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We describe a case of a young child with HHT who presented with acute paraparesis due to acute thrombosis of a spinal perimedullary arteriovenous fistula. Patient underwent coil embolization of spinal arteriovenous shunt with resolution of clinical symptoms. This case highlights the possibility of catastrophic complications in young children with HHT, the potential preventive role of screening for spinal AVMs in HHT and the importance of timely intervention.<\/jats:p>","DOI":"10.1177\/15910199211022499","type":"journal-article","created":{"date-parts":[[2021,5,29]],"date-time":"2021-05-29T16:30:45Z","timestamp":1622305845000},"page":"132-135","update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":1,"title":["Acute thrombosis of a giant perimedullary arteriovenous fistula in a pediatric HHT patient"],"prefix":"10.1177","volume":"28","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-6330-0375","authenticated-orcid":false,"given":"Janaki","family":"Devara","sequence":"first","affiliation":[{"name":"Division of Pediatric Pulmonology, Mayo Clinic, Rochester, MN, USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Vivek 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