta (OI) is a rare disorder causing bone fragility, pain, and functional impairment that causes substantial psychosocial burden. This study examined how self-perceived burden (SPB), or distress from feelings of dependence on caregivers, relates to depression, anxiety, and suicidality in adults with OI. A total of 208 adults (\n                    <jats:italic toggle=\"yes\">M<\/jats:italic>\n                    age\u2009=\u200942.9, predominately White and female) with OI were recruited to complete a cross-sectional survey assessing SPB, psychological symptoms, health, and sociodemographics. Results indicated that SPB was significantly higher among younger individuals, those not living with a partner, those living with adult family members, lower-income groups, and individuals unable to work due to health-related concerns. SPB was positively associated with pain, disability, and worse global health scores, and independently predicted depressive and anxiety symptoms, but not suicidality. Findings suggest SPB contributes to mental health burden in OI and that addressing it may improve psychological outcomes and quality of life.\n                  <\/jats:p>","DOI":"10.1177\/13591053261460738","type":"journal-article","created":{"date-parts":[[2026,6,23]],"date-time":"2026-06-23T11:59:07Z","timestamp":1782215947000},"update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":0,"title":["Self-perceived burden and mental health outcomes in adults with osteogenesis imperfecta"],"prefix":"10.1177","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-3967-8500","authenticated-orcid":false,"given":"Emily R.","family":"Strouphauer","sequence":"first","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0009-0001-9540-044X","authenticated-orcid":false,"given":"Camille","family":"Villar","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Ryan J.","family":"McCarty","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"},{"name":"University of Florida, Gainesville, FL, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Danqi","family":"Li","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Gianna M.","family":"Colombo","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Brendan","family":"Lee","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"},{"name":"Texas Children\u2019s Hospital, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"name":"Members of the BBDC","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Chaya N.","family":"Murali","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"},{"name":"Texas Children\u2019s Hospital, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Dianne","family":"Nguyen","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Sarah","family":"Sadek","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Marie-Eve","family":"Robinson","sequence":"additional","affiliation":[{"name":"University of Ottawa, Canada"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Jocelyn","family":"Gomez","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"},{"name":"Texas Children\u2019s Hospital, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Michelle","family":"Fynan","sequence":"additional","affiliation":[{"name":"Osteogenesis Imperfecta (OI) Foundation, Gaithersburg, MD, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"V.","family":"Reid Sutton","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"},{"name":"Texas Children\u2019s Hospital, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Andrew D.","family":"Wiese","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-7631-3703","authenticated-orcid":false,"given":"Eric A.","family":"Storch","sequence":"additional","affiliation":[{"name":"Baylor College of