{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:38:42Z","timestamp":1787755122519,"version":"build-2784847793"},"reference-count":17,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"2","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>A 51-year-old woman presented with a 2-month history of pain in the right thigh. Radiography and computed tomography of the pelvis showed cortical hyperostosis of the right ilium. She was diagnosed with meralgia paresthetica (MP) caused by melorheostosis involving the right ilium. After 6 weeks of conservative management, an operation was performed for the persisting pain. At the 1-year follow-up, no findings of recurrence were observed clinically and radiographically.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>MP, caused by proximal irritation of the lateral femoral cutaneous nerve, can occur because of melorheostosis, which is a rare condition.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.20.00727","type":"journal-article","created":{"date-parts":[[2021,4,2]],"date-time":"2021-04-02T15:00:09Z","timestamp":1617375609000},"update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Meralgia Paresthetica Caused by Melorheostosis Affecting the Ipsilateral Ilium"],"prefix":"10.2106","volume":"11","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-4433-6932","authenticated-orcid":false,"given":"Hideaki","family":"Miyoshi","sequence":"first","affiliation":[{"name":"Department of Orthopedic Surgery, Marugame Medical Center, Kagawa, Japan"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-4346-1643","authenticated-orcid":false,"given":"Takehiko","family":"Nishisho","sequence":"additional","affiliation":[{"name":"Department of Orthopedic Surgery, Marugame Medical Center, Kagawa, Japan"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2021,4]]},"reference":[{"key":"bib1-20240731","first-page":"1141","article-title":"Une affection non d\u00e9crite des os: hyperostose \u201cen coul\u00e9e\u201d sur toute la longeur d'un membre ou \u201cmelorh\u00e9ostose\u201d","volume":"46","author":"Leri","year":"1922","journal-title":"Bull Mem Soc Med Hosp Paris."},{"issue":"7","key":"bib2-20240731","doi-asserted-by":"crossref","first-page":"1281","DOI":"10.2106\/00004623-196850070-00001","article-title":"Melorheostosis. A report of the clinical, roentgenographic, and pathological findings in fourteen cases","volume":"50","author":"Campbell","year":"1968","journal-title":"J Bone Joint Surg Am."},{"issue":"3","key":"bib4-20240731","doi-asserted-by":"crossref","first-page":"283","DOI":"10.1016\/j.pmrj.2016.07.530","article-title":"Melorheostosis: a retrospective clinical analysis of 24 patients at the Mayo Clinic","volume":"9","author":"Smith","year":"2017","journal-title":"PM R."},{"issue":"3","key":"bib5-20240731","doi-asserted-by":"crossref","first-page":"474","DOI":"10.1007\/s003300000562","article-title":"Melorheostosis: a review of 23 cases","volume":"11","author":"Freyschmidt","year":"2001","journal-title":"Eur Radiol."},{"issue":"11","key":"bib6-20240731","doi-asserted-by":"crossref","first-page":"12","DOI":"10.3941\/jrcr.v12i11.3539","article-title":"Melorheostosis of the leg: a case report","volume":"12","author":"Alothman","year":"2018","journal-title":"J Radiol Case Rep."},{"issue":"1","key":"bib7-20240731","doi-asserted-by":"crossref","first-page":"84","DOI":"10.1136\/jnnp.2005.072363","article-title":"Meralgia paresthetica (Bernhardt-Roth syndrome)","volume":"77","author":"Pearce","year":"2006","journal-title":"J Neurol Neurosurg Psychiatry."},{"issue":"5","key":"bib8-20240731","first-page":"324","article-title":"Bone dysplasia series. Melorheostosis: review and update","volume":"50","author":"Greenspan","year":"1999","journal-title":"Can Assoc Radiol J."},{"key":"bib9-20240731","doi-asserted-by":"crossref","first-page":"1191","DOI":"10.2106\/00004623-196345060-00007","article-title":"Melorheostosis. Review of the literature and report of an interesting case with a nineteen-year follow-up","volume":"45","author":"Morris","year":"1963","journal-title":"J Bone Joint Surg Am."},{"issue":"2","key":"bib10-20240731","doi-asserted-by":"crossref","first-page":"57","DOI":"10.1007\/BF00349329","article-title":"Melorheostosis and the sclerotomes: a radiological correlation","volume":"4","author":"Murray","year":"1979","journal-title":"Skeletal Radiol."},{"issue":"11","key":"bib11-20240731","doi-asserted-by":"crossref","first-page":"1213","DOI":"10.1038\/ng1453","article-title":"Loss-of-function mutations in LEMD3 result in osteopoikilosis, Buschke-Ollendorff syndrome and melorheostosis","volume":"36","author":"Hellemans","year":"2004","journal-title":"Nat Genet."},{"issue":"1","key":"bib12-20240731","doi-asserted-by":"crossref","first-page":"1390","DOI":"10.1038\/s41467-018-03720-z","article-title":"Somatic activating mutations in MAP2K1 cause melorheostosis","volume":"9","author":"Kang","year":"2018","journal-title":"Nat Commun."},{"issue":"3","key":"bib13-20240731","doi-asserted-by":"crossref","first-page":"273","DOI":"10.3928\/0147-7447-20010301-20","article-title":"Histopathological characterization of melorheostosis","volume":"24","author":"Hoshi","year":"2001","journal-title":"Orthopedics."},{"issue":"4","key":"bib14-20240731","doi-asserted-by":"crossref","first-page":"335","DOI":"10.1007\/s11914-017-0375-y","article-title":"Melorheostosis: a rare sclerosing bone dysplasia","volume":"15","author":"Kotwal","year":"2017","journal-title":"Curr Osteoporos Rep."},{"issue":"2","key":"bib15-20240731","first-page":"25","article-title":"Melorheostosis-case report of rare disease","volume":"4","author":"Kumar","year":"2014","journal-title":"J Orthop Case Rep."},{"issue":"12","key":"bib16-20240731","doi-asserted-by":"crossref","first-page":"709","DOI":"10.1007\/s00256-002-0576-y","article-title":"Atypical form of active melorheostosis and its treatment with bisphosphonate","volume":"31","author":"Don\u00e1th","year":"2002","journal-title":"Skeletal Radiol."},{"issue":"12","key":"bib17-20240731","doi-asserted-by":"crossref","first-page":"2759","DOI":"10.2106\/00004623-200512000-00022","article-title":"Severe myelopathy resulting from melorheostosis of the cervicothoracic spine. A case report","volume":"87","author":"Zeiller","year":"2005","journal-title":"J Bone Joint Surg Am"},{"key":"bib18-20240731","doi-asserted-by":"crossref","first-page":"1","DOI":"10.1016\/j.wneu.2019.04.208","article-title":"Melorheostosis causing compression of common peroneal nerve at fibular tunnel","volume":"128","author":"Puffer","year":"2019","journal-title":"World Neurosurg."}],"container-title":["JBJS Case Connector"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.20.00727","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T13:37:55Z","timestamp":1787751475000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.20.00727"}},"subtitle":["A Case Report"],"short-title":[],"issued":{"date-parts":[[2021,4]]},"references-count":17,"journal-issue":{"issue":"2","published-online":{"date-parts":[[2021]]}},"URL":"https:\/\/doi.org\/10.2106\/jbjs.cc.20.00727","relation":{},"ISSN":["2160-3251"],"issn-type":[{"value":"2160-3251","type":"electronic"}],"subject":[],"published":{"date-parts":[[2021,4]]}}}