{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:31:33Z","timestamp":1787754693109,"version":"build-2784847793"},"reference-count":24,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"3","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>Stickler syndrome is a collagen disorder associated with hypermobility and juvenile osteoarthritis in multiple joints. This report presents a 12-year-old adolescent boy with Stickler syndrome presenting with bilateral ankle pain. He had bilateral distal tibial recurvatum-valgus deformity and distal tibial slipped epiphysis (DTSE). He underwent osteotomy along the true plane of deformity and internal fixation. At the latest follow-up, he had decreased pain and improved clinical and radiographic alignment.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusions:<\/jats:title>\n                    <jats:p>DTSE is a rare condition contributing to ankle deformity. Previously reported in renal osteodystrophy and myelomeningocele, DTSE is reported herein for the first time in association with Stickler syndrome.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.25.00143","type":"journal-article","created":{"date-parts":[[2025,7,17]],"date-time":"2025-07-17T18:00:53Z","timestamp":1752775253000},"update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Distal Tibial Slipped Epiphysis in Stickler Syndrome"],"prefix":"10.2106","volume":"15","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-9959-4210","authenticated-orcid":false,"given":"Nickolas J.","family":"Nahm","sequence":"first","affiliation":[{"name":"Gillette Children's Specialty Healthcare, Saint Paul, Minnesota"},{"name":"Department of Orthopaedic Surgery, University of Minnesota, Minneapolis, Minnesota"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-3624-8273","authenticated-orcid":false,"given":"Andrew G.","family":"Georgiadis","sequence":"additional","affiliation":[{"name":"Gillette Children's Specialty Healthcare, Saint Paul, Minnesota"},{"name":"Department of Orthopaedic Surgery, University of Minnesota, Minneapolis, Minnesota"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Mark T.","family":"Dahl","sequence":"additional","affiliation":[{"name":"Gillette Children's Specialty Healthcare, Saint Paul, Minnesota"},{"name":"Department of Orthopaedic Surgery, University of Minnesota, Minneapolis, Minnesota"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2025,7]]},"reference":[{"issue":"10","key":"bib1-20250717","doi-asserted-by":"crossref","first-page":"546","DOI":"10.1056\/NEJM197203092861020","article-title":"The Stickler syndrome","volume":"286","author":"Opitz","year":"1972","journal-title":"N Engl J Med."},{"issue":"5","key":"bib2-20250717","first-page":"681","article-title":"Genetic linkage analysis of hereditary arthro-ophthalmopathy (Stickler syndrome) and the type II procollagen gene","volume":"45","author":"Knowlton","year":"1989","journal-title":"Am J Hum Genet."},{"issue":"7","key":"bib3-20250717","doi-asserted-by":"crossref","first-page":"807","DOI":"10.1038\/sj.ejhg.5200377","article-title":"Stickler syndrome: further mutations in COL11A1 and evidence for additional locus heterogeneity","volume":"7","author":"Martin","year":"1999","journal-title":"Eur J Hum Genet."},{"issue":"6","key":"bib4-20250717","doi-asserted-by":"crossref","first-page":"760","DOI":"10.1097\/01241398-199011000-00010","article-title":"Stickler syndrome","volume":"10","author":"Bennett","year":"1990","journal-title":"J Pediatr Orthop."},{"key":"bib5-20250717","first-page":"433","article-title":"Hereditary progressive arthro-ophthalmopathy","volume":"40","author":"Stickler","year":"1965","journal-title":"Mayo Clin Proc."},{"issue":"1","key":"bib6-20250717","doi-asserted-by":"crossref","first-page":"e20.00687","DOI":"10.2106\/JBJS.CC.20.00687","article-title":"Challenging diagnosis of stickler syndrome in a patient with premature osteoarthritis: a case report","volume":"11","author":"Yousef","year":"2021","journal-title":"JBJS Case Connector."