Medicine, Houston, TX, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"179","published-online":{"date-parts":[[2026,6,23]]},"reference":[{"key":"e_1_3_2_2_1","doi-asserted-by":"crossref","unstructured":"Bogart KR (2014) The role of disability self-concept in adaptation to congenital or acquired disability. Rehabilitation Psychology 59(1): 107\u2013115. https:\/\/doi.org\/10.1037\/a0035800","DOI":"10.1037\/a0035800"},{"key":"e_1_3_2_3_1","doi-asserted-by":"crossref","unstructured":"Bowleg L (2012) The problem with the phrase women and minorities: Intersectionality-an important theoretical framework for public health. American Journal of Public Health 102(7): 1267\u20131273. https:\/\/doi.org\/10.2105\/AJPH.2012.300750","DOI":"10.2105\/AJPH.2012.300750"},{"key":"e_1_3_2_4_1","unstructured":"Brown RL Ciciurkaite G (2022) Chapter 12: Disability ableism and mental health. Available at: https:\/\/www.elgaronline.com\/edcollchap\/book\/9781800378483\/book-part-9781800378483-17.xml (accessed 20 June 2025)."},{"key":"e_1_3_2_5_1","doi-asserted-by":"crossref","unstructured":"Bruce B Fries JF (2003) The Stanford Health Assessment Questionnaire: Dimensions and practical applications. Health and Quality of Life Outcomes 1(1): 20. https:\/\/doi.org\/10.1186\/1477-7525-1-20","DOI":"10.1186\/1477-7525-1-20"},{"key":"e_1_3_2_6_1","unstructured":"Center on Budget and Policy Priorities (2011) Policy basics: Supplemental security income. Available at: https:\/\/www.cbpp.org\/research\/social-security\/supplemental-security-income (accessed 29 June 2025)."},{"key":"e_1_3_2_7_1","doi-asserted-by":"crossref","unstructured":"Chen X Wang Z Zhou J et al. (2023) The impact of self-perceived burden caregiver burden and dyadic coping on negative emotions in colorectal cancer patient-spousal caregiver dyads: A dyadic analysis. Frontiers in Psychology 14: 1238924. https:\/\/doi.org\/10.3389\/fpsyg.2023.1238924","DOI":"10.3389\/fpsyg.2023.1238924"},{"key":"e_1_3_2_8_1","doi-asserted-by":"crossref","unstructured":"Cho HE Shepherd WS Colombo GM et al. (2024) Resilience and coping: A qualitative analysis of cognitive and behavioral factors in adults with osteogenesis imperfecta. Disability and Rehabilitation 47: 709\u2013718. https:\/\/doi.org\/10.1080\/09638288.2024.2358903","DOI":"10.1080\/09638288.2024.2358903"},{"key":"e_1_3_2_9_1","doi-asserted-by":"crossref","unstructured":"Chu C Buchman-Schmitt JM Stanley IH et al. (2017) The interpersonal theory of suicide: A systematic review and meta-analysis of a decade of cross-national research. Psychological Bulletin 143(12): 1313\u20131345. https:\/\/doi.org\/10.1037\/bul0000123","DOI":"10.1037\/bul0000123"},{"key":"e_1_3_2_10_1","doi-asserted-by":"crossref","unstructured":"Conde-Sala JL Garre-Olmo J Turr\u00f3-Garriga O et al. (2010) Differential features of burden between spouse and adult-child caregivers of patients with Alzheimer\u2019s disease: An exploratory comparative design. International Journal of Nursing Studies 47(10): 1262\u20131273. https:\/\/doi.org\/10.1016\/j.ijnurstu.2010.03.001","DOI":"10.1016\/j.ijnurstu.2010.03.001"},{"key":"e_1_3_2_11_1","doi-asserted-by":"crossref","unstructured":"Cousineau N McDowell I Hotz S et al. (2003) Measuring chronic patients\u2019 feelings of being a burden to their caregivers: Development and preliminary validation of a scale. Medical Care 41(1): 110\u2013118. https:\/\/doi.org\/10.1097\/00005650-200301000-00013","DOI":"10.1097\/00005650-200301000-00013"},{"key":"e_1_3_2_12_1","doi-asserted-by":"crossref","unstructured":"Dahan-Oliel N Oliel S Tsimicalis A et al. (2016) Quality of life in osteogenesis imperfecta: A mixed-methods systematic review. American Journal of Medical Genetics Part A 170A(1): 