{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,18]],"date-time":"2026-08-18T02:17:57Z","timestamp":1787019477296,"version":"build-2736575974"},"reference-count":10,"publisher":"SAGE Publications","issue":"1","license":[{"start":{"date-parts":[[2015,2,10]],"date-time":"2015-02-10T00:00:00Z","timestamp":1423526400000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["Child Neurology Open"],"published-print":{"date-parts":[[2015,3,1]]},"abstract":"<jats:p>Arthrogryposis multiplex congenita is a syndromic condition defined by contracture of 2 or more joints. A large range of etiologies has been reported such as neuromuscular disorders (peripheral dysfunction), chromosomal abnormalities, or cerebral malformations (central dysfunction) leading to fetal immobility. Severity of arthrogryposis depends on the etiology and duration of fetal immobility. The authors report a 34 gestational weeks infant presenting with severe diffuse arthrogryposis symptoms and respiratory failure at birth. Her mother experienced cardiac arrest at 29 gestational weeks due to carbon monoxide intoxication. Fetal magnetic resonance imaging revealed extensive corticospinal tract lesions. Antenatal ischemia of the deep gray matter needs to be considered as a possible arthrogryposis cause.<\/jats:p>","DOI":"10.1177\/2329048x14567532","type":"journal-article","created":{"date-parts":[[2015,2,10]],"date-time":"2015-02-10T22:02:18Z","timestamp":1423605738000},"update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":2,"title":["Arthrogryposis Multiplex Congenita Related to Third-Trimester Basal Ganglia Ischemia"],"prefix":"10.1177","volume":"2","author":[{"given":"Perrine","family":"Venot","sequence":"first","affiliation":[{"name":"Neonatal Intensive Care Unit, Institut Alix de Champagne, Reims, France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Philippe","family":"Vo Van","sequence":"additional","affiliation":[{"name":"Neonatal Intensive Care Unit, Institut Alix de Champagne, Reims, France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Gratiella","family":"Mac Caby","sequence":"additional","affiliation":[{"name":"Department of Pediatric Radiology, H\u00f4pital Robert Debr\u00e9, Reims, France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Gauthier","family":"Loron","sequence":"additional","affiliation":[{"name":"Neonatal Intensive Care Unit, Institut Alix de Champagne, Reims, France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Jean Paul","family":"Bory","sequence":"additional","affiliation":[{"name":"Department of Obstetrics and Gynecology, Institut Alix de Champagne, Reims, France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Ahmad","family":"Akhavi","sequence":"additional","affiliation":[{"name":"Neonatal Intensive Care Unit, Institut Alix de Champagne, Reims, France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Nathalie","family":"Bednarek","sequence":"additional","affiliation":[{"name":"Neonatal Intensive Care Unit, Institut Alix de Champagne, Reims, France"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"179","published-online":{"date-parts":[[2015,2,10]]},"reference":[{"key":"bibr1-2329048X14567532","volume-title":"Neurology of the Newborn","author":"Volpe JJ.","year":"2008"},{"key":"bibr2-2329048X14567532","doi-asserted-by":"publisher","DOI":"10.5402\/2012\/264918"},{"key":"bibr3-2329048X14567532","doi-asserted-by":"publisher","DOI":"10.1007\/978-3-642-18747-6"},{"key":"bibr4-2329048X14567532","doi-asserted-by":"publisher","DOI":"10.1055\/s-2001-12222"},{"key":"bibr5-2329048X14567532","doi-asserted-by":"publisher","DOI":"10.1067\/mpd.2002.121148"},{"key":"bibr6-2329048X14567532","doi-asserted-by":"publisher","DOI":"10.1055\/s-2008-1073045"},{"key":"bibr7-2329048X14567532","doi-asserted-by":"publisher","DOI":"10.1016\/j.jns.2007.06.037"},{"key":"bibr8-2329048X14567532","doi-asserted-by":"publisher","DOI":"10.1016\/j.jgyn.2013.03.002"},{"issue":"3","key":"bibr9-2329048X14567532","first-page":"427","volume":"16","author":"Barkovich AJ","year":"1995","journal-title":"AJNR Am J Neuroradiol"},{"key":"bibr10-2329048X14567532","doi-asserted-by":"publisher","DOI":"10.1053\/crad.1999.0369"}],"container-title":["Child Neurology Open"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/2329048X14567532","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/full-xml\/10.1177\/2329048X14567532","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.1177\/2329048X14567532","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,4,28]],"date-time":"2026-04-28T15:57:32Z","timestamp":1777391852000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.sagepub.com\/doi\/10.1177\/2329048X14567532"}},"subtitle":["A Case Report"],"short-title":[],"issued":{"date-parts":[[2015,2,10]]},"references-count":10,"journal-issue":{"issue":"1","published-print":{"date-parts":[[2015,3,1]]}},"alternative-id":["10.1177\/2329048X14567532"],"URL":"https:\/\/doi.org\/10.1177\/2329048x14567532","relation":{},"ISSN":["2329-048X","2329-048X"],"issn-type":[{"value":"2329-048X","type":"print"},{"value":"2329-048X","type":"electronic"}],"subject":[],"published":{"date-parts":[[2015,2,10]]},"article-number":"2329048X14567532"}}