{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,20]],"date-time":"2026-08-20T14:34:30Z","timestamp":1787236470177,"version":"build-2736575974"},"reference-count":22,"publisher":"Springer Science and Business Media LLC","issue":"1","license":[{"start":{"date-parts":[[2019,6,26]],"date-time":"2019-06-26T00:00:00Z","timestamp":1561507200000},"content-version":"tdm","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"},{"start":{"date-parts":[[2019,6,26]],"date-time":"2019-06-26T00:00:00Z","timestamp":1561507200000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":["link.springer.com"],"crossmark-restriction":false},"short-container-title":["Orphanet J Rare Dis"],"published-print":{"date-parts":[[2019,12]]},"DOI":"10.1186\/s13023-019-1122-5","type":"journal-article","created":{"date-parts":[[2019,6,26]],"date-time":"2019-06-26T10:02:33Z","timestamp":1561543353000},"update-policy":"https:\/\/doi.org\/10.1007\/springer_crossmark_policy","source":"Crossref","is-referenced-by-count":15,"title":["The updated retrospective questionnaire study of sporadic inclusion body myositis in Japan"],"prefix":"10.1186","volume":"14","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-8880-8554","authenticated-orcid":false,"given":"Naoki","family":"Suzuki","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Madoka","family":"Mori-Yoshimura","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Satoshi","family":"Yamashita","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Satoshi","family":"Nakano","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Ken-ya","family":"Murata","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Megumi","family":"Mori","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Yukie","family":"Inamori","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Naoko","family":"Matsui","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"En","family":"Kimura","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Hirofumi","family":"Kusaka","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Tomoyoshi","family":"Kondo","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Hidefumi","family":"Ito","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Itsuro","family":"Higuchi","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Akihiro","family":"Hashiguchi","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Hiroyuki","family":"Nodera","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Ryuji","family":"Kaji","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Maki","family":"Tateyama","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Rumiko","family":"Izumi","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Hiroya","family":"Ono","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Masaaki","family":"Kato","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Hitoshi","family":"Warita","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Toshiaki","family":"Takahashi","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Ichizo","family":"Nishino","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Masashi","family":"Aoki","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"297","published-online":{"date-parts":[[2019,6,26]]},"reference":[{"key":"1122_CR1","doi-asserted-by":"publisher","first-page":"2239","DOI":"10.1212\/WNL.0000000000001070","volume":"83","author":"AA Amato","year":"2014","unstructured":"Amato AA, Sivakumar K, Goyal N, David WS, Salajegheh M, Praestgaard J, Lach-Trifilieff E, Trendelenburg AU, Laurent D, Glass DJ, Roubenoff R, Tseng BS, Greenberg SA. Treatment of sporadic inclusion body myositis with bimagrumab. Neurology. 