62\u201376. https:\/\/doi.org\/10.1002\/ajmg.a.37377","DOI":"10.1002\/ajmg.a.37377"},{"key":"e_1_3_2_13_1","doi-asserted-by":"crossref","unstructured":"Deguchi M Tsuji S Katsura D et al. (2021) Current overview of osteogenesis imperfecta. Medicinar 57(5): 464. https:\/\/doi.org\/10.3390\/medicina57050464","DOI":"10.3390\/medicina57050464"},{"key":"e_1_3_2_14_1","doi-asserted-by":"crossref","unstructured":"Dempsey LE Karver MS Labouliere C et al. (2012) Self-perceived burden as a mediator of depression symptoms amongst individuals living with a movement disorder. Journal of Clinical Psychology 68(10): 1149\u20131160. https:\/\/doi.org\/10.1002\/jclp.21901","DOI":"10.1002\/jclp.21901"},{"key":"e_1_3_2_15_1","doi-asserted-by":"crossref","unstructured":"Dhingra SS Kroenke K Zack MM et al. (2011) PHQ-8 Days: A measurement option for DSM-5 major depressive disorder (MDD) severity. Population Health Metrics 9: 11. https:\/\/doi.org\/10.1186\/1478-7954-9-11","DOI":"10.1186\/1478-7954-9-11"},{"key":"e_1_3_2_16_1","doi-asserted-by":"crossref","unstructured":"Fishbain DA Bruns D Bruns A et al. (2016) The perception of being a burden in acute and chronic pain patients is associated with affirmation of different types of suicidality. Pain Medicine 17(3): 530\u2013538. https:\/\/doi.org\/10.1111\/pme.12889","DOI":"10.1111\/pme.12889"},{"key":"e_1_3_2_17_1","doi-asserted-by":"crossref","unstructured":"Ghosh S Choi WY Williams A et al. (2020) Burden on caregivers of adults with multiple chronic conditions: Intersectionality of age gender education level employment status and impact on social life. Canadian Journal on Aging\/La Revue canadienne du vieillissement 39(3): 456\u2013467. https:\/\/doi.org\/10.1017\/S071498081900045X","DOI":"10.1017\/S071498081900045X"},{"key":"e_1_3_2_18_1","doi-asserted-by":"crossref","unstructured":"Graham JW Olchowski AE Gilreath TD (2007) How many imputations are really needed? Some practical clarifications of multiple imputation theory. Prevention Science 8(3): 206\u2013213. https:\/\/doi.org\/10.1007\/s11121-007-0070-9","DOI":"10.1007\/s11121-007-0070-9"},{"key":"e_1_3_2_19_1","doi-asserted-by":"crossref","unstructured":"Hart T Westerheim I van Welzenis T et al. (2024) The IMPACT Survey: the economic impact of osteogenesis imperfecta in adults. Orphanet Journal of Rare Diseases 19(1): 222. https:\/\/doi.org\/10.1186\/s13023-024-03218-6","DOI":"10.1186\/s13023-024-03218-6"},{"key":"e_1_3_2_20_1","doi-asserted-by":"crossref","unstructured":"Hill M Hammond J Sharmin M et al. (2022) Living with osteogenesis imperfecta: A qualitative study exploring experiences and psychosocial impact from the perspective of patients parents and professionals. Disability and Health Journal 15(1): 101168. https:\/\/doi.org\/10.1016\/j.dhjo.2021.101168","DOI":"10.1016\/j.dhjo.2021.101168"},{"key":"e_1_3_2_21_1","doi-asserted-by":"crossref","unstructured":"Hill M Lewis C Riddington M et al. (2019) Exploring the impact of osteogenesis imperfecta on families: A mixed-methods systematic review. Disability and Health Journal 12(3): 340\u2013349. https:\/\/doi.org\/10.1016\/j.dhjo.2018.12.003","DOI":"10.1016\/j.dhjo.2018.12.003"},{"key":"e_1_3_2_22_1","doi-asserted-by":"crossref","unstructured":"Horowitz LM Bridge JA Teach SJ et al. (2012) Ask Suicide-Screening Questions (ASQ): A brief instrument for the pediatric emergency department. Archives of Pediatrics & Adolescent Medicine 166(12): 1170\u20131176. https:\/\/doi.org\/10.1001\/archpediatrics.2012.1276","DOI":"10.1001\/archpediatrics.2012.1276"},{"key":"e_1_3_2_23_1","doi-asserted-by":"crossref","unstructured":"Ilgen MA Zivin K Austin KL et al. (2010) Severe pain predicts greater likelihood of subsequent suicide. Suicide and Life-Threatening Behavior 40(6): 