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Pediatr"},{"key":"pmed.1003356.ref071","doi-asserted-by":"crossref","first-page":"138","DOI":"10.1016\/j.jpeds.2019.11.006","article-title":"Mortality Among Children with Down syndrome in Hong Kong: A Population-Based Cohort Study from Birth","volume":"218","author":"GT Chua","year":"2020","journal-title":"J Pediatr"},{"issue":"4","key":"pmed.1003356.ref072","doi-asserted-by":"crossref","first-page":"825","DOI":"10.1002\/ajmg.a.37495","article-title":"Survival of children with trisomy 13 and trisomy 18: A multi-state population-based study","volume":"170A","author":"RE Meyer","year":"2016","journal-title":"Am J Med Genet A"},{"issue":"6","key":"pmed.1003356.ref073","doi-asserted-by":"crossref","first-page":"506","DOI":"10.1111\/j.1440-1754.2011.02225.x","article-title":"Prader-Willi syndrome in Victoria: mortality and causes of death","volume":"48","author":"T Lionti","year":"2012","journal-title":"J Paediatr Child Health"},{"issue":"12","key":"pmed.1003356.ref074","doi-asserted-by":"crossref","first-page":"1561","DOI":"10.1001\/jama.287.12.1561","article-title":"Relationship of prenatal diagnosis and pregnancy termination to overall infant mortality in Canada","volume":"287","author":"S Liu","year":"2002","journal-title":"JAMA"},{"key":"pmed.1003356.ref075","doi-asserted-by":"crossref","first-page":"112","DOI":"10.1186\/s12884-016-0904-1","article-title":"Stillbirth and neonatal death rates across time: the influence of pregnancy terminations and birth defects in a Western Australian population-based cohort study","volume":"16","author":"BM Farrant","year":"2016","journal-title":"BMC Pregnancy Childbirth"},{"issue":"3","key":"pmed.1003356.ref076","doi-asserted-by":"crossref","first-page":"803","DOI":"10.1542\/peds.2005-1364","article-title":"Survival of infants with neural tube defects in the presence of folic acid fortification","volume":"117","author":"National Birth Defects Prevention N","year":"2006","journal-title":"Pediatrics"},{"issue":"9448","key":"pmed.1003356.ref077","doi-asserted-by":"crossref","first-page":"1885","DOI":"10.1016\/S0140-6736(04)17445-X","article-title":"Spina bifida","volume":"364","author":"LE Mitchell","year":"2004","journal-title":"Lancet"},{"key":"pmed.1003356.ref078","doi-asserted-by":"crossref","first-page":"121","DOI":"10.1016\/j.bpobgyn.2019.03.004","article-title":"Open fetal surgery for neural tube defects","volume":"58","author":"JS Moldenhauer","year":"2019","journal-title":"Best Pract Res Clin Obstet Gynaecol"},{"issue":"1","key":"pmed.1003356.ref079","doi-asserted-by":"crossref","first-page":"241","DOI":"10.1016\/j.yapd.2018.05.001","article-title":"Congenital Diaphragmatic Hernia: Management & Outcomes","volume":"65","author":"M Dingeldein","year":"2018","journal-title":"Adv Pediatr"},{"issue":"4","key":"pmed.1003356.ref080","doi-asserted-by":"crossref","first-page":"344","DOI":"10.1097\/MPG.0b013e318282a913","article-title":"International incidence and outcomes of biliary atresia","volume":"56","author":"C Jimenez-Rivera","year":"2013","journal-title":"J Pediatr Gastroenterol Nutr"},{"issue":"6","key":"pmed.1003356.ref081","doi-asserted-by":"crossref","first-page":"1132","DOI":"10.1542\/peds.2010-1824","article-title":"Survival and morbidity outcomes for very low birth weight infants with Down syndrome","volume":"126","author":"NS Boghossian","year":"2010","journal-title":"Pediatrics"},{"issue":"19","key":"pmed.1003356.ref082","doi-asserted-by":"crossref","first-page":"1552","DOI":"10.1136\/heartjnl-2016-309437","article-title":"Eisenmenger syndrome and long-term survival in patients with Down syndrome and congenital heart disease","volume":"102","author":"MA Korten","year":"2016","journal-title":"Heart"},{"issue":"19","key":"pmed.1003356.ref083","doi-asserted-by":"crossref","first-page":"1515","DOI":"10.1136\/heartjnl-2016-309835","article-title":"Patients with Down syndrome and congenital heart disease: survival is improving, but challenges remain","volume":"102","author":"K Dimopoulos","year":"2016","journal-title":"Heart"},{"issue":"8","key":"pmed.1003356.ref084","doi-asserted-by":"crossref","first-page":"742","DOI":"10.1002\/pd.4117","article-title":"Trisomies 18 and 13: trends in prevalence and prenatal diagnosis\u2014population based study","volume":"33","author":"AM Tonks","year":"2013","journal-title":"Prenat