{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:41:10Z","timestamp":1787755270584,"version":"build-2784847793"},"reference-count":7,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"3","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>We present the case of a patient who developed scaphoid avascular necrosis in the setting of scaphoid hypoplasia, 37 years after an index finger repositioning for thumb agenesis, due to Holt-Oram syndrome.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>To the best of our knowledge, this is a unique case of scaphoid avascular necrosis in a patient with Holt-Oram syndrome with scaphoid hypoplasia who underwent index finger repositioning 37 years earlier. Her wrist pain was successfully treated with scaphoid excision and intercarpal fusion.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.21.00428","type":"journal-article","created":{"date-parts":[[2022,8,30]],"date-time":"2022-08-30T08:16:23Z","timestamp":1661847383000},"update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Preiser's Disease as a Consequence of Scaphoid Hypoplasia After Remote Index Finger Repositioning"],"prefix":"10.2106","volume":"12","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-8513-6710","authenticated-orcid":false,"given":"William","family":"Pipkin","sequence":"first","affiliation":[{"name":"Department of Orthopaedic Surgery, JPS Health Network, Fort Worth, Texas"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Alex","family":"Frangenberg","sequence":"additional","affiliation":[{"name":"University of North Texas Health Science Center, Fort Worth, Texas"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-4202-9798","authenticated-orcid":false,"given":"William F.","family":"Pientka","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, JPS Health Network, Fort Worth, Texas"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2022,7]]},"reference":[{"issue":"10","key":"bib1-20240805","doi-asserted-by":"crossref","first-page":"1400","DOI":"10.1302\/0301-620X.91B10.22498","article-title":"Bilateral idiopathic avascular necrosis of the scaphoid: a rare case of Preiser's disease","volume":"91","author":"Imam","year":"2009","journal-title":"J Bone Joint Surg Br."},{"issue":"2","key":"bib2-20240805","doi-asserted-by":"crossref","first-page":"159","DOI":"10.1055\/s-0032-1329591","article-title":"Treatment of avascular necrosis of the proximal pole of the scaphoid by arthroscopic resection and prosthetic semireplacement arthroplasty using the pyrocarbon adaptive proximal scaphoid implant (Apsi): long-term functional outcomes","volume":"1","author":"Gras","year":"2012","journal-title":"J Wrist Surg."},{"issue":"13","key":"bib3-20240805","doi-asserted-by":"crossref","first-page":"885","DOI":"10.1056\/NEJM199403313301302","article-title":"The clinical and genetic spectrum of the Holt-Oram syndrome (Heart-hand syndrome)","volume":"330","author":"Basson","year":"1994","journal-title":"N Engl J Med."},{"issue":"4","key":"bib4-20240805","doi-asserted-by":"crossref","first-page":"538","DOI":"10.1016\/S0022-3476(79)80758-1","article-title":"Holt-Oram syndrome","volume":"95","author":"Smith","year":"1979","journal-title":"J Pediatr."},{"issue":"1","key":"bib5-20240805","doi-asserted-by":"crossref","first-page":"112","DOI":"10.1054\/jhsb.1999.0286","article-title":"Bipartite scaphoid with proximal pole osteonecrosis in a patient with Holt-Oram syndrome","volume":"25","author":"Tate","year":"2000","journal-title":"J Hand Surg Br."},{"issue":"2","key":"bib6-20240805","doi-asserted-by":"crossref","first-page":"140","DOI":"10.1007\/s11552-008-9144-9","article-title":"Fracture of the proximal pole of the bipartite carpal scaphoid: a probable Holt-Oram-like syndrome","volume":"4","author":"Saccomanni","year":"2009","journal-title":"Hand (N Y)."},{"key":"bib7-20240805","doi-asserted-by":"crossref","first-page":"82","DOI":"10.1016\/S1297-3203(00)73464-0","article-title":"Avascular nontraumatic necrosis of the scaphoid. Preiser's disease?","volume":"19","author":"de Smet","year":"2000","journal-title":"Chir Main."}],"container-title":["JBJS Case Connector"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.21.00428","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T13:40:23Z","timestamp":1787751623000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.21.00428"}},"subtitle":["A Case Report"],"short-title":[],"issued":{"date-parts":[[2022,7]]},"references-count":7,"journal-issue":{"issue":"3","published-online":{"date-parts":[[2022]]}},"URL":"https:\/\/doi.org\/10.2106\/jbjs.cc.21.00428","relation":{},"ISSN":["2160-3251"],"issn-type":[{"value":"2160-3251","type":"electronic"}],"subject":[],"published":{"date-parts":[[2022,7]]}}}