{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,11,29]],"date-time":"2025-11-29T16:26:03Z","timestamp":1764433563710,"version":"3.37.3"},"reference-count":19,"publisher":"Springer Science and Business Media LLC","issue":"1","license":[{"start":{"date-parts":[[2024,4,28]],"date-time":"2024-04-28T00:00:00Z","timestamp":1714262400000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0"},{"start":{"date-parts":[[2024,4,28]],"date-time":"2024-04-28T00:00:00Z","timestamp":1714262400000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0"}],"content-domain":{"domain":["link.springer.com"],"crossmark-restriction":false},"short-container-title":["J Med Case Reports"],"abstract":"<jats:title>Abstract<\/jats:title><jats:sec>\n                <jats:title>Background<\/jats:title>\n                <jats:p>Sprengel\u2019s deformity is a congenital abnormality of the shoulder girdle. Because scapular retraction, such as the Green procedure, is usually performed during childhood to improve esthetics and shoulder function, Sprengel\u2019s deformity is rarely found in older patients.<\/jats:p>\n              <\/jats:sec><jats:sec>\n                <jats:title>Case presentation<\/jats:title>\n                <jats:p>We presented a unique case of a Japanese female cadaver with Sprengel\u2019s deformity at the age of 80\u00a0years. Anatomical dissection and radiological imaging revealed musculoskeletal anomalies associated with Sprengel\u2019s deformity, including Klippel\u2013Feil syndrome, presence of an omovertebral bone, and absence of the trapezius muscle. In addition, bilateral cervical ribs were in contact with the brachial plexus. These anomalies may lead to numbness, pain, and limited range of motion of the neck and upper girdle with aging.<\/jats:p>\n              <\/jats:sec><jats:sec>\n                <jats:title>Conclusions<\/jats:title>\n                <jats:p>Because most adult patients with Sprengel\u2019s deformity experience neck pain and limited movement of the shoulder, the presented case is a rare case of neglected Sprengel\u2019s deformity in an 80-year-old cadaver.<\/jats:p>\n              <\/jats:sec>","DOI":"10.1186\/s13256-024-04528-w","type":"journal-article","created":{"date-parts":[[2024,4,28]],"date-time":"2024-04-28T00:02:17Z","timestamp":1714262537000},"update-policy":"https:\/\/doi.org\/10.1007\/springer_crossmark_policy","source":"Crossref","is-referenced-by-count":1,"title":["Neglected Sprengel\u2019s deformity in an 80-year-old female cadaver: a case report"],"prefix":"10.1186","volume":"18","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-1832-9472","authenticated-orcid":false,"given":"Shun","family":"Otsuka","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Yuki","family":"Tamaki","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Masaki","family":"Matsushita","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Naoyuki","family":"Hatayama","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Munekazu","family":"Naito","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"297","published-online":{"date-parts":[[2024,4,28]]},"reference":[{"key":"4528_CR1","doi-asserted-by":"publisher","first-page":"598","DOI":"10.1302\/0301-620X.65B5.6643564","volume":"65","author":"DP Grogan","year":"1983","unstructured":"Grogan DP, Stanley EA, Bobechko WP. The congenital undescended scapula. Surgical correction by the woodward procedure. J Bone Joint Surg Br. 1983;65:598\u2013605.","journal-title":"J Bone Joint Surg Br"},{"key":"4528_CR2","first-page":"288","volume":"4","author":"HAPP Pinsky","year":"1980","unstructured":"Pinsky HAPP, MacEwen GD. Congenital elevation of the scapula. Orthopade Trans. 1980;4:288\u20139.","journal-title":"Orthopade Trans"},{"key":"4528_CR3","doi-asserted-by":"publisher","first-page":"145","DOI":"10.1177\/095952878306600111","volume":"66","author":"A Willett","year":"1883","unstructured":"Willett A, Walsham WJ. A second case of malformation of the left shoulder-girdle: removal of the abnormal portion of bone; with remarks on the probable nature of the deformity. 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Surgical treatment of Sprengel\u2019s deformity: a systematic review and meta-analysis. Children (Basel). 2021;8:1142.","journal-title":"Children (Basel)"},{"key":"4528_CR7","doi-asserted-by":"publisher","first-page":"E798","DOI":"10.1097\/01.brs.0000239222.36505.46","volume":"31","author":"DD Samartzis","year":"2006","unstructured":"Samartzis DD, Herman J, Lubicky JP, Shen FH. Classification of congenitally fused cervical patterns in Klippel-Feil patients: epidemiology and role in the development of cervical spine-related symptoms. Spine (Phila Pa 1976). 2006;31:E798-804.","journal-title":"Spine (Phila Pa 1976)"},{"key":"4528_CR8","first-page":"264","volume":"71","author":"U Aydinli","year":"2005","unstructured":"Aydinli U, Ozturk C, Akesen B, Ozer O. Surgical treatment of Sprengel\u2019s deformity: a modified Green procedure. Acta Orthop Belg. 2005;71:264\u20138.","journal-title":"Acta Orthop Belg"},{"key":"4528_CR9","doi-asserted-by":"publisher","first-page":"E1501","DOI":"10.1097\/BRS.0b013e31823145e4","volume":"36","author":"D Samartzis","year":"2011","unstructured":"Samartzis D, Kalluri P, Herman J, Lubicky JP, Shen FH. Cervical scoliosis in the Klippel-Feil patient. Spine (Phila Pa 1976). 2011;36:E1501\u20138.","journal-title":"Spine (Phila Pa 1976)"},{"key":"4528_CR10","first-page":"385","volume":"4","author":"PFC Nyemb","year":"2017","unstructured":"Nyemb PFC, Ndoye JM. Review of the literature on anatomical variations of the trapezius muscle. MOJ Anat Physiol. 2017;4:385\u201390.","journal-title":"MOJ Anat Physiol"},{"key":"4528_CR11","doi-asserted-by":"publisher","DOI":"10.1155\/2012\/398254","volume":"2012","author":"MH Kariminasab","year":"2012","unstructured":"Kariminasab MH, Shayeste-Azar M, Sajjadi Saravi M, Taghipour GM. Sprengel\u2019s deformity associated with musculoskeletal dysfunctions and renal anomalies: a case report. Case Rep Med. 2012;2012: 398254.","journal-title":"Case Rep Med"},{"key":"4528_CR12","doi-asserted-by":"publisher","first-page":"234","DOI":"10.28922\/qmj.2014.10.17.234-238","volume":"10","author":"MI Imran Alghazali","year":"2014","unstructured":"Imran Alghazali MI. Sprengel\u2019s deformity associated with omovertebral bar between inferior angle of the scapula and the cervical spine: a case report. Al-Qadisiyah Med J. 2014;10:234\u20138.","journal-title":"Al-Qadisiyah Med J"},{"key":"4528_CR13","doi-asserted-by":"publisher","first-page":"330","DOI":"10.1016\/j.otsr.2009.04.015","volume":"95","author":"G Andrault","year":"2009","unstructured":"Andrault G, Salmeron F, Laville JM. Green\u2019s surgical procedure in Sprengel\u2019s deformity: cosmetic and functional results. 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