Diagn"},{"issue":"1","key":"pmed.1003356.ref085","doi-asserted-by":"crossref","first-page":"13","DOI":"10.1002\/ajmg.a.61370","article-title":"Emerging evidence that medical and surgical interventions improve the survival and outcome in the trisomy 13 and 18 syndromes","volume":"182","author":"JC Carey","year":"2020","journal-title":"Am J Med Genet A"},{"issue":"3","key":"pmed.1003356.ref086","doi-asserted-by":"crossref","first-page":"251","DOI":"10.1002\/ajmg.c.31512","article-title":"Trisomy 13 and 18: Selecting the road previously not taken","volume":"172","author":"MJ McCaffrey","year":"2016","journal-title":"Am J Med Genet C Semin Med Genet"},{"issue":"3","key":"pmed.1003356.ref087","doi-asserted-by":"crossref","first-page":"213","DOI":"10.1007\/s10730-017-9319-2","article-title":"Treatment Decisions for Babies with Trisomy 13 and 18","volume":"29","author":"I Pallotto","year":"2017","journal-title":"HEC Forum"},{"key":"pmed.1003356.ref088","unstructured":"Office for National Statistics. Child and infant mortality in England and Wales: 2017. Statistical bulletin [Internet]. 2019 [cited xxxx]. https:\/\/www.ons.gov.uk\/peoplepopulationandcommunity\/birthsdeathsandmarriages\/deaths\/bulletins\/childhoodinfantandperinatalmortalityinenglandandwales\/2017."},{"key":"pmed.1003356.ref089","doi-asserted-by":"crossref","unstructured":"Royal College of Paediatrics and Child Health. State of Child Health 2017: Report 2017. 2017 [2019 Oct 4]. https:\/\/www.rcpch.ac.uk\/resources\/state-child-health-2017-full-report.","DOI":"10.12968\/cypn.2017.6.35"},{"issue":"4","key":"pmed.1003356.ref090","doi-asserted-by":"crossref","first-page":"364","DOI":"10.1046\/j.1365-3016.2001.0379a.x","article-title":"Stillbirth and neonatal mortality due to congenital anomalies: temporal trends and variation by small area deprivation scores in England and Wales, 1986\u201396","volume":"15","author":"D Neasham","year":"2001","journal-title":"Paediatr Perinat Epidemiol"},{"key":"pmed.1003356.ref091","doi-asserted-by":"crossref","first-page":"d4306","DOI":"10.1136\/bmj.d4306","article-title":"Socioeconomic inequalities in outcome of pregnancy and neonatal mortality associated with congenital anomalies: population based study","volume":"343","author":"LK Smith","year":"2011","journal-title":"BMJ"},{"issue":"2","key":"pmed.1003356.ref092","doi-asserted-by":"crossref","first-page":"114","DOI":"10.1111\/j.1471-1842.2009.00863.x","article-title":"Literature searching for social science systematic reviews: consideration of a range of search techniques","volume":"27","author":"D Papaioannou","year":"2010","journal-title":"Health Info Libr J"},{"issue":"10","key":"pmed.1003356.ref093","doi-asserted-by":"crossref","first-page":"907","DOI":"10.1136\/archdischild-2014-306752","article-title":"UK child survival in a European context: recommendations for a national Countdown Collaboration","volume":"100","author":"I Wolfe","year":"2015","journal-title":"Arch Dis Child"},{"issue":"4","key":"pmed.1003356.ref094","doi-asserted-by":"crossref","first-page":"291","DOI":"10.1111\/ppe.12564","article-title":"Socio-economic inequalities in mortality in children with congenital heart disease: A systematic review and meta-analysis","volume":"33","author":"KE Best","year":"2019","journal-title":"Paediatr Perinat Epidemiol"},{"issue":"4","key":"pmed.1003356.ref095","doi-asserted-by":"crossref","first-page":"80","DOI":"10.13105\/wjma.v5.i4.80","article-title":"Assessing the quality of studies in meta-analyses: Advantages and limitations of the Newcastle Ottawa Scale","volume":"5","author":"C Luchini","year":"2017","journal-title":"World J Meta-Anal"}],"container-title":["PLOS Medicine"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/dx.plos.org\/10.1371\/journal.pmed.1003356","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2022,11,20]],"date-time":"2022-11-20T17:35:43Z","timestamp":1668965743000},"score":1,"resource":{"primary":{"URL":"https:\/\/dx.plos.org\/10.1371\/journal.pmed.1003356"}},"subtitle":[],"editor":[{"given":"Lars \u00c5ke","family":"Persson","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"editor"}]}],"short-title":[],"issued":{"date-parts":[[2020,9,28]]},"references-count":96,"journal-issue":{"issue":"9","published-online":{"date-parts":[[2020,9,28]]}},"URL":"https:\/\/doi.org\/10.1371\/journal.pmed.1003356","relation":{},"ISSN":["1549-1676"],"issn-type":[{"value":"1549-1676","type":"electronic"}],"subject":[],"published":{"date-parts":[[2020,9,28]]}}}