597\u2013608. https:\/\/doi.org\/10.1521\/suli.2010.40.6.597","DOI":"10.1521\/suli.2010.40.6.597"},{"key":"e_1_3_2_24_1","doi-asserted-by":"crossref","unstructured":"Jung J Mukherjee K Brown M et al. (2024) Association between financial hardship and psychological burden and the role of social and mental health support: An observational study. Medicine 103(28): e38871. https:\/\/doi.org\/10.1097\/MD.0000000000038871","DOI":"10.1097\/MD.0000000000038871"},{"key":"e_1_3_2_25_1","doi-asserted-by":"crossref","unstructured":"Kim AM Park JH (2024) Depression and its associated factors: A comparison between congenital and acquired physical disabilities. International Journal of Psychiatry in Medicine 59(6): 655\u2013669. https:\/\/doi.org\/10.1177\/00912174231219037","DOI":"10.1177\/00912174231219037"},{"key":"e_1_3_2_26_1","doi-asserted-by":"crossref","unstructured":"Kowal J Wilson KG McWilliams LA et al. (2012) Self-perceived burden in chronic pain: Relevance prevalence and predictors. Pain 153(8): 1735\u20131741. https:\/\/doi.org\/10.1016\/j.pain.2012.05.009","DOI":"10.1016\/j.pain.2012.05.009"},{"key":"e_1_3_2_27_1","doi-asserted-by":"crossref","unstructured":"Kroenke K Spitzer RL Williams JBW (2001) The PHQ-9. Journal of General Internal Medicine 16(9): 606\u2013613. https:\/\/doi.org\/10.1046\/j.1525-1497.2001.016009606.x","DOI":"10.1046\/j.1525-1497.2001.016009606.x"},{"key":"e_1_3_2_28_1","doi-asserted-by":"crossref","unstructured":"Lin J Su Y Lv X et al. (2020) Perceived stressfulness mediates the effects of subjective social support and negative coping style on suicide risk in Chinese patients with major depressive disorder. Journal of Affective Disorders 265: 32\u201338. https:\/\/doi.org\/10.1016\/j.jad.2020.01.026","DOI":"10.1016\/j.jad.2020.01.026"},{"key":"e_1_3_2_29_1","doi-asserted-by":"crossref","unstructured":"Liu B Lee K Sun C et al. (2022) Systematic review on factors associated with self-perceived burden among cancer patients. Supportive Care in Cancer 30(10): 8417\u20138428. https:\/\/doi.org\/10.1007\/s00520-022-07129-9","DOI":"10.1007\/s00520-022-07129-9"},{"key":"e_1_3_2_30_1","unstructured":"MedlinePlus Medical Encyclopedia (n.d.) Osteogenesis imperfecta. MedlinePlus Medical Encyclopedia. Available at: https:\/\/medlineplus.gov\/ency\/article\/001573.htm (accessed 7 January 2025)."},{"key":"e_1_3_2_31_1","doi-asserted-by":"crossref","unstructured":"Mournet AM Bower E Van Orden KA (2020) Domains of functional impairment and their associations with thwarted belonging and perceived burden in older adults. Clinical Gerontologist 43(1): 95\u2013103. https:\/\/doi.org\/10.1080\/07317115.2019.1650406","DOI":"10.1080\/07317115.2019.1650406"},{"key":"e_1_3_2_32_1","unstructured":"National HIV Curriculum (n.d) Generalized Anxiety Disorder 7-item (GAD-7) - Mental Health Screening. Available at: https:\/\/www.hiv.uw.edu\/page\/mental-health-screening\/gad-7 (accessed 30 May 2025)."},{"key":"e_1_3_2_33_1","unstructured":"National Institute of Mental Health (NIMH) (n.D) Ask Suicide-Screening Questions (ASQ) Toolkit. Available at: https:\/\/www.nimh.nih.gov\/research\/research-conducted-at-nimh\/asq-toolkit-materials (accessed 30 May 2025)."},{"key":"e_1_3_2_34_1","doi-asserted-by":"crossref","unstructured":"Nikbakht Nasrabadi A Pahlevan Sharif S Allen KA et al. (2022) The role of socioeconomic status in the relationship between social support and burden among cancer caregivers. European Journal of Cancer Prevention 31(2): 198\u2013203. https:\/\/doi.org\/10.1097\/CEJ.0000000000000683","DOI":"10.1097\/CEJ.0000000000000683"},{"key":"e_1_3_2_35_1","doi-asserted-by":"crossref","unstructured":"Oeki M Mogami T Hagino H (2012) Self-perceived burden in patients with cancer: Scale development and descriptive study. European Journal of Oncology Nursing 