{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,19]],"date-time":"2026-06-19T07:54:53Z","timestamp":1781855693861,"version":"3.54.5"},"reference-count":12,"publisher":"SAGE Publications","issue":"6","license":[{"start":{"date-parts":[[2025,12,26]],"date-time":"2025-12-26T00:00:00Z","timestamp":1766707200000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["Hand (New York, N,Y.)"],"published-print":{"date-parts":[[2026,7]]},"abstract":"<jats:p>Preaxial polydactyly (PPD) is characterized by a supernumerary finger or duplication of digital parts on the radial aspect of the thumb. There is a wide phenotypic variety among presentations of PPD. Numerous classification systems have been created to categorize these phenotypes. Here, we present a rare case of PPD that does not fit into any of the known classification systems. The patient was born with a large nonosseous PPD. The patient was treated successfully with sharp excision, and pathology confirmed the diagnosis of a soft-tissue-only supernumerary digit containing unique features of vascular proliferation and subepidermal bullae. While this case is the only one of its kind, similar cases have been reported in the recent literature. Therefore, we should consider implementing this PPD phenotype into a classification system to guide patient counseling, clinical decision-making, and management.<\/jats:p>","DOI":"10.1177\/15589447251404958","type":"journal-article","created":{"date-parts":[[2025,12,26]],"date-time":"2025-12-26T09:11:11Z","timestamp":1766740271000},"update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":0,"title":["Large Nonosseous Preaxial Polydactyly: Unique Case With Vascular Proliferation and Subepidermal Bullae"],"prefix":"10.1177","volume":"21","author":[{"ORCID":"https:\/\/orcid.org\/0009-0002-2264-6032","authenticated-orcid":false,"given":"Hunter Myles","family":"Rogoff","sequence":"first","affiliation":[{"name":"Department of Plastic and Reconstructive Surgery, Geisinger Medical Center, Danville, PA, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"John Paul","family":"Prodoehl","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Geisinger Medical Center, Danville, PA, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Katie","family":"Lee","sequence":"additional","affiliation":[{"name":"Geisinger Commonwealth School of Medicine, Geisinger Health System, Scranton, PA, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Liping","family":"Li","sequence":"additional","affiliation":[{"name":"Department of Clinical and Laboratory Pathology, Geisinger Medical Center, Danville, PA, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Christian A.","family":"Kauffman","sequence":"additional","affiliation":[{"name":"Department of Plastic and Reconstructive Surgery, Geisinger Medical Center, Danville, PA, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"179","published-online":{"date-parts":[[2025,12,26]]},"reference":[{"key":"e_1_3_3_2_2","doi-asserted-by":"publisher","DOI":"10.1111\/cge.12276"},{"key":"e_1_3_3_3_2","doi-asserted-by":"publisher","DOI":"10.3389\/fgene.2018.00447"},{"key":"e_1_3_3_4_2","unstructured":"Al Amin ASM Carter KR. Polydactyly. StatPearls Publishing; 2023. Accessed August 8 2023. https:\/\/www.ncbi.nlm.nih.gov\/books\/NBK562295\/"},{"key":"e_1_3_3_5_2","doi-asserted-by":"publisher","DOI":"10.2174\/1573396314666180124102012"},{"key":"e_1_3_3_6_2","first-page":"175","article-title":"The results of surgery for polydactyly of the thumb. A review","volume":"64","author":"Wassel HD","year":"1969","unstructured":"Wassel HD. The results of surgery for polydactyly of the thumb. A review. Clin Orthop Relat Res. 1969;64:175-193.","journal-title":"Clin Orthop Relat Res"},{"key":"e_1_3_3_7_2","first-page":"1","article-title":"The genetics of hand malformations","volume":"14","author":"Temtamy SA","year":"1978","unstructured":"Temtamy SA, McKusick VA. The genetics of hand malformations. Birth Defects Orig Artic Ser. 1978;14:1-28.","journal-title":"Birth Defects Orig Artic Ser"},{"key":"e_1_3_3_8_2","doi-asserted-by":"publisher","DOI":"10.4055\/cios.2012.4.1.1"},{"key":"e_1_3_3_9_2","doi-asserted-by":"publisher","DOI":"10.1097\/00006534-198907000-00026"},{"key":"e_1_3_3_10_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.ijscr.2024.110090"},{"key":"e_1_3_3_11_2","doi-asserted-by":"publisher","DOI":"10.1142\/S0218810411005138"},{"key":"e_1_3_3_12_2","doi-asserted-by":"publisher","DOI":"10.1136\/bcr-2018-228183"},{"key":"e_1_3_3_13_2","doi-asserted-by":"publisher","DOI":"10.1046\/j.1525-1470.2003.20202.x"}],"container-title":["HAND"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/15589447251404958","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/full-xml\/10.1177\/15589447251404958","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/15589447251404958","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,6,19]],"date-time":"2026-06-19T07:46:38Z","timestamp":1781855198000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.sagepub.com\/doi\/10.1177\/15589447251404958"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2025,12,26]]},"references-count":12,"journal-issue":{"issue":"6","published-print":{"date-parts":[[2026,7]]}},"alternative-id":["10.1177\/15589447251404958"],"URL":"https:\/\/doi.org\/10.1177\/15589447251404958","relation":{},"ISSN":["1558-9447","1558-9455"],"issn-type":[{"value":"1558-9447","type":"print"},{"value":"1558-9455","type":"electronic"}],"subject":[],"published":{"date-parts":[[2025,12,26]]}}}