{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:41:57Z","timestamp":1787755317643,"version":"build-2784847793"},"reference-count":14,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"4","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>This is a case of a female patient born with thrombocytopenia-absent radius syndrome, with bilateral upper extremity phocomelia, bilateral hip dislocations, and congenital fusion of the right knee with progressively worsening flexion contracture. At age 3 years and 5 months, the patient was treated with excision of the knee ankylosis and Van Nes rotationplasty. This proved durable at age 20 years (final follow-up) without any need for further surgery and without complication.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>This is the first known report of Van Nes rotationplasty as a durable treatment option in the management of congenital knee ankylosis, which may avoid reoperation and eliminate risk of recurrence.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.23.00303","type":"journal-article","created":{"date-parts":[[2023,10,13]],"date-time":"2023-10-13T14:05:09Z","timestamp":1697205909000},"update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Congenital Ankylosis of the Knee Treated with Van Nes Rotationplasty"],"prefix":"10.2106","volume":"13","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-9954-845X","authenticated-orcid":false,"given":"Matthew J.","family":"Siebert","sequence":"first","affiliation":[{"name":"Shriner's Hospital for Children, Salt Lake City, Utah"},{"name":"Primary Children's Hospital, Salt Lake City, Utah"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"James W.","family":"Roach","sequence":"additional","affiliation":[{"name":"Shriner's Hospital for Children, Salt Lake City, Utah"},{"name":"Primary Children's Hospital, Salt Lake City, Utah"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-1863-272X","authenticated-orcid":false,"given":"Alan K.","family":"Stotts","sequence":"additional","affiliation":[{"name":"Shriner's Hospital for Children, Salt Lake City, Utah"},{"name":"Primary Children's Hospital, Salt Lake City, Utah"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2023,10]]},"reference":[{"issue":"4","key":"bib1-20240805","doi-asserted-by":"crossref","first-page":"246","DOI":"10.1097\/BPO.0000000000002356","article-title":"Congenital synostosis of the knee: long-term outcomes of limb reconstruction surgery","volume":"43","author":"Belthur","year":"2023","journal-title":"J Pediatr Orthop."},{"issue":"6","key":"bib2-20240805","doi-asserted-by":"crossref","first-page":"421","DOI":"10.1016\/j.knee.2009.12.004","article-title":"Congenital bony fusion (absence) of the knee: a case report","volume":"17","author":"Madadi","year":"2010","journal-title":"Knee."},{"issue":"4","key":"bib3-20240805","doi-asserted-by":"crossref","first-page":"590","DOI":"10.1302\/0301-620X.86B4.14534","article-title":"Congenital absence (ankylosis) of the knee","volume":"86","author":"Yaniv","year":"2004","journal-title":"J Bone Joint Surg Br."},{"key":"bib4-20240805","first-page":"34","article-title":"Congenital synostosis of the knee","volume":"135","author":"Ryan","year":"1978","journal-title":"Clin Orthop Relat Res."},{"issue":"2","key":"bib5-20240805","first-page":"91","article-title":"Tetraphocomelia and bilateral femorotibial synostosis. 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Impact of the associated 1q21. 1 deletion on the genetic counselling","volume":"54","author":"Houeijeh","year":"2011","journal-title":"Eur J Med Genet."},{"issue":"2","key":"bib8-20240805","doi-asserted-by":"crossref","first-page":"192","DOI":"10.1302\/0301-620X.95B2.30853","article-title":"Long-term follow-up of Van Nes rotationplasty in patients with congenital proximal focal femoral deficiency","volume":"95-B","author":"Ackman","year":"2013","journal-title":"Bone Joint J."},{"issue":"6","key":"bib9-20240805","doi-asserted-by":"crossref","first-page":"462","DOI":"10.3390\/children8060462","article-title":"Rotationplasty for severe congenital femoral deficiency","volume":"8","author":"Fuller","year":"2021","journal-title":"Children."},{"key":"bib10-20240805","doi-asserted-by":"crossref","first-page":"775","DOI":"10.1007\/s00776-012-0278-9","article-title":"Indications for and surgical complications of rotationplasty","volume":"17","author":"Sawamura","year":"2012","journal-title":"J Orthop Sci."},{"issue":"6","key":"bib11-20240805","doi-asserted-by":"crossref","first-page":"1065","DOI":"10.1302\/0301-620X.72B6.2246290","article-title":"Modified Van Nes rotationplasty for osteosarcoma of the proximal tibia in children","volume":"72","author":"de Bari","year":"1990","journal-title":"J Bone Joint Surg Br."},{"key":"bib12-20240805","doi-asserted-by":"crossref","first-page":"74","DOI":"10.1097\/00003086-199101000-00010","article-title":"Modified Van Nes rotationplasty in the treatment of malignant neoplasms in the lower extremities of children","volume":"262","author":"Krajbich","year":"1991","journal-title":"Clin Orthop Relat Res."},{"key":"bib13-20240805","doi-asserted-by":"crossref","first-page":"52","DOI":"10.1097\/01.blo.0000093896.12372.c1","article-title":"Functional outcome of patients with rotationplasty about the knee","volume":"415","author":"Fuchs","year":"2003","journal-title":"Clin Orthop Relat Res."},{"issue":"2","key":"bib14-20240805","doi-asserted-by":"crossref","first-page":"187","DOI":"10.2106\/00004623-200002000-00004","article-title":"Electromyographic and gait analysis of forty-three patients after rotationplasty","volume":"82","author":"Hillmann","year":"2000","journal-title":"J Bone Joint Surg Am."}],"container-title":["JBJS Case Connector"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.23.00303","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T13:41:04Z","timestamp":1787751664000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.23.00303"}},"subtitle":["A Case Report"],"short-title":[],"issued":{"date-parts":[[2023,10]]},"references-count":14,"journal-issue":{"issue":"4","published-online":{"date-parts":[[2023]]}},"URL":"https:\/\/doi.org\/10.2106\/jbjs.cc.23.00303","relation":{},"ISSN":["2160-3251"],"issn-type":[{"value":"2160-3251","type":"electronic"}],"subject":[],"published":{"date-parts":[[2023,10]]}}}