{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,3,21]],"date-time":"2026-03-21T01:12:49Z","timestamp":1774055569867,"version":"3.50.1"},"reference-count":23,"publisher":"Informa UK Limited","issue":"1","content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2025,1,1]]},"abstract":"<jats:title>Abstract<\/jats:title>\n                  <jats:p>Sleep problems are common in Rett syndrome and other neurogenetic syndromes. Actigraphy is a cost-effective, objective method for measuring sleep. Current guidelines require caregiver-reported bed and wake times to facilitate actigraphy data scoring. The current study examined missingness and consistency of caregiver-reported bed and wake times from paper sleep diaries and actigraphy event mark button presses in a sample of 38 individuals with Rett and related syndromes (aged 2\u201336 years, mean = 13.1) across two 14-day collection time points. Rates of missingness and discrepancy between the 2 sources were relatively high and correlated with clinical severity and quality of life. Overall, the results suggest a need for alternative actigraphy scoring methods that do not rely on caregiver report in this population.<\/jats:p>","DOI":"10.1352\/1944-7558-130.1.1","type":"journal-article","created":{"date-parts":[[2024,12,22]],"date-time":"2024-12-22T19:00:32Z","timestamp":1734894032000},"page":"1-12","source":"Crossref","is-referenced-by-count":3,"title":["Challenges in Using Parent-Reported Bed and Wake Times for Actigraphy Scoring in Rett-Related Syndromes"],"prefix":"10.1080","volume":"130","author":[{"given":"Breanne J.","family":"Byiers","sequence":"first","affiliation":[{"name":"Breanne J. Byiers and Alyssa M. Merbler, University of Minnesota, Chantel C. Burkitt, Gillette Children\u2019s Specialty Healthcare, St. Paul, MN, and Frank J. Symons, University of Minnesota"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Alyssa M.","family":"Merbler","sequence":"additional","affiliation":[{"name":"Breanne J. Byiers and Alyssa M. Merbler, University of Minnesota, Chantel C. Burkitt, Gillette Children\u2019s Specialty Healthcare, St. Paul, MN, and Frank J. Symons, University of Minnesota"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Chantel C.","family":"Burkitt","sequence":"additional","affiliation":[{"name":"Breanne J. Byiers and Alyssa M. Merbler, University of Minnesota, Chantel C. Burkitt, Gillette Children\u2019s Specialty Healthcare, St. Paul, MN, and Frank J. Symons, University of Minnesota"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Frank J.","family":"Symons","sequence":"additional","affiliation":[{"name":"Breanne J. Byiers and Alyssa M. Merbler, University of Minnesota, Chantel C. Burkitt, Gillette Children\u2019s Specialty Healthcare, St. Paul, MN, and Frank J. 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