{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,5,4]],"date-time":"2026-05-04T07:01:46Z","timestamp":1777878106928,"version":"3.51.4"},"reference-count":25,"publisher":"SAGE Publications","license":[{"start":{"date-parts":[[2026,2,21]],"date-time":"2026-02-21T00:00:00Z","timestamp":1771632000000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by-nc\/4.0\/"},{"start":{"date-parts":[[2026,2,21]],"date-time":"2026-02-21T00:00:00Z","timestamp":1771632000000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["Rare Tumors"],"published-print":{"date-parts":[[2026,3]]},"abstract":"<jats:sec>\n                    <jats:title>Background<\/jats:title>\n                    <jats:p>M\u00fcllerian adenosarcoma is an uncommon mixed epithelial\u2013mesenchymal neoplasm that predominantly develops in the uterine corpus and rarely occurs in extrauterine sites, including the ovary. Ovarian adenosarcoma is associated with a more aggressive course and is often linked to endometriosis.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Case presentation<\/jats:title>\n                    <jats:p>We present the case of a nulliparous woman in her early 30s who presented with abdominal bloating, pelvic pain, and significant ascites. Imaging studies revealed bilateral adnexal solid\u2013cystic masses. Histopathologic and immunohistochemical (IHC) evaluation of the resected specimens demonstrated M\u00fcllerian adenosarcoma involving both adnexa and peritoneal surfaces, likely arising from endometriosis.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion<\/jats:title>\n                    <jats:p>This case highlights the diagnostic difficulty of extrauterine M\u00fcllerian adenosarcoma, particularly when presenting as bilateral adnexal M\u00fcllerian adenosarcoma with peritoneal involvement arising in the setting of endometriosis. Detailed histopathologic evaluation is essential, especially when glandular elements show mucinous differentiation, which broadens the differential diagnosis.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.1177\/20363613261426718","type":"journal-article","created":{"date-parts":[[2026,2,21]],"date-time":"2026-02-21T10:18:37Z","timestamp":1771669117000},"update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":0,"title":["A rare case of bilateral adnexal M\u00fcllerian adenosarcoma arising from endometriosis: A case report and literature review"],"prefix":"10.1177","volume":"18","author":[{"given":"Firouze","family":"Jafari","sequence":"first","affiliation":[{"name":"Shiraz University of Medical Sciences"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Mojgan","family":"Akbarzadeh Jahromi","sequence":"additional","affiliation":[{"name":"Shiraz University of Medical Sciences"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Saeed","family":"Askari","sequence":"additional","affiliation":[{"name":"Shiraz University of Medical Sciences"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-9868-082X","authenticated-orcid":false,"given":"Elham","family":"EntezarAlmahdi","sequence":"additional","affiliation":[{"name":"Shiraz University of Medical Sciences"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"179","published-online":{"date-parts":[[2026,2,21]]},"reference":[{"key":"e_1_3_9_2_2","doi-asserted-by":"publisher","DOI":"10.1097\/PGP.0000000000000997"},{"key":"e_1_3_9_3_2","doi-asserted-by":"publisher","DOI":"10.1097\/PAP.0b013e3181cfe732"},{"key":"e_1_3_9_4_2","doi-asserted-by":"publisher","DOI":"10.1002\/1097-0142(197410)34:4<1138::AID-CNCR2820340425>3.0.CO;2-9"},{"key":"e_1_3_9_5_2","doi-asserted-by":"publisher","DOI":"10.1097\/00004347-200104000-00004"},{"key":"e_1_3_9_6_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