{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,5,28]],"date-time":"2026-05-28T10:06:06Z","timestamp":1779962766012,"version":"3.53.1"},"reference-count":12,"publisher":"Charles University in Prague, Karolinum Press","issue":"4","license":[{"start":{"date-parts":[[2026,1,2]],"date-time":"2026-01-02T00:00:00Z","timestamp":1767312000000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"},{"start":{"date-parts":[[2026,1,2]],"date-time":"2026-01-02T00:00:00Z","timestamp":1767312000000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"abstract":"<jats:p>Freeman-Sheldon syndrome is a rare form of multiple congenital contracture syndromes (arthrogryposes) and is the most severe form of distal arthrogryposis. The main skeletal malformations include camptodactyly with ulnar deviation and talipes equinovarus while facial characteristics include deep-sunken eyes with hypertelorism, increased philtrum length, small nose and nostrils, and a small mouth. Here we report a rare case of Freeman-Sheldon syndrome (FSS) in an 8-years-old patient giving emphasis on the dental management of FSS.<\/jats:p>","DOI":"10.14712\/23362936.2025.37","type":"journal-article","created":{"date-parts":[[2026,1,2]],"date-time":"2026-01-02T10:08:48Z","timestamp":1767348528000},"page":"238-242","source":"Crossref","is-referenced-by-count":0,"special_numbering":"4\/2025","title":["Freeman-Sheldon Syndrome: A Rare Case Report with Dental Perspective"],"prefix":"10.14712","volume":"126","author":[{"given":"Sahil Mustafa","family":"Kidwai","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-5659-8679","authenticated-orcid":false,"given":"Suman","family":"Sen","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Nikil Kumar","family":"Jain","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Sudhir Ramesh","family":"Maheshkar","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"5727","published-online":{"date-parts":[[2026,1,2]]},"reference":[{"key":"23362936.2025.37_1","doi-asserted-by":"crossref","first-page":"184","DOI":"10.4103\/0970-4388.117978","volume":"31","author":"Bijumon","year":"2013","journal-title":"J. Indian Soc. Pedod. Prev. Dent."},{"key":"23362936.2025.37_2","first-page":"311","volume":"16","author":"Biria","year":"2015","journal-title":"Eur. J. Paediatr. Dent."},{"key":"23362936.2025.37_3","first-page":"71","volume":"16","author":"Buyukavci","year":"2005","journal-title":"Genet. Couns."},{"key":"23362936.2025.37_4","doi-asserted-by":"crossref","first-page":"277","DOI":"10.1136\/adc.13.75.277","volume":"13","author":"Freeman","year":"1938","journal-title":"Arch. Dis. Child."},{"key":"23362936.2025.37_5","doi-asserted-by":"crossref","first-page":"388","DOI":"10.1007\/BF03010755","volume":"33","author":"Laishley","year":"1986","journal-title":"Can. Anaesth. Soc. 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Case Rep."},{"key":"23362936.2025.37_11","doi-asserted-by":"crossref","first-page":"222","DOI":"10.14712\/23362936.2021.20","volume":"122","author":"Sen","year":"2021","journal-title":"Prague Med. Rep."},{"key":"23362936.2025.37_12","doi-asserted-by":"crossref","first-page":"681","DOI":"10.1086\/368294","volume":"72","author":"Sung","year":"2003","journal-title":"Am. J. Hum. Genet."}],"container-title":["PRAGUE MEDICAL REPORT"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/pmr.lf1.cuni.cz\/media\/pdf\/pmr_2025126040238.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/pmr.lf1.cuni.cz\/media\/pdf\/pmr_2025126040238.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,5,28]],"date-time":"2026-05-28T09:33:14Z","timestamp":1779960794000},"score":1,"resource":{"primary":{"URL":"https:\/\/pmr.lf1.cuni.cz\/126\/4\/0238\/"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2026,1,2]]},"references-count":12,"journal-issue":{"issue":"4","published-online":{"date-parts":[[2026,1,2]]}},"URL":"https:\/\/doi.org\/10.14712\/23362936.2025.37","relation":{},"ISSN":["2336-2936","1214-6994"],"issn-type":[{"value":"2336-2936","type":"electronic"},{"value":"1214-6994","type":"print"}],"subject":[],"published":{"date-parts":[[2026,1,2]]}}}