16(2): 145\u2013152. https:\/\/doi.org\/10.1016\/j.ejon.2011.04.010","DOI":"10.1016\/j.ejon.2011.04.010"},{"key":"e_1_3_2_36_1","doi-asserted-by":"crossref","unstructured":"Rapoport M Bober MB Raggio C et al. (2023) The patient clinical journey and socioeconomic impact of osteogenesis imperfecta: A systematic scoping review. Orphanet Journal of Rare Diseases 18: 34. https:\/\/doi.org\/10.1186\/s13023-023-02627-3","DOI":"10.1186\/s13023-023-02627-3"},{"key":"e_1_3_2_37_1","doi-asserted-by":"crossref","unstructured":"Rauch F Glorieux FH (2004) Osteogenesis imperfecta. Lancet 363(9418): 1377\u20131385. https:\/\/doi.org\/10.1016\/S0140-6736(04)16051-0","DOI":"10.1016\/S0140-6736(04)16051-0"},{"key":"e_1_3_2_38_1","doi-asserted-by":"crossref","unstructured":"Ren H Liu C Li J et al. (2016) Self-perceived burden in the young and middle-aged inpatients with stroke: A cross-sectional survey. Rehabilitation Nursing 41(2): 101\u2013111. https:\/\/doi.org\/10.1002\/rnj.193","DOI":"10.1002\/rnj.193"},{"key":"e_1_3_2_39_1","doi-asserted-by":"crossref","unstructured":"Rork WC Hertz AG Wiese AD et al. (2023) A qualitative exploration of patient perspectives on psychosocial burdens and positive factors in adults with osteogenesis imperfecta. American Journal of Medical Genetics Part A 191(9): 2267\u20132275. https:\/\/doi.org\/10.1002\/ajmg.a.63323","DOI":"10.1002\/ajmg.a.63323"},{"key":"e_1_3_2_40_1","doi-asserted-by":"crossref","unstructured":"Schindeler A Lee LR O'Donohue AK et al. (2022) Curative cell and gene therapy for Osteogenesis Imperfecta. Journal of Bone and Mineral Research 37(5): 826\u2013836. https:\/\/doi.org\/10.1002\/jbmr.4549","DOI":"10.1002\/jbmr.4549"},{"key":"e_1_3_2_41_1","doi-asserted-by":"crossref","unstructured":"Shepherd WS Wiese AD Cho HE et al. (2024) Psychosocial outcomes of pain and pain management in adults with osteogenesis imperfecta: A Qualitative Study. Journal of Clinical Psychology in Medical Settings 31(3): 614\u2013627. https:\/\/doi.org\/10.1007\/s10880-023-09991-z","DOI":"10.1007\/s10880-023-09991-z"},{"key":"e_1_3_2_42_1","doi-asserted-by":"crossref","unstructured":"Shih CA Li CC Chang YF et al. (2024) Demographics and medical burden of osteogenesis imperfecta: A nationwide database analysis. Osteoporosis International 35(7): 1185\u20131193. https:\/\/doi.org\/10.1007\/s00198-024-07051-2","DOI":"10.1007\/s00198-024-07051-2"},{"key":"e_1_3_2_43_1","doi-asserted-by":"crossref","unstructured":"Shindi J (1983) Emotional adjustment of physically handicapped children: A comparison of children with congenital and acquired orthopaedic disabilities. International Journal of Social Psychiatry 29(4): 292\u2013298. https:\/\/doi.org\/10.1177\/002076408302900409","DOI":"10.1177\/002076408302900409"},{"key":"e_1_3_2_44_1","doi-asserted-by":"crossref","unstructured":"Simmons LA (2007) Self-perceived burden in cancer patients: Validation of the self-perceived burden scale. Cancer Nursing 30(5): 405\u2013411. https:\/\/doi.org\/10.1097\/01.NCC.0000290816.37442.af","DOI":"10.1097\/01.NCC.0000290816.37442.af"},{"key":"e_1_3_2_45_1","doi-asserted-by":"crossref","unstructured":"Spitzer RL Kroenke K Williams JB et al. (2006) A brief measure for assessing generalized anxiety disorder: The GAD-7. Archive of Internal Medicine 166(10): 1092\u20131097. https:\/\/doi.org\/10.1001\/archinte.166.10.1092","DOI":"10.1001\/archinte.166.10.1092"},{"key":"e_1_3_2_46_1","doi-asserted-by":"crossref","unstructured":"Stoddard-Dare P DeRigne L Collins CC et al. (2018) Paid sick leave and psychological distress: An analysis of U.S. workers. American Journal of Orthopsychiatry 88(1): 1\u20139. https:\/\/doi.org\/10.1037\/ort0000293","DOI":"10.1037\/ort0000293"},{"key":"e_1_3_2_47_1","doi-asserted-by":"crossref","unstructured":"Storoni S Treurniet S Maugeri A et al. (2022) Prevalence and hospital admissions in patients with osteogenesis imperfecta in the Netherlands: A Nationwide Registry Study. Frontiers in Endocrinology 13: 869604. https:\/\/doi.org\/10.3389\/fendo.2022.869604","DOI":"10.3389\/fendo.2022.869604"},{"key":"e_1_3_2_48_1","unstructured":"Subramanian S Anastasopoulou C Viswanathan VK (2024) Osteogenesis Imperfecta. StatPearls Publishing. Available at: http:\/\/www.ncbi.nlm.nih.gov\/books\/NBK536957\/ (accessed 26 December 2024)."