2014;83:2239\u201346.","journal-title":"Neurology"},{"key":"1122_CR2","doi-asserted-by":"publisher","first-page":"3176","DOI":"10.1093\/brain\/awr213","volume":"134","author":"O Benveniste","year":"2011","unstructured":"Benveniste O, Guiguet M, Freebody J, Dubourg O, Squier W, Maisonobe T, Stojkovic T, Leite MI, Allenbach Y, Herson S, Brady S, Eymard B, Hilton-Jones D. Long-term observational study of sporadic inclusion body myositis. Brain. 2011;134:3176\u201384.","journal-title":"Brain"},{"key":"1122_CR3","doi-asserted-by":"publisher","first-page":"127","DOI":"10.3233\/JND-160198","volume":"4","author":"A Callan","year":"2017","unstructured":"Callan A, Capkun G, Vasanthaprasad V, Freitas R, Needham M. A systematic review and meta-analysis of prevalence studies of sporadic inclusion body myositis. J Neuromuscul Dis. 2017;4:127\u201337.","journal-title":"J Neuromuscul Dis"},{"key":"1122_CR4","doi-asserted-by":"publisher","first-page":"326","DOI":"10.1212\/WNL.58.2.326","volume":"58","author":"P Cherin","year":"2002","unstructured":"Cherin P, Pelletier S, Teixeira A, Laforet P, Simon A, Herson S, Eymard B. Intravenous immunoglobulin for dysphagia of inclusion body myositis. Neurology. 2002;58:326.","journal-title":"Neurology"},{"key":"1122_CR5","doi-asserted-by":"publisher","first-page":"404","DOI":"10.1016\/j.nmd.2013.02.010","volume":"23","author":"A Cortese","year":"2013","unstructured":"Cortese A, Machado P, Morrow J, Dewar L, Hiscock A, Miller A, Brady S, Hilton-Jones D, Parton M, Hanna MG. Longitudinal observational study of sporadic inclusion body myositis: implications for clinical trials. Neuromuscul Disord. 2013;23:404\u201312.","journal-title":"Neuromuscul Disord"},{"key":"1122_CR6","first-page":"838","volume":"30","author":"C Dobloug","year":"2012","unstructured":"Dobloug C, Walle-Hansen R, Gran JT, Molberg O. Long-term follow-up of sporadic inclusion body myositis treated with intravenous immunoglobulin: a retrospective study of 16 patients. Clin Exp Rheumatol. 2012;30:838\u201342.","journal-title":"Clin Exp Rheumatol"},{"key":"1122_CR7","doi-asserted-by":"publisher","first-page":"604","DOI":"10.1016\/j.nmd.2014.04.009","volume":"24","author":"JY Hogrel","year":"2014","unstructured":"Hogrel JY, Allenbach Y, Canal A, Leroux G, Ollivier G, Mariampillai K, Servais L, Herson S, Decostre V, Benveniste O. Four-year longitudinal study of clinical and functional endpoints in sporadic inclusion body myositis: implications for therapeutic trials. Neuromuscul Disord. 2014;24:604\u201310.","journal-title":"Neuromuscul Disord"},{"key":"1122_CR8","doi-asserted-by":"publisher","first-page":"473","DOI":"10.1002\/mus.20958","volume":"37","author":"CE Jackson","year":"2008","unstructured":"Jackson CE, Barohn RJ, Gronseth G, Pandya S, Herbelin L, Muscle Study G. Inclusion body myositis functional rating scale: a reliable and valid measure of disease severity. Muscle Nerve. 2008;37:473\u20136.","journal-title":"Muscle Nerve"},{"issue":"5","key":"1122_CR9","doi-asserted-by":"publisher","first-page":"400","DOI":"10.1080\/03009742.2017.1423109","volume":"47","author":"AN J\u00f8rgensen","year":"2018","unstructured":"Jorgensen AN, Aagaard P, Frandsen U, Boyle E, Diederichsen LP. Blood-flow restricted resistance training in patients with sporadic inclusion body myositis: a randomized controlled trial. Scand J Rheumatol. 2018;47:400\u2013409.","journal-title":"Scandinavian Journal of Rheumatology"},{"key":"1122_CR10","doi-asserted-by":"publisher","first-page":"6","DOI":"10.1016\/j.jocn.2014.09.012","volume":"22","author":"FL Mastaglia","year":"2015","unstructured":"Mastaglia FL, Needham M. Inclusion body myositis: a review of clinical and genetic aspects, diagnostic criteria and therapeutic approaches. J Clin Neurosci. 