{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:42:02Z","timestamp":1787755322654,"version":"build-2784847793"},"reference-count":16,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"1","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>We describe an adult patient with bilateral Sprengel deformity (BSD) with bilateral omovertebral bone and thoracic spinal failure of segmentation (T2-T4) successfully surgically treated only at 19-year-old. After resection of the bilateral omovertebral bone and simultaneous relocation of the scapula, disabilities of the arm, shoulder, and hand score improved from 26.7 preoperatively to 2.5 at the 3-year follow-up.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>The surgical treatment of Sprengel deformity is typically recommended between 3 and 7 years of age when significant shoulder impairment and\/or severe cosmetic concerns are present. The authors were able to achieve a successful surgical outcome in a patient with BSD despite an unusual late presentation.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.22.00217","type":"journal-article","created":{"date-parts":[[2023,2,3]],"date-time":"2023-02-03T14:04:38Z","timestamp":1675433078000},"update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":4,"title":["Bilateral Sprengel Deformity With Bilateral Omovertebral Bone: An Unusual Case in an Adult Patient"],"prefix":"10.2106","volume":"13","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-0641-6253","authenticated-orcid":false,"given":"Joana","family":"P\u00e1scoa Pinheiro","sequence":"first","affiliation":[{"name":"Centro Hospitalar Universit\u00e1rio Lisboa Norte (North Lisbon University Hospital Centre), Lisbon, Portugal."}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Pedro","family":"Fernandes","sequence":"additional","affiliation":[{"name":"Centro Hospitalar Universit\u00e1rio Lisboa Norte (North Lisbon University Hospital Centre), Lisbon, Portugal."}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Marco","family":"Sarmento","sequence":"additional","affiliation":[{"name":"Centro Hospitalar Universit\u00e1rio Lisboa Norte (North Lisbon University Hospital Centre), Lisbon, Portugal."}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2023,1]]},"reference":[{"issue":"3","key":"bib1-20240731","doi-asserted-by":"crossref","first-page":"177","DOI":"10.5435\/JAAOS-20-03-177","article-title":"Sprengel deformity: pathogenesis and management","volume":"20","author":"Harvey","year":"2012","journal-title":"J Am Acad Orthop Surg."},{"key":"bib3-20240731","first-page":"545","article-title":"Die angeborene verschiebung des schulterblattes nach oben","volume":"42","author":"Sprengel","year":"1891","journal-title":"Archiv Fur Klinische Chirurgie."},{"issue":"2","key":"bib4-20240731","doi-asserted-by":"crossref","first-page":"158","DOI":"10.1002\/1096-8628(20010615)101:2<158::AID-AJMG1343>3.0.CO;2-4","article-title":"Klippel-Feil anomaly with Sprengel anomaly, omovertebral bone, thumb abnormalities, and flexion-crease changes: novel association or syndrome?","volume":"101","author":"Larson","year":"2001","journal-title":"Am J Med Genet."},{"issue":"3","key":"bib5-20240731","doi-asserted-by":"crossref","first-page":"395","DOI":"10.1302\/0301-620X.54B3.395","article-title":"Congenital elevation of the scapula","volume":"54-B","author":"Cavendish","year":"1972","journal-title":"J Bone Joint Surg Br."},{"issue":"4","key":"bib6-20240731","first-page":"e1900120","article-title":"Sprengel deformity in biological sisters","volume":"4","author":"Pargas","year":"2020","journal-title":"JAAOS."},{"issue":"2","key":"bib7-20240731","doi-asserted-by":"crossref","first-page":"252","DOI":"10.1016\/j.jse.2017.08.011","article-title":"The congenital undescended scapula syndrome: sprengel and the cleithrum: a case series and hypothesis","volume":"27","author":"Dhir","year":"2018","journal-title":"J Shoulder Elbow Surg."},{"key":"bib8-20240731","first-page":"13","article-title":"Sprengel deformity: magnetic resonance imaging findings in two pediatric cases","volume":"1","author":"Dilli","year":"2011","journal-title":"J Clin Imaging Sci."},{"issue":"1","key":"bib9-20240731","first-page":"5","article-title":"[Congenital elevation of the scapula in children. 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