},{"key":"e_1_3_2_49_1","doi-asserted-by":"crossref","unstructured":"Tauer JT Robinson ME Rauch F (2019) Osteogenesis imperfecta: New perspectives from clinical and translational research. JBMR plus 3(8): e10174. https:\/\/doi.org\/10.1002\/jbm4.10174","DOI":"10.1002\/jbm4.10174"},{"key":"e_1_3_2_50_1","doi-asserted-by":"crossref","unstructured":"Teismann T Brailovskaia J Robison M et al. (2023) Self-burdensomeness other-burdensomeness and suicidal ideation. Behaviour Research and Therapy 169: 104388. https:\/\/doi.org\/10.1016\/j.brat.2023.104388","DOI":"10.1016\/j.brat.2023.104388"},{"key":"e_1_3_2_51_1","doi-asserted-by":"crossref","unstructured":"Ting CY Teh GC Yu KL et al. (2020) Self-perceived burden and its associations with health-related quality of life among urologic cancer patients. European Journal of Cancer Care 29(4): e13248. https:\/\/doi.org\/10.1111\/ecc.13248","DOI":"10.1111\/ecc.13248"},{"key":"e_1_3_2_52_1","doi-asserted-by":"crossref","unstructured":"Tosi LL Oetgen ME Floor MK et al. (2015) Initial report of the osteogenesis imperfecta adult natural history initiative. Orphanet Journal of Rare Diseases 10: 146. https:\/\/doi.org\/10.1186\/s13023-015-0362-2","DOI":"10.1186\/s13023-015-0362-2"},{"key":"e_1_3_2_53_1","doi-asserted-by":"crossref","unstructured":"Tsimicalis A Denis-Larocque G Michalovic A et al. (2016) The psychosocial experience of individuals living with osteogenesis imperfecta: A mixed-methods systematic review. Quality of Life Research 25(8): 1877\u20131896. https:\/\/doi.org\/10.1007\/s11136-016-1247-0","DOI":"10.1007\/s11136-016-1247-0"},{"key":"e_1_3_2_54_1","doi-asserted-by":"crossref","unstructured":"Wang K Ostrove JM Manning RB et al. (2024a) Ableism in mental healthcare settings: A qualitative study among U.S. adults with disabilities. SSM\u2013Qualitative Research in Health 6: 100498. https:\/\/doi.org\/10.1016\/j.ssmqr.2024.100498","DOI":"10.1016\/j.ssmqr.2024.100498"},{"key":"e_1_3_2_55_1","doi-asserted-by":"crossref","unstructured":"Wang L Peng R Xie W et al. (2025) Path analysis of social support and self-efficacy on self-perceived burden in patients with newly diagnosed diabetes mellitus. Journal of Clinical Nursing 34: 5306\u20135314. https:\/\/doi.org\/10.1111\/jocn.17788[Preprint].","DOI":"10.1111\/jocn.17788"},{"key":"e_1_3_2_56_1","doi-asserted-by":"crossref","unstructured":"Wang X Li Y Zhong Y et al. (2024b) Home care needs assessment among caregivers of children and adolescents with osteogenesis imperfecta: A cross-sectional study. BMC Primary Care 25(1): 119. https:\/\/doi.org\/10.1186\/s12875-024-02367-8","DOI":"10.1186\/s12875-024-02367-8"},{"key":"e_1_3_2_57_1","doi-asserted-by":"crossref","unstructured":"Wehrli S Rohrbach M Landolt MA (2023) Quality of life of pediatric and adult individuals with osteogenesis imperfecta: A meta-analysis. Orphanet Journal of Rare Diseases 18(1): 123. https:\/\/doi.org\/10.1186\/s13023-023-02728-z","DOI":"10.1186\/s13023-023-02728-z"},{"key":"e_1_3_2_58_1","doi-asserted-by":"crossref","unstructured":"Westerheim I Hart T van Welzenis T et al. (2024) The IMPACT survey: A mixed methods study to understand the experience of children adolescents and adults with osteogenesis