2015;22:6\u201313.","journal-title":"J Clin Neurosci"},{"key":"1122_CR11","doi-asserted-by":"publisher","first-page":"333","DOI":"10.2169\/internalmedicine.52.8910","volume":"52","author":"H Nakanishi","year":"2013","unstructured":"Nakanishi H, Koike H, Matsuo K, Tanaka F, Noda T, Fujikake A, Kimura S, Katsuno M, Doyu M, Watanabe H, Sobue G. Demographic features of Japanese patients with sporadic inclusion body myositis: a single-center referral experience. Intern Med. 2013;52:333\u20137.","journal-title":"Intern Med"},{"key":"1122_CR12","doi-asserted-by":"publisher","first-page":"620","DOI":"10.1016\/S1474-4422(07)70171-0","volume":"6","author":"M Needham","year":"2007","unstructured":"Needham M, Mastaglia FL. Inclusion body myositis: current pathogenetic concepts and diagnostic and therapeutic approaches. Lancet Neurol. 2007;6:620\u201331.","journal-title":"Lancet Neurol"},{"key":"1122_CR13","doi-asserted-by":"publisher","first-page":"1044","DOI":"10.1016\/j.nmd.2013.08.007","volume":"23","author":"MR Rose","year":"2013","unstructured":"Rose MR, Group EIW. 188th ENMC international workshop: inclusion body myositis, 2-4 December 2011, Naarden. The Netherlands Neuromuscul Disord. 2013;23:1044\u201355.","journal-title":"The Netherlands Neuromuscul Disord"},{"key":"1122_CR14","doi-asserted-by":"publisher","first-page":"97","DOI":"10.1111\/ane.12455","volume":"133","author":"M Saltychev","year":"2016","unstructured":"Saltychev M, Mikkelsson M, Laimi K. Medication of inclusion body myositis: a systematic review. Acta Neurol Scand. 2016;133:97\u2013102.","journal-title":"Acta Neurol Scand"},{"key":"1122_CR15","doi-asserted-by":"publisher","first-page":"325","DOI":"10.1016\/j.jns.2017.09.014","volume":"381","author":"S Shibata","year":"2017","unstructured":"Shibata S, Izumi R, Hara T, Ohshima R, Nakamura N, Suzuki N, Kato K, Katori Y, Tateyama M, Kuroda H, Aoki M. Five-year history of dysphagia as a sole initial symptom in inclusion body myositis. J Neurol Sci. 2017;381:325\u20137.","journal-title":"J Neurol Sci"},{"key":"1122_CR16","doi-asserted-by":"publisher","first-page":"3521","DOI":"10.2169\/internalmedicine.55.7285","volume":"55","author":"Y Suwa","year":"2016","unstructured":"Suwa Y, Suzuki N, Soga T, Harada R, Shibui A, Kuroda H, Izumi R, Tateyama M, Nakashima I, Sonoo M, Aoki M. Sporadic inclusion body myositis manifesting as isolated Muscle weakness of the finger flexors three years after disease onset. Intern Med. 2016;55:3521\u20134.","journal-title":"Intern Med"},{"key":"1122_CR17","doi-asserted-by":"publisher","first-page":"554","DOI":"10.1007\/s00415-011-6185-8","volume":"259","author":"N Suzuki","year":"2012","unstructured":"Suzuki N, Aoki M, Mori-Yoshimura M, Hayashi YK, Nonaka I, Nishino I. Increase in number of sporadic inclusion body myositis (sIBM) in Japan. J Neurol. 2012;259:554\u20136.","journal-title":"J Neurol"},{"key":"1122_CR18","doi-asserted-by":"publisher","first-page":"146","DOI":"10.1186\/s13023-016-0524-x","volume":"11","author":"N Suzuki","year":"2016","unstructured":"Suzuki N, Mori-Yoshimura M, Yamashita S, Nakano S, Murata KY, Inamori Y, Matsui N, Kimura E, Kusaka H, Kondo T, Higuchi I, Kaji R, Tateyama M, Izumi R, Ono H, Kato M, Warita H, Takahashi T, Nishino I, Aoki M. Multicenter questionnaire survey for sporadic inclusion body myositis in Japan. Orphanet J Rare Dis. 2016;11:146.","journal-title":"Orphanet J Rare Dis"},{"key":"1122_CR19","doi-asserted-by":"publisher","first-page":"185","DOI":"10.1159\/000324525","volume":"54","author":"J Tanaka","year":"2011","unstructured":"Tanaka J, Koyama T, Mizui M, Uchida S, Katayama K, Matsuo J, Akita T, Nakashima A, Miyakawa Y, Yoshizawa H. Total numbers of undiagnosed carriers of hepatitis C and B viruses in Japan estimated by age- and area-specific prevalence on the national scale. Intervirology. 