{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2023,11,13]],"date-time":"2023-11-13T02:12:55Z","timestamp":1699841575498},"reference-count":0,"publisher":"British Editorial Society of Bone & Joint Surgery","issue":"4","license":[{"start":{"date-parts":[[1976,11,1]],"date-time":"1976-11-01T00:00:00Z","timestamp":215654400000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/online.boneandjoint.org.uk\/TDM"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["The Journal of Bone and Joint Surgery. British volume"],"published-print":{"date-parts":[[1976,11]]},"abstract":"<jats:p> During the course of a nation-wide survey of patients with bone and joint deformities, twenty-six individuals with arthrogryposis multiplex congenita, in the narrow and precise sense of the term, were investigated. No patient was more than twenty-four years of age. However, on a basis of the figures of population, it can be estimated that 21-0 +\/- 6-5 older affected individuals should have been encountered. Furthermore, there was a relative excess of younger children. The series was reasonably unbiased, and as arthrogryposis is non-lethal the deficiency of affected adults is an anomalous finding. It is tentatively suggested that arthrogryposis might result from the intra-uterine influence of an unknown environmental agent which has been present in South Africa for only a limited period of time. Detection of this factor could be an important step in the prevention of the disease. <\/jats:p>","DOI":"10.1302\/0301-620x.58b4.1018038","type":"journal-article","created":{"date-parts":[[2018,2,21]],"date-time":"2018-02-21T11:30:56Z","timestamp":1519212656000},"page":"492-495","source":"Crossref","is-referenced-by-count":5,"title":["Whence the arthrogrypotics?"],"prefix":"10.1302","volume":"58-B","author":[{"given":"J","family":"Davidson","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"P","family":"Beighton","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"42","container-title":["The Journal of Bone and Joint Surgery. British volume"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/online.boneandjoint.org.uk\/doi\/pdf\/10.1302\/0301-620X.58B4.1018038","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/online.boneandjoint.org.uk\/doi\/pdf\/10.1302\/0301-620X.58B4.1018038","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2021,8,16]],"date-time":"2021-08-16T22:00:36Z","timestamp":1629151236000},"score":1,"resource":{"primary":{"URL":"https:\/\/online.boneandjoint.org.uk\/doi\/10.1302\/0301-620X.58B4.1018038"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[1976,11]]},"references-count":0,"journal-issue":{"issue":"4","published-print":{"date-parts":[[1976,11]]}},"alternative-id":["10.1302\/0301-620X.58B4.1018038"],"URL":"https:\/\/doi.org\/10.1302\/0301-620x.58b4.1018038","relation":{},"ISSN":["0301-620X","2044-5377"],"issn-type":[{"value":"0301-620X","type":"print"},{"value":"2044-5377","type":"electronic"}],"subject":[],"published":{"date-parts":[[1976,11]]}}}