.pathol.2017.10.006"},{"key":"e_1_3_9_7_2","doi-asserted-by":"publisher","DOI":"10.1038\/nrendo.2013.255"},{"key":"e_1_3_9_8_2","doi-asserted-by":"publisher","DOI":"10.1056\/NEJMoa1614814"},{"key":"e_1_3_9_9_2","doi-asserted-by":"publisher","DOI":"10.1111\/j.1479-828X.2008.00914.x"},{"key":"e_1_3_9_10_2","doi-asserted-by":"publisher","DOI":"10.1097\/00000478-200210000-00001"},{"key":"e_1_3_9_11_2","doi-asserted-by":"publisher","DOI":"10.1186\/s12885-018-4037-y"},{"key":"e_1_3_9_12_2","doi-asserted-by":"publisher","DOI":"10.1016\/j.ygyno.2016.10.013"},{"key":"e_1_3_9_13_2","doi-asserted-by":"publisher","DOI":"10.1001\/archsurg.1925.01120100007001"},{"key":"e_1_3_9_14_2","doi-asserted-by":"publisher","DOI":"10.1002\/1097-0142(19810715)48:2<354::AID-CNCR2820480222>3.0.CO;2-Q"},{"key":"e_1_3_9_15_2","doi-asserted-by":"publisher","DOI":"10.7453\/gahmj.2013.008"},{"key":"e_1_3_9_16_2","doi-asserted-by":"publisher","DOI":"10.1053\/hp.2000.6712"},{"key":"e_1_3_9_17_2","doi-asserted-by":"publisher","DOI":"10.1097\/00000478-200004000-00005"},{"key":"e_1_3_9_18_2","doi-asserted-by":"publisher","DOI":"10.21037\/gpm-23-33"},{"key":"e_1_3_9_19_2","first-page":"284","article-title":"Primary ovarian adenosarcoma with elevated Ca-125 levels and normal ascitic fluid cytology: a case report and review of literature","volume":"6","author":"Shakuntala P","year":"2012","unstructured":"Shakuntala P, Umadevi K, Usha A, et al. Primary ovarian adenosarcoma with elevated Ca-125 levels and normal ascitic fluid cytology: a case report and review of literature. Ecancermedicalscience 2012; 6: 284.","journal-title":"Ecancermedicalscience"},{"key":"e_1_3_9_20_2","doi-asserted-by":"publisher","DOI":"10.1016\/0020-7292(94)02267-3"},{"key":"e_1_3_9_21_2","doi-asserted-by":"publisher","DOI":"10.1097\/01.AOG.0000192550.19403.0f"},{"key":"e_1_3_9_22_2","doi-asserted-by":"publisher","DOI":"10.1006\/gyno.2000.5905"},{"issue":"2","key":"e_1_3_9_23_2","first-page":"361","article-title":"Extrauterine M\u00fcllerian adenosarcoma associated with endometriosis and rectal villotubular adenoma: report of a case and review of the literature","volume":"15","author":"Chang H-Y","year":"2005","unstructured":"Chang H-Y, Changchien C-C, Chen H-H, et al. Extrauterine M\u00fcllerian adenosarcoma associated with endometriosis and rectal villotubular adenoma: report of a case and review of the literature. International Journal of Gynecologic Cancer 2005; 15(2): 361\u2013365.","journal-title":"International Journal of Gynecologic Cancer"},{"key":"e_1_3_9_24_2","doi-asserted-by":"publisher","DOI":"10.3346\/jkms.1998.13.6.680"},{"key":"e_1_3_9_25_2","doi-asserted-by":"publisher","DOI":"10.1097\/PAS.0b013e318161d1be"},{"key":"e_1_3_9_26_2","doi-asserted-by":"publisher","DOI":"10.1097\/PAS.0b013e318181a80d"}],"container-title":["Rare Tumors"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/20363613261426718","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/full-xml\/10.1177\/20363613261426718","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/20363613261426718","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,4,30]],"date-time":"2026-04-30T23:12:00Z","timestamp":1777590720000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.sagepub.com\/doi\/10.1177\/20363613261426718"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2026,2,21]]},"references-count":25,"alternative-id":["10.1177\/20363613261426718"],"URL":"https:\/\/doi.org\/10.1177\/20363613261426718","relation":{},"ISSN":["2036-3613","2036-3613"],"issn-type":[{"value":"2036-3613","type":"print"},{"value":"2036-3613","type":"electronic"}],"subject":[],"published":{"date-parts":[[2026,2,21]]},"article-number":"20363613261426718"}}