2011;54:185\u201395.","journal-title":"Intervirology"},{"key":"1122_CR20","doi-asserted-by":"publisher","first-page":"658","DOI":"10.1212\/WNL.0000000000001862","volume":"85","author":"JP Taylor","year":"2015","unstructured":"Taylor JP. Multisystem proteinopathy: intersecting genetics in muscle, bone, and brain degeneration. Neurology. 2015;85:658\u201360.","journal-title":"Neurology"},{"key":"1122_CR21","doi-asserted-by":"publisher","first-page":"211","DOI":"10.1212\/WNL.0000000000002291","volume":"86","author":"A Uruha","year":"2016","unstructured":"Uruha A, Noguchi S, Hayashi YK, Tsuburaya RS, Yonekawa T, Nonaka I, Nishino I. Hepatitis C virus infection in inclusion body myositis: a case-control study. Neurology. 2016;86:211\u20137.","journal-title":"Neurology"},{"key":"1122_CR22","doi-asserted-by":"publisher","first-page":"308","DOI":"10.1016\/j.nmd.2009.01.009","volume":"19","author":"CC Weihl","year":"2009","unstructured":"Weihl CC, Pestronk A, Kimonis VE. Valosin-containing protein disease: inclusion body myopathy with Paget's disease of the bone and fronto-temporal dementia. Neuromuscul Disord. 2009;19:308\u201315.","journal-title":"Neuromuscul Disord"}],"container-title":["Orphanet Journal of Rare Diseases"],"original-title":[],"language":"en","link":[{"URL":"http:\/\/link.springer.com\/content\/pdf\/10.1186\/s13023-019-1122-5.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"http:\/\/link.springer.com\/article\/10.1186\/s13023-019-1122-5\/fulltext.html","content-type":"text\/html","content-version":"vor","intended-application":"text-mining"},{"URL":"http:\/\/link.springer.com\/content\/pdf\/10.1186\/s13023-019-1122-5.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2020,6,24]],"date-time":"2020-06-24T19:10:38Z","timestamp":1593025838000},"score":1,"resource":{"primary":{"URL":"https:\/\/ojrd.biomedcentral.com\/articles\/10.1186\/s13023-019-1122-5"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2019,6,26]]},"references-count":22,"journal-issue":{"issue":"1","published-print":{"date-parts":[[2019,12]]}},"alternative-id":["1122"],"URL":"https:\/\/doi.org\/10.1186\/s13023-019-1122-5","relation":{},"ISSN":["1750-1172"],"issn-type":[{"value":"1750-1172","type":"electronic"}],"subject":[],"published":{"date-parts":[[2019,6,26]]},"assertion":[{"value":"10 February 2019","order":1,"name":"received","label":"Received","group":{"name":"ArticleHistory","label":"Article History"}},{"value":"10 June 2019","order":2,"name":"accepted","label":"Accepted","group":{"name":"ArticleHistory","label":"Article History"}},{"value":"26 June 2019","order":3,"name":"first_online","label":"First Online","group":{"name":"ArticleHistory","label":"Article History"}},{"value":"All protocols were approved by the ethics committee of Tohoku University (No. 2014\u20131-358).","order":1,"name":"Ethics","group":{"name":"EthicsHeading","label":"Ethics approval and consent to participate"}},{"value":"Not applicable","order":2,"name":"Ethics","group":{"name":"EthicsHeading","label":"Consent for publication"}},{"value":"The authors declare that they have no competing interests.","order":3,"name":"Ethics","group":{"name":"EthicsHeading","label":"Competing interests"}}],"article-number":"155"}}