imperfecta and their caregivers. Orphanet Journal of Rare Diseases 19(1): 128. https:\/\/doi.org\/10.1186\/s13023-024-03126-9","DOI":"10.1186\/s13023-024-03126-9"},{"key":"e_1_3_2_59_1","doi-asserted-by":"crossref","unstructured":"White IR Royston P Wood AM (2011) Multiple imputation using chained equations: Issues and guidance for practice. Statistics in Medicine 30(4): 377\u2013399. https:\/\/doi.org\/10.1002\/sim.4067","DOI":"10.1002\/sim.4067"},{"key":"e_1_3_2_60_1","doi-asserted-by":"crossref","unstructured":"Wilson KG Chochinov HM McPherson CJ et al. (2007a) Desire for euthanasia or physician-assisted suicide in palliative cancer care. Health Psychology 26(3): 314\u2013323. https:\/\/doi.org\/10.1037\/0278-6133.26.3.314","DOI":"10.1037\/0278-6133.26.3.314"},{"key":"e_1_3_2_61_1","doi-asserted-by":"crossref","unstructured":"Wilson KG Chochinov HM Skirko MG et al. (2007b) Depression and anxiety disorders in palliative cancer care. Journal of Pain and Symptom Management 33(2): 118\u2013129. https:\/\/doi.org\/10.1016\/j.jpainsymman.2006.07.016","DOI":"10.1016\/j.jpainsymman.2006.07.016"},{"key":"e_1_3_2_62_1","doi-asserted-by":"crossref","unstructured":"Wilson KG Kowal J Caird SM et al. (2017) Self-perceived burden perceived burdensomeness and suicidal ideation in patients with chronic pain. Canadian Journal of Pain 1(1): 127\u2013136. https:\/\/doi.org\/10.1080\/24740527.2017.1368009","DOI":"10.1080\/24740527.2017.1368009"},{"key":"e_1_3_2_63_1","doi-asserted-by":"crossref","unstructured":"Wilson KG Scott JF Graham ID et al. (2000) Attitudes of terminally ill patients toward euthanasia and physician-assisted suicide. Archive of Internal Medicine 160(16): 2454\u20132460. https:\/\/doi.org\/10.1001\/archinte.160.16.2454","DOI":"10.1001\/archinte.160.16.2454"},{"key":"e_1_3_2_64_1","doi-asserted-by":"crossref","unstructured":"Xiaodan L Guiru X Guojuan C et al. (2022) Self-perceived burden predicts lower quality of life in advanced cancer patients: The mediating role of existential distress and anxiety. BMC Geriatrics 22(1): 803. https:\/\/doi.org\/10.1186\/s12877-022-03494-6","DOI":"10.1186\/s12877-022-03494-6"},{"key":"e_1_3_2_65_1","doi-asserted-by":"crossref","unstructured":"Yu J Goldstein RB Haynie DL et al. (2021) Resilience factors in the association between depressive symptoms and suicidality. Journal of Adolescent Health 69(2): 280\u2013287. https:\/\/doi.org\/10.1016\/j.jadohealth.2020.12.004","DOI":"10.1016\/j.jadohealth.2020.12.004"},{"key":"e_1_3_2_66_1","doi-asserted-by":"crossref","unstructured":"Zhang W Hong S Takeuchi DT et al. (2012) Limited English proficiency and psychological distress among Latinos and Asian Americans. Social Science & Medicine 75(6): 1006\u20131014. https:\/\/doi.org\/10.1016\/j.socscimed.2012.05.012","DOI":"10.1016\/j.socscimed.2012.05.012"}],"container-title":["Journal of Health Psychology"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/13591053261460738","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/full-xml\/10.1177\/13591053261460738","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/13591053261460738","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,6,26]],"date-time":"2026-06-26T12:56:44Z","timestamp":1782478604000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.sagepub.com\/doi\/10.1177\/13591053261460738"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2026,6,23]]},"references-count":65,"alternative-id":["10.1177\/13591053261460738"],"URL":"https:\/\/doi.org\/10.1177\/13591053261460738","relation":{},"ISSN":["1359-1053","1461-7277"],"issn-type":[{"value":"1359-1053","type":"print"},{"value":"1461-7277","type":"electronic"}],"subject":[],"published":{"date-parts":[[2026,6,23]]},"article-number":"13591053261460738"}}