{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,7,30]],"date-time":"2025-07-30T13:51:52Z","timestamp":1753883512245,"version":"3.41.2"},"reference-count":10,"publisher":"The Endocrine Society","issue":"4","license":[{"start":{"date-parts":[[2023,8,14]],"date-time":"2023-08-14T00:00:00Z","timestamp":1691971200000},"content-version":"vor","delay-in-days":44,"URL":"https:\/\/creativecommons.org\/licenses\/by-nc-nd\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2023,7,1]]},"abstract":"<jats:title>Abstract<\/jats:title>\n               <jats:p>Solid pseudopapillary tumor (SPT) is a low-grade malignant tumor of the pancreas. SPT typically affects women and can occur in ectopic pancreatic region; however, it also occurs rarely in retroperitoneum. The tumor may be bulky at the time of diagnosis since there is no specific clinical manifestation. Here we present an older male case with retroperitoneal SPT. A 67-year-old man consulted for intermittent fever and lumbago. His basal hormonal profile screened out a functional tumor. Computed tomography (CT) showed a gigantic mass in his left adrenal region. A normal left adrenal gland was not identified, and the tumor's feeding artery was recognized as the left adrenal artery by the contrast-enhanced CT. Adrenal malignant tumor was suspected, and tumor resection was performed. The resected tumor size was 15 \u00d7 10 \u00d7 9\u2005cm. Histologically, epithelial-like cells with round nuclei and a small amount of eosinophilic cytoplasm proliferated in papillary (around the blood vessels) or uniformly solid form. By immunostaining, tumor cells were vimentin, CD56, cytokeratin AE1\/AE3, CD10, \u03b2-catenin in the nucleus, cyclin D1, and PgR positive. These findings led to the diagnosis of SPT. Although rare, SPT should be considered as a differential diagnosis in cases of a mass arising from the adrenal region.<\/jats:p>","DOI":"10.1210\/jcemcr\/luad090","type":"journal-article","created":{"date-parts":[[2023,8,14]],"date-time":"2023-08-14T17:25:45Z","timestamp":1692033945000},"source":"Crossref","is-referenced-by-count":1,"title":["Retroperitoneal Solid Pseudopapillary Tumor Mimicking Adrenal Malignant Tumor in a 67-Year-Old Man"],"prefix":"10.1210","volume":"1","author":[{"given":"Takahiro","family":"Ishii","sequence":"first","affiliation":[{"name":"Department of Nephrology, Rheumatology, Endocrinology and Metabolism, Okayama University Graduate School of Medicine, Dentistry and Pharmaceutical Sciences , Okayama, 700-8558 , Japan"},{"name":"Endocrine Center, Okayama University Hospital , Okayama, 700-8558 , Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-7316-2447","authenticated-orcid":false,"given":"Tomohiro","family":"Terasaka","sequence":"additional","affiliation":[{"name":"Department of Nephrology, Rheumatology, Endocrinology and Metabolism, Okayama University Graduate School of Medicine, Dentistry and Pharmaceutical Sciences , Okayama, 700-8558 , Japan"},{"name":"Endocrine Center, Okayama University Hospital , Okayama, 700-8558 , Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Kenji","family":"Nishida","sequence":"additional","affiliation":[{"name":"Department of Pathology, Okayama University Graduate School of Medicine, Dentistry and Pharmaceutical Science , Okayama, 700-8558 , Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-1468-5170","authenticated-orcid":false,"given":"Jun","family":"Wada","sequence":"additional","affiliation":[{"name":"Department of Nephrology, Rheumatology, Endocrinology and Metabolism, Okayama University Graduate School of Medicine, Dentistry and Pharmaceutical Sciences , Okayama, 700-8558 , Japan"},{"name":"Endocrine Center, Okayama University Hospital , Okayama, 700-8558 , Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"80","published-online":{"date-parts":[[2023,8,14]]},"reference":[{"issue":"2","key":"2023081417253459100_luad090-B1","doi-asserted-by":"crossref","first-page":"G1","DOI":"10.1530\/EJE-16-0467","article-title":"Management of adrenal incidentalomas: European society