{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:35:14Z","timestamp":1787754914937,"version":"build-2784847793"},"reference-count":12,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"3","content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["JBJS Case Connector"],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>We report the case of a patient with a long-standing and progressive forearm deformity, secondary to underlying hereditary multiple exostoses (HME). A salvage surgery was performed with excision of the pathologic parts of the radius and the ulna, followed by the creation of a 1-bone forearm.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>One of the common manifestations of HME is forearm deformity due to abnormal ossification and osteochondromas that affect the radius and\/or the ulna. Progressive deformity can lead to increasing pain, joint instability, limited motion, and functional decline. Neglected or recalcitrant deformities pose a treatment challenge. At 1.5 years after surgery, the patient had a satisfactory outcome with a fully functional, pain-free forearm in a fixed, neutral position.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.17.00295","type":"journal-article","created":{"date-parts":[[2018,7,25]],"date-time":"2018-07-25T00:26:59Z","timestamp":1532478419000},"page":"e53-e53","source":"Crossref","is-referenced-by-count":3,"title":["A Rare Presentation and Management of Forearm Deformity in a Patient with Hereditary Multiple Exostoses"],"prefix":"10.2106","volume":"8","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-5475-2086","authenticated-orcid":false,"given":"Mandar","family":"Agashe","sequence":"first","affiliation":[{"name":"Center for Pediatric Orthopedic Care, Mumbai, India"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-3933-131X","authenticated-orcid":false,"given":"Avi","family":"Shah","sequence":"additional","affiliation":[{"name":"Cincinnati Children\u2019s Hospital, Cincinnati, Ohio"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-4391-0525","authenticated-orcid":false,"given":"Shital N.","family":"Parikh","sequence":"additional","affiliation":[{"name":"Cincinnati Children\u2019s Hospital, Cincinnati, Ohio"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2018,9]]},"reference":[{"key":"bib1-20230811","first-page":"969","article-title":"Ueber knochen und gelenkanomalieen, insbesondere bei partiellem riesenwuchs und bei multiplen cartilaginaren exostosen","volume":"41","author":"Bessel Hagen","year":"1891","journal-title":"Arch Klin Chir."},{"key":"bib2-20230811","first-page":"335","article-title":"Hereditary multiple exostosis","volume":"36","author":"Jaffe","year":"1943","journal-title":"Arch Pathol Lab Med."},{"issue":"6","key":"bib3-20230811","doi-asserted-by":"crossref","first-page":"815","DOI":"10.2106\/00004623-197961060-00003","article-title":"Hereditary multiple exostoses. Anthropometric, roentgenographic, and clinical aspects","volume":"61","author":"Shapiro","year":"1979","journal-title":"J Bone Joint Surg Am."},{"issue":"1","key":"bib4-20230811","doi-asserted-by":"crossref","first-page":"24","DOI":"10.1302\/0301-620X.71B1.2914999","article-title":"Operations for forearm deformity caused by multiple osteochondromas","volume":"71","author":"Masada","year":"1989","journal-title":"J Bone Joint Surg Br."},{"issue":"5","key":"bib5-20230811","doi-asserted-by":"crossref","first-page":"670","DOI":"10.2106\/00004623-198466050-00004","article-title":"Management of deformities of the forearm in multiple hereditary osteochondromas","volume":"66","author":"Fogel","year":"1984","journal-title":"J Bone Joint Surg Am."},{"issue":"1","key":"bib6-20230811","doi-asserted-by":"crossref","first-page":"92","DOI":"10.1097\/01241398-199401000-00019","article-title":"Deformities and problems of the forearm in children with multiple hereditary osteochondromata","volume":"14","author":"Peterson","year":"1994","journal-title":"J Pediatr Orthop."},{"issue":"2","key":"bib7-20230811","first-page":"351","article-title":"Radio-ulnar fusion for defects in the forearm bones","volume":"45-B","author":"Lowe","year":"1963","journal-title":"Bone Joint J."},{"issue":"4","key":"bib8-20230811","doi-asserted-by":"crossref","first-page":"804","DOI":"10.2106\/00004623-195234040-00007","article-title":"Reconstructive surgery for defects in the shaft of the ulna in children","volume":"34","author":"Vitale","year":"1952","journal-title":"J Bone Joint Surg Am."},{"issue":"2","key":"bib9-20230811","doi-asserted-by":"crossref","first-page":"95","DOI":"10.1097\/BPB.0b013e3282f54849","article-title":"The ulnius: a one-bone forearm in children","volume":"17","author":"Peterson","year":"2008","journal-title":"J Pediatr Orthop B."},{"issue":"5","key":"bib10-20230811","doi-asserted-by":"crossref","first-page":"587","DOI":"10.1097\/01241398-199309000-00006","article-title":"One-bone forearm as a salvage procedure for recalcitrant forearm deformity in hereditary multiple exostoses","volume":"13","author":"Rodgers","year":"1993","journal-title":"J Pediatr Orthop."},{"issue":"3","key":"bib11-20230811","doi-asserted-by":"crossref","first-page":"290","DOI":"10.1097\/01241398-198505000-00006","article-title":"One-bone forearm procedure for partial defect of the ulna","volume":"5","author":"Kitano","year":"1985","journal-title":"J Pediatr Orthop."},{"issue":"4","key":"bib12-20230811","doi-asserted-by":"crossref","first-page":"609","DOI":"10.1016\/S0363-5023(05)80277-1","article-title":"Clinical results of the one-bone forearm","volume":"20","author":"Peterson","year":"1995 Jul","journal-title":"J Hand Surg Am."}],"container-title":["JBJS Case Connector"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/01709767-201809000-00009","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T13:34:47Z","timestamp":1787751287000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/01709767-201809000-00009"}},"subtitle":["A Case Report"],"short-title":[],"issued":{"date-parts":[[2018,7,25]]},"references-count":12,"journal-issue":{"issue":"3","published-online":{"date-parts":[[2018]]}},"URL":"https:\/\/doi.org\/10.2106\/jbjs.cc.17.00295","relation":{},"ISSN":["2160-3251"],"issn-type":[{"value":"2160-3251","type":"electronic"}],"subject":[],"published":{"date-parts":[[2018,7,25]]}}}