{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:35:10Z","timestamp":1787754910043,"version":"build-2784847793"},"reference-count":13,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"3","content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["JBJS Case Connector"],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>A 29-year-old man with mild hemophilia A and Ollier disease presented with bilateral atraumatic forearm pseudotumors. Both forearm pseudotumors were successfully treated surgically with staged radical extirpation and factor VIII replacement therapy.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>Pseudotumors typically occur in adolescents with severe, poorly controlled hemophilia A. The development of factor VIII replacement therapy has progressively reduced the incidence of pseudotumors in patients in the developed world. No standardized therapy exists for pseudotumors that continue to bleed into the muscles despite nonoperative measures. Persistent masses require surgical removal with careful preoperative planning and a team approach.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.17.00234","type":"journal-article","created":{"date-parts":[[2018,7,25]],"date-time":"2018-07-25T00:26:59Z","timestamp":1532478419000},"page":"e54-e54","source":"Crossref","is-referenced-by-count":2,"title":["Bilateral Forearm Pseudotumors in an Adult with Hemophilia A and Ollier Disease"],"prefix":"10.2106","volume":"8","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-5292-6919","authenticated-orcid":false,"given":"Barkha","family":"Gurbani","sequence":"first","affiliation":[{"name":"Department of Orthopaedic Surgery and Rehabilitation, University of Texas Medical Branch at Galveston, Galveston, Texas"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-1621-3214","authenticated-orcid":false,"given":"Matthew","family":"Igbinigie","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery and Rehabilitation, University of Texas Medical Branch at Galveston, Galveston, Texas"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-0836-359X","authenticated-orcid":false,"given":"Aristides","family":"Koutrouvelis","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery and Rehabilitation, University of Texas Medical Branch at Galveston, Galveston, Texas"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-5519-4461","authenticated-orcid":false,"given":"Jack B.","family":"Alperin","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery and Rehabilitation, University of Texas Medical Branch at Galveston, Galveston, Texas"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-3223-0252","authenticated-orcid":false,"given":"Ronald W.","family":"Lindsey","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery and Rehabilitation, University of Texas Medical Branch at Galveston, Galveston, Texas"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2018,9]]},"reference":[{"issue":"11","key":"bib1-20230811","doi-asserted-by":"crossref","first-page":"2546","DOI":"10.2106\/00004623-200511000-00024","article-title":"Hemophilic pseudotumor of the distal parts of the radius and ulna. A case report","volume":"87","author":"Shaheen","year":"2005","journal-title":"J Bone Joint Surg Am."},{"issue":"Suppl 1","key":"bib2-20230811","first-page":"S39","article-title":"Surgery\u2014a challenge in haemophiliacs with inhibitors","volume":"29","author":"Serban","year":"2009","journal-title":"Hamostaseologie."},{"issue":"8","key":"bib3-20230811","doi-asserted-by":"crossref","first-page":"1133","DOI":"10.2106\/00004623-197557080-00020","article-title":"On the natural history of hemophilic pseudotumor","volume":"57","author":"Ahlberg","year":"1975","journal-title":"J Bone Joint Surg Am."},{"issue":"12","key":"bib4-20230811","doi-asserted-by":"crossref","first-page":"1262","DOI":"10.1038\/ng.994","article-title":"Ollier disease and Maffucci syndrome are caused by somatic mosaic mutations of IDH1 and IDH2","volume":"43","author":"Amary","year":"2011","journal-title":"Nat Genet."},{"issue":"10","key":"bib5-20230811","first-page":"774","article-title":"Ollier\u2019s disease with myelodysplastic syndrome","volume":"25","author":"Faizan","year":"2015","journal-title":"J Coll Physicians Surg Pak."},{"issue":"3","key":"bib7-20230811","doi-asserted-by":"crossref","first-page":"393","DOI":"10.1046\/j.1365-2516.2002.00609.x","article-title":"Haemophilic cysts (pseudotumours)","volume":"8","author":"Rodriguez-Merchan","year":"2002","journal-title":"Haemophilia."},{"issue":"4","key":"bib8-20230811","doi-asserted-by":"crossref","first-page":"e369","DOI":"10.1097\/SCS.0000000000000856","article-title":"Bilateral cranial hemophilic pseudotumor","volume":"25","author":"Xu","year":"2014","journal-title":"J Craniofac Surg."},{"issue":"7","key":"bib9-20230811","doi-asserted-by":"crossref","first-page":"828","DOI":"10.1016\/j.ijporl.2010.04.003","article-title":"Multidisciplinary management of expanding bilateral neck hematomas in a patient with hemophilia A with high-titer inhibitor","volume":"74","author":"Jaryszak","year":"2010","journal-title":"Int J Pediatr Otorhinolaryngol."},{"issue":"4","key":"bib10-20230811","doi-asserted-by":"crossref","first-page":"622","DOI":"10.3892\/mco.2016.736","article-title":"Bilateral recurrent external obturator muscle hematoma: an unusual cause of pelvic pain in hemophilia","volume":"4","author":"Arpaci","year":"2016","journal-title":"Mol Clin Oncol."},{"issue":"5","key":"bib11-20230811","first-page":"406","article-title":"[Clinical characteristics and rehabilitation treatment of iliopsoas hemorrage in 41 patients with hemophilia]","volume":"33","author":"Chen","year":"2012","journal-title":"Zhonghua Xue Ye Xue Za Zhi."},{"issue":"10","key":"bib12-20230811","doi-asserted-by":"crossref","first-page":"2157","DOI":"10.1007\/s00264-012-1593-7","article-title":"Surgical treatment of the haemophilic pseudotumour: a single centre experience","volume":"36","author":"Panotopoulos","year":"2012","journal-title":"Int Orthop."},{"key":"bib13-20230811","first-page":"257","article-title":"The hemophilic pseudotumor","volume":"324","author":"Gilbert","year":"1990","journal-title":"Prog Clin Biol Res."},{"issue":"2","key":"bib14-20230811","doi-asserted-by":"crossref","first-page":"103","DOI":"10.1002\/ajh.2830450202","article-title":"Hemophilic pseudotumor: multicenter experience over a 25-year period","volume":"45","author":"Magall\u00f3n","year":"1994","journal-title":"Am J Hematol."}],"container-title":["JBJS Case Connector"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/01709767-201809000-00010","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T13:34:42Z","timestamp":1787751282000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/01709767-201809000-00010"}},"subtitle":["A Case Report"],"short-title":[],"issued":{"date-parts":[[2018,7,25]]},"references-count":13,"journal-issue":{"issue":"3","published-online":{"date-parts":[[2018]]}},"URL":"https:\/\/doi.org\/10.2106\/jbjs.cc.17.00234","relation":{},"ISSN":["2160-3251"],"issn-type":[{"value":"2160-3251","type":"electronic"}],"subject":[],"published":{"date-parts":[[2018,7,25]]}}}