of endocrinology clinical practice guideline in collaboration with the European network for the study of adrenal tumors","volume":"175","author":"Fassnacht","year":"2016","journal-title":"Eur J Endocrinol"},{"issue":"8","key":"2023081417253459100_luad090-B2","doi-asserted-by":"crossref","first-page":"896","DOI":"10.4254\/wjh.v13.i8.896","article-title":"Solid pseudopapillary neoplasm of the pancreas","volume":"13","author":"Omiyale","year":"2021","journal-title":"World J Hepatol"},{"issue":"5","key":"2023081417253459100_luad090-B3","doi-asserted-by":"crossref","first-page":"1501","DOI":"10.3892\/ol.2013.1242","article-title":"Extrapancreatic solid pseudopapillary neoplasm: report of a case of primary retroperitoneal origin and review of the literature","volume":"5","author":"Zhu","year":"2013","journal-title":"Oncol Lett"},{"issue":"2","key":"2023081417253459100_luad090-B4","doi-asserted-by":"crossref","first-page":"165","DOI":"10.1007\/s10147-011-0261-z","article-title":"Extrapancreatic solid pseudopapillary tumor: case report and review of the literature","volume":"17","author":"Miyazaki","year":"2012","journal-title":"Int J Clin Oncol"},{"issue":"7","key":"2023081417253459100_luad090-B5","doi-asserted-by":"crossref","first-page":"598","DOI":"10.1007\/s11604-012-0084-5","article-title":"A case of extrapancreatic solid pseudopapillary tumor in the retroperitoneum","volume":"30","author":"Junzu","year":"2012","journal-title":"Jpn J Radiol"},{"issue":"5","key":"2023081417253459100_luad090-B6","doi-asserted-by":"crossref","first-page":"845","DOI":"10.3892\/mco.2016.802","article-title":"Extrapancreatic solid pseudopapillary tumors: A clinicopathological analysis of two cases","volume":"4","author":"Guo","year":"2016","journal-title":"Mol Clin Oncol"},{"issue":"5","key":"2023081417253459100_luad090-B7","doi-asserted-by":"crossref","first-page":"473","DOI":"10.1007\/s004280050475","article-title":"Solid-pseudopapillary tumor of the pancreas: its origin revisited","volume":"436","author":"Kosmahl","year":"2000","journal-title":"Virchows Arch"},{"issue":"2","key":"2023081417253459100_luad090-B8","doi-asserted-by":"crossref","first-page":"641","DOI":"10.1007\/s12253-019-00671-8","article-title":"Solid-pseudopapillary neoplasms of the pancreas is still an enigma: a clinicopathological review","volume":"26","author":"Zalatnai","year":"2020","journal-title":"Pathol Oncol Res"},{"issue":"7","key":"2023081417253459100_luad090-B9","doi-asserted-by":"crossref","first-page":"829","DOI":"10.5858\/arpa.2019-0473-RA","article-title":"Pancreatic solid pseudopapillary neoplasm: key pathologic and genetic features","volume":"144","author":"La Rosa","year":"2020","journal-title":"Arch Pathol Lab Med"},{"issue":"1","key":"2023081417253459100_luad090-B10","doi-asserted-by":"crossref","first-page":"12","DOI":"10.1016\/j.hpb.2019.06.005","article-title":"A systematic review and meta-analysis of predictors of recurrence in patients with solid pseudopapillary tumors of the pancreas","volume":"22","author":"Yepuri","year":"2020","journal-title":"HPB (Oxford)"}],"container-title":["JCEM Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/academic.oup.com\/jcemcr\/article-pdf\/1\/4\/luad090\/51111151\/luad090.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/academic.oup.com\/jcemcr\/article-pdf\/1\/4\/luad090\/51111151\/luad090.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2023,8,14]],"date-time":"2023-08-14T17:25:51Z","timestamp":1692033951000},"score":1,"resource":{"primary":{"URL":"https:\/\/academic.oup.com\/jcemcr\/article\/doi\/10.1210\/jcemcr\/luad090\/7242398"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2023,7,1]]},"references-count":10,"journal-issue":{"issue":"4","published-print":{"date-parts":[[2023,7,1]]}},"URL":"https:\/\/doi.org\/10.1210\/jcemcr\/luad090","relation":{},"ISSN":["2755-1520"],"issn-type":[{"type":"electronic","value":"2755-1520"}],"subject":[],"published-other":{"date-parts":[[2023,7]]},"published":{"date-parts":[[2023,7,1]]},"article-number":"luad090"}}