{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,2,21]],"date-time":"2025-02-21T10:57:59Z","timestamp":1740135479502,"version":"3.37.3"},"reference-count":14,"publisher":"Springer Science and Business Media LLC","issue":"1","license":[{"start":{"date-parts":[[2021,2,25]],"date-time":"2021-02-25T00:00:00Z","timestamp":1614211200000},"content-version":"tdm","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"},{"start":{"date-parts":[[2021,2,25]],"date-time":"2021-02-25T00:00:00Z","timestamp":1614211200000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":["link.springer.com"],"crossmark-restriction":false},"short-container-title":["BMC Endocr Disord"],"published-print":{"date-parts":[[2021,12]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:sec>\n                <jats:title>Background<\/jats:title>\n                <jats:p>Multiple endocrine neoplasia type 1 (MEN1) is a rare inherited syndrome that concurrently involves various endocrine glands. We report a rare case of MEN1 in a 43-year-old man whose first manifestation was an asymptomatic mediastinal mass.<\/jats:p>\n              <\/jats:sec><jats:sec>\n                <jats:title>Case presentation<\/jats:title>\n                <jats:p>A 13-cm-sized mediastinal mass was diagnosed as an atypical thymic carcinoid by computed tomography and percutaneous needle biopsy. In addition, hypercalcemia from a left inferior parathyroid hyperplasia, and a non-functioning gastric neuroendocrine tumor seen on esophagogastroduodenoscopy were found. Therefore, the patient was clinically diagnosed with MEN1 syndrome, and underwent surgical resection of thymic carcinoid tumor after pre-operative concurrent chemoradiation therapy to decrease tumor size and volume. Parathyroid lesion and gastric neuroendocrine tumor were also removed. Finally, a <jats:italic>MEN1<\/jats:italic> gene mutation was observed in the patient and his 7-year-old son.<\/jats:p>\n              <\/jats:sec><jats:sec>\n                <jats:title>Conclusion<\/jats:title>\n                <jats:p>Despite its rare occurrence, thymic carcinoid tumor should be considered as a MEN1-associated tumor and necessitates screening of other endocrine glands. Thymic carcinoid tumor carries a poor prognosis in patients with MEN1, and thus it needs to be carefully monitored even after radical excision.<\/jats:p>\n              <\/jats:sec>","DOI":"10.1186\/s12902-021-00695-9","type":"journal-article","created":{"date-parts":[[2021,2,25]],"date-time":"2021-02-25T11:04:41Z","timestamp":1614251081000},"update-policy":"https:\/\/doi.org\/10.1007\/springer_crossmark_policy","source":"Crossref","is-referenced-by-count":0,"title":["A rare case of multiple endocrine neoplasia type 1 initially presenting as an asymptomatic, huge mediastinal mass: case report"],"prefix":"10.1186","volume":"21","author":[{"given":"Ji Eun","family":"Jun","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"You-Cheol","family":"Hwang","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Kyu Jeong","family":"Ahn","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ho Yeon","family":"Chung","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-7857-546X","authenticated-orcid":false,"given":"In-Kyung","family":"Jeong","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"297","published-online":{"date-parts":[[2021,2,25]]},"reference":[{"key":"695_CR1","doi-asserted-by":"publisher","first-page":"38","DOI":"10.1186\/1750-1172-1-38","volume":"1","author":"F Marini","year":"2006","unstructured":"Marini F, Falchetti A, Del Monte F, Carbonell Sala S, Gozzini A, Luzi E, et al. Multiple endocrine neoplasia type 1. Orphanet J Rare Dis. 2006;1:38.","journal-title":"Orphanet J Rare Dis"},{"key":"695_CR2","doi-asserted-by":"publisher","unstructured":"Kamilaris CDC, Stratakis CA. Multiple endocrine Neoplasia type 1 (MEN1): an update and the significance of early genetic and clinical diagnosis. Front. Endocrinol. 2019. https:\/\/doi.org\/10.3389\/fendo.2019.00339.","DOI":"10.3389\/fendo.2019.00339"},{"issue":"4","key":"695_CR3","doi-asserted-by":"publisher","first-page":"533","DOI":"10.1111\/j.1365-2265.2011.04227.x","volume":"76","author":"A Sakurai","year":"2012","unstructured":"Sakurai A, Suzuki S, Kosugi S, Okamoto T, Uchino S, Miya A, et al. Multiple endocrine neoplasia type 1 in Japan: establishment and analysis of a multicentre database. 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World J Surg. 2010;34(2):249\u201355.","journal-title":"World J Surg"},{"issue":"3","key":"695_CR6","doi-asserted-by":"publisher","first-page":"355","DOI":"10.1016\/j.beem.2010.07.003","volume":"24","author":"RV Thakker","year":"2010","unstructured":"Thakker RV. Multiple endocrine neoplasia type 1 (MEN1). Best Pract Res Clin Endocrinol Metab. 2010;24(3):355\u201370.","journal-title":"Best Pract Res Clin Endocrinol Metab"},{"key":"695_CR7","first-page":"1293","volume":"2","author":"S Carrera","year":"2017","unstructured":"Carrera S, Garin I, Sancho A, Beristain E, Azkona E, L\u00f3pez-Vivanco G, et al. Thymic carcinoid tumor as single manifestation of multiple endocrine Neoplasia type 1: a clue to suspect a Germline MEN1 mutation. 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Clin Endocrinol (Oxf). 2016;84(1):13\u20136.","journal-title":"Clin Endocrinol (Oxf)"},{"key":"695_CR10","doi-asserted-by":"crossref","unstructured":"Brandi ML, Gagel RF, Angeli A, Bilezikian JP, Beck-Peccoz P, Bordi C, et al. ConsensBrandi ML, Gagel RF, Angeli A, Bilezikian JP, Beck-Peccoz P, Bordi C, et al. Consensus: guidelines for diagnosis and therapy of MEN type 1 and 2. J Clin Endocrinol Metabol. 2001;86(12):5658-71.","DOI":"10.1210\/jcem.86.12.8070"},{"issue":"9","key":"695_CR11","doi-asserted-by":"publisher","first-page":"2990","DOI":"10.1210\/jc.2012-1230","volume":"97","author":"RV Thakker","year":"2012","unstructured":"Thakker RV, Newey PJ, Walls GV, Bilezikian J, Dralle H, Ebeling PR, et al. Clinical practice guidelines for multiple endocrine neoplasia type 1 (MEN1). J Clin Endocrinol Metabol. 2012;97(9):2990\u20133011.","journal-title":"J Clin Endocrinol Metabol"},{"key":"695_CR12","doi-asserted-by":"crossref","unstructured":"Giusti F, Marini F, Tonelli F, Brandi ML. 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It was reviewed and approved by established our Institutaional Review Boards (IRB No. 2018\u201307-023).","order":1,"name":"Ethics","group":{"name":"EthicsHeading","label":"Ethics approval and consent to participate"}},{"value":"Written informed consent was obtained from all patients whose details were discussed in the manuscript for publication of this case report and any accompanying images.The patients gave written consent for their personal or clinical details along with any identifying images to be published in this study.","order":2,"name":"Ethics","group":{"name":"EthicsHeading","label":"Consent for publication"}},{"value":"The authors have no competing interest to disclose.","order":3,"name":"Ethics","group":{"name":"EthicsHeading","label":"Competing interests"}}],"article-number":"31"}}