{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:51:09Z","timestamp":1787755869484,"version":"build-2784847793"},"reference-count":8,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"4","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>A 1-year old boy was presented with cauda equina syndrome and progressive loss of motor function in lower limbs. MRI and CT scans revealed a sacrococcygeal teratoma with metastases para-aortically and in L3 producing compression into the epidural space. Despite metastases and a progressive cauda equina, neoadjuvant treatment was given to achieve cytoreduction for neurological recovery and facilitate curative treatment.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>Malignant sacrococcygeal teratoma with intraspinal infiltration or metastasis requires surgical and adjuvant treatment. If primary neurologic function-sparing surgery makes curative treatment impossible, adequate and quick decompression of neural structures with similar results can be achieved by preoperative chemotherapy, avoiding the local spill of malignant cells.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.23.00683","type":"journal-article","created":{"date-parts":[[2024,10,24]],"date-time":"2024-10-24T14:01:34Z","timestamp":1729778494000},"update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Delayed En Bloc Excision of L3 for Metastatic Sacrococcygeal Teratoma on a 1-Year-Old Boy"],"prefix":"10.2106","volume":"14","author":[{"ORCID":"https:\/\/orcid.org\/0009-0005-0762-3096","authenticated-orcid":false,"given":"Sandra","family":"T\u00f6tterman","sequence":"first","affiliation":[{"name":"Department of Pediatric Surgery and Orthopedics, University of Turku, Turku University Hospital, Turku, Finland"},{"name":"Department of Obstetrics and Gynecology, Helsinki University Hospital, Helsinki, Finland"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Johanna","family":"Syv\u00e4nen","sequence":"additional","affiliation":[{"name":"Department of Pediatric Surgery and Orthopedics, University of Turku, Turku University Hospital, Turku, Finland"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Marika","family":"Gr\u00f6nroos","sequence":"additional","affiliation":[{"name":"Department of Pediatrics and Adolescent Medicine, University of Turku and Turku University Hospital, Turku, Finland"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Maria","family":"Gardberg","sequence":"additional","affiliation":[{"name":"Department of Pathology, University of Turku and Turku University Hospital, Turku, Finland"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Arimatias","family":"Raitio","sequence":"additional","affiliation":[{"name":"Department of Pediatric Surgery and Orthopedics, University of Turku, Turku University Hospital, Turku, Finland"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-6275-5140","authenticated-orcid":false,"given":"Ilkka","family":"Helenius","sequence":"additional","affiliation":[{"name":"Department of Orthopedics and Traumatology, University of Helsinki and Helsinki University Hospital, Helsinki, Finland"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2024,10]]},"reference":[{"issue":"1","key":"bib2-20241024","doi-asserted-by":"crossref","first-page":"65","DOI":"10.1002\/jso.1068","article-title":"Pelvic neoplasms in children","volume":"77","author":"Groff","year":"2001","journal-title":"J Surg Oncol."},{"issue":"7","key":"bib3-20241024","doi-asserted-by":"crossref","first-page":"1113","DOI":"10.1016\/j.jpedsurg.2013.11.063","article-title":"Sacrococcygeal malignant germ cell tumor (SC-MGCT) with intraspinal extension","volume":"49","author":"Garg","year":"2014","journal-title":"J Pediatr Surg."},{"issue":"10","key":"bib4-20241024","doi-asserted-by":"crossref","first-page":"2022","DOI":"10.1016\/j.jpedsurg.2020.02.003","article-title":"Sacrococcygeal teratoma with intraspinal extension: a case series and review of literature","volume":"55","author":"Seilern Und Aspang","year":"2020","journal-title":"J Pediatr Surg."},{"issue":"12","key":"bib5-20241024","doi-asserted-by":"crossref","first-page":"1543","DOI":"10.1002\/bjs.5379","article-title":"Factors associated with recurrence and metastasis in sacrococcygeal teratoma","volume":"93","author":"Derikx","year":"2006","journal-title":"Br J Surg."},{"issue":"1","key":"bib6-20241024","doi-asserted-by":"crossref","first-page":"16","DOI":"10.1016\/j.ejso.2022.09.002","article-title":"Long-term functional outcomes of sacrococcygeal teratoma: a systematic review of published studies exploring \u2018real world\u2019 outcomes","volume":"49","author":"Salim","year":"2023","journal-title":"Eur J Surg Oncol."},{"issue":"1","key":"bib7-20241024","doi-asserted-by":"crossref","first-page":"51","DOI":"10.1053\/j.sempedsurg.2011.10.005","article-title":"Pediatric germ cell tumors","volume":"21","author":"Rescorla","year":"2012","journal-title":"Semin Pediatr Surg."},{"issue":"2","key":"bib8-20241024","doi-asserted-by":"crossref","first-page":"171","DOI":"10.1016\/S0022-3468(98)90426-2","article-title":"Long-term outcome for infants and children with sacrococcygeal teratoma: a report from the Children's Cancer Group","volume":"33","author":"Rescorla","year":"1998","journal-title":"J Pediatr Surg."},{"issue":"5","key":"bib9-20241024","doi-asserted-by":"crossref","first-page":"718","DOI":"10.1227\/NEU.0000000000000903","article-title":"The neurological compromised spine due to ewing sarcoma. What first: surgery or chemotherapy? Therapy, survival, and neurological outcome of 15 cases with primary Ewing sarcoma of the vertebral column","volume":"77","author":"Mirzaei","year":"2015","journal-title":"Neurosurgery."}],"container-title":["JBJS Case Connector"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.23.00683","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T13:51:26Z","timestamp":1787752286000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.23.00683"}},"subtitle":["A Case Report"],"short-title":[],"issued":{"date-parts":[[2024,10]]},"references-count":8,"journal-issue":{"issue":"4","published-online":{"date-parts":[[2024]]}},"URL":"https:\/\/doi.org\/10.2106\/jbjs.cc.23.00683","relation":{},"ISSN":["2160-3251"],"issn-type":[{"value":"2160-3251","type":"electronic"}],"subject":[],"published":{"date-parts":[[2024,10]]}}}