{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,5,7]],"date-time":"2026-05-07T19:10:02Z","timestamp":1778181002150,"version":"3.51.4"},"reference-count":26,"publisher":"Walter de Gruyter GmbH","issue":"1","license":[{"start":{"date-parts":[[2020,1,1]],"date-time":"2020-01-01T00:00:00Z","timestamp":1577836800000},"content-version":"unspecified","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2020,11,14]]},"abstract":"<jats:title>Abstract<\/jats:title>\n               <jats:p>Rapunzel syndrome, defined by the presence of a trichobezoar extending from the stomach to the small intestine, is a rare cause of intestinal obstruction. It usually presents with vague symptoms; however, it can also present with complications such as perforation, peritonitis and obstructive jaundice. We report a rare case of a 37-year-old woman with Rapunzel syndrome complicated by acute cholangitis and pancreatitis and analyse the diagnosis and management of this complicated pathology. Although she reported a history of trichotillomania and trichophagia, she had been asymptomatic for ten years. We review the steps of diagnosis, highlighting the importance of a thorough clinical history and detailed examination, with supporting evidence from the contrast-enhanced computed tomography (CECT) scan. She was successfully managed with gastrotomy and trichobezoar removal. She had an uneventful postoperative recovery and was discharged after psychiatric counselling. To our knowledge, this is the first case of Rapunzel syndrome in a young female presenting with both cholangitis and pancreatitis.<\/jats:p>","DOI":"10.1515\/med-2020-0243","type":"journal-article","created":{"date-parts":[[2020,11,30]],"date-time":"2020-11-30T21:20:04Z","timestamp":1606771204000},"page":"1137-1142","source":"Crossref","is-referenced-by-count":11,"title":["Rapunzel syndrome with cholangitis and pancreatitis\u2009\u2013\u2009A rare case report"],"prefix":"10.1515","volume":"15","author":[{"given":"Rajendran","family":"Vellaisamy","sequence":"first","affiliation":[{"name":"Institute of Surgical Gastroenterology, Center of Excellence in Upper GI Surgery, Madras Medical College , Chennai , India 600003, EsoIndia Research Volunteer"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Shruti","family":"Iyer","sequence":"additional","affiliation":[{"name":"Sri Ramachandra Institute of Higher Education and Research, EsoIndia Research Volunteer , No. 1, Ramachandra Nagar, Porur , Chennai 600116 , India"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Servarayan Murugesan","family":"Chandramohan","sequence":"additional","affiliation":[{"name":"International Students Programme, Sri Ramachandra Institute of Higher Education and Research, President and Founder \u2013 EsoIndia , Chennai 600116 , India"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Sakthivel","family":"Harikrishnan","sequence":"additional","affiliation":[{"name":"MCh Surgical Gastroenterology Resident, Department of Surgical Gastroenterology & Liver Transplant, Government Stanley Medical College EsoIndia Research Volunteer , Chennai 600001 , India"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"374","published-online":{"date-parts":[[2020,11,14]]},"reference":[{"key":"2022052423242012163_j_med-2020-0243_ref_001_w2aab3b7d944b1b6b1ab2b2b1Aa","unstructured":"Vaughan ED, Sawyers JL, Scott HW. The Rapunzel syndrome: an unusual complication of intestinal bezoar. Surgery. 1968;63(2):339\u201343."},{"key":"2022052423242012163_j_med-2020-0243_ref_002_w2aab3b7d944b1b6b1ab2b2b2Aa","doi-asserted-by":"crossref","unstructured":"Obinwa O, Cooper D, Khan F, O\u2019Riordan JM. Rapunzel syndrome is not just a mere surgical problem: a case report and review of current management. World J Clin Cases. 2017;5(2):50\u20135.","DOI":"10.12998\/wjcc.v5.i2.50"},{"key":"2022052423242012163_j_med-2020-0243_ref_003_w2aab3b7d944b1b6b1ab2b2b3Aa","unstructured":"Tripodi V, Caruso A, Luraghi M, Armao FT, Bisagni P, Romano S, et al. Paediatric gastric trichobezoar: the Rapunzel syndrome A report of two cases. Ann Ital Chir. 2020;9:9."},{"key":"2022052423242012163_j_med-2020-0243_ref_004_w2aab3b7d944b1b6b1ab2b2b4Aa","unstructured":"Ahmad Z, Sharma A, Ahmed M, Vatti V. Trichobezoar causing gastric perforation: a case report. Iran J Med Sci. 2016;41(1):67\u201370."},{"key":"2022052423242012163_j_med-2020-0243_ref_005_w2aab3b7d944b1b6b1ab2b2b5Aa","doi-asserted-by":"crossref","unstructured":"Janssen-Aguilar R, Rochel-P\u00e9rez A, Cuevas-Koh OJ, Santos-Zaldivar KD, Rodr\u00edguez-Cuevas M, Inurreta-D\u00edaz MJ, et al. Systematic review of Rapunzel Syndrome. Rev Biomed. 2020;31(1):38\u201357.","DOI":"10.32776\/revbiomed.v30i3.678"},{"key":"2022052423242012163_j_med-2020-0243_ref_006_w2aab3b7d944b1b6b1ab2b2b6Aa","doi-asserted-by":"crossref","unstructured":"Fallon SC, Slater BJ, Larimer EL, Brandt ML, Lopez ME. The surgical management of Rapunzel syndrome: a case series and literature review. J Pediatr Surg. 2013;48(4):830\u20134.","DOI":"10.1016\/j.jpedsurg.2012.07.046"},{"key":"2022052423242012163_j_med-2020-0243_ref_007_w2aab3b7d944b1b6b1ab2b2b7Aa","unstructured":"Khan AA, Alam T, Faizi R, Maroof S. Trichobezoar: case report. 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