},{"issue":"5","key":"bib7-20250717","doi-asserted-by":"crossref","first-page":"657","DOI":"10.1097\/01241398-200109000-00020","article-title":"The hip in Stickler syndrome","volume":"21","author":"Rose","year":"2001","journal-title":"J Pediatr Orthop."},{"issue":"2","key":"bib8-20250717","doi-asserted-by":"crossref","first-page":"140","DOI":"10.1097\/BPO.0b013e3181d076b6","article-title":"Valgus slipped capital femoral epiphysis: prevalence, presentation, and treatment options","volume":"30","author":"Shank","year":"2010","journal-title":"J Pediatr Orthop."},{"issue":"2","key":"bib9-20250717","doi-asserted-by":"crossref","first-page":"211","DOI":"10.1097\/01241398-198305000-00011","article-title":"Slippage of the distal tibial epiphysis","volume":"3","author":"Tebor","year":"1983","journal-title":"J Pediatr Orthop."},{"key":"bib10-20250717","doi-asserted-by":"crossref","first-page":"40","DOI":"10.1302\/0301-620X.46B1.40","article-title":"Persistent joint laxity and congenital dislocation of the hip","volume":"46","author":"Carter","year":"1964","journal-title":"J Bone Joint Surg Br."},{"key":"bib11-20250717","first-page":"503","article-title":"Preoperative planning in deformity correction and limb lengthening surgery","volume":"49","author":"Dahl","year":"2000","journal-title":"Instr Course Lect."},{"issue":"7","key":"bib12-20250717","doi-asserted-by":"crossref","first-page":"545","DOI":"10.1136\/adc.50.7.545","article-title":"Slipped epiphyses in renal osteodystrophy","volume":"50","author":"Mehls","year":"1975","journal-title":"Arch Dis Child."},{"key":"bib13-20250717","doi-asserted-by":"crossref","first-page":"191","DOI":"10.1097\/00003086-196701000-00018","article-title":"Bilateral distal tibial and fibular epiphyseal separation associated with spina bifida. A case report","volume":"50","author":"Stern","year":"1967","journal-title":"Clin Orthop Relat Res."},{"key":"bib14-20250717","doi-asserted-by":"crossref","first-page":"106","DOI":"10.1302\/0301-620X.44B1.106","article-title":"Spina bifida and epiphysial displacement. Report of two cases","volume":"44-B","author":"Soutter","year":"1962","journal-title":"J Bone Joint Surg Br."},{"key":"bib15-20250717","doi-asserted-by":"crossref","first-page":"387","DOI":"10.1302\/0301-620X.42B2.387","article-title":"Museum pages. III. Spina bifida and epiphysial displacement","volume":"42-B","author":"Golding","year":"1960","journal-title":"J Bone Joint Surg Br."},{"issue":"6","key":"bib16-20250717","doi-asserted-by":"crossref","first-page":"1119","DOI":"10.1016\/j.pcl.2014.08.001","article-title":"Slipped capital femoral epiphysis: how to evaluate with a review and update of treatment","volume":"61","author":"Georgiadis","year":"2014","journal-title":"Pediatr Clin North Am."},{"issue":"3","key":"bib17-20250717","doi-asserted-by":"crossref","first-page":"349","DOI":"10.1097\/01241398-199505000-00018","article-title":"Slipped capital femoral epiphysis associated with endocrine disorders","volume":"15","author":"Loder","year":"1995","journal-title":"J Pediatr Orthop."},{"issue":"5","key":"bib18-20250717","doi-asserted-by":"crossref","first-page":"610","DOI":"10.1097\/01241398-199313050-00011","article-title":"Review of slipped capital femoral epiphysis associated with endocrine disease","volume":"13","author":"Wells","year":"1993","journal-title":"J Pediatr Orthop."},{"issue":"2","key":"bib19-20250717","doi-asserted-by":"crossref","first-page":"169","DOI":"10.1097\/01241398-200303000-00007","article-title":"Outcome of slipped capital femoral epiphysis in renal osteodystrophy","volume":"23","author":"Oppenheim","year":"2003","journal-title":"J Pediatr Orthop."},{"issue":"2","key":"bib20-20250717","doi-asserted-by":"crossref","first-page":"205","DOI":"10.1097\/00004694-199703000-00013","article-title":"Slipped capital femoral epiphysis associated with renal failure osteodystrophy","volume":"17","author":"Loder","year":"1997","journal-title":"J Pediatr Orthop."},{"issue":"suppl_431","key":"bib21-20250717","doi-asserted-by":"crossref","first-page":"1","DOI":"10.1080\/03655950410009733","article-title":"Slipped capital femoral epiphysis. The mechanical function of the periosteum: new aspects and theory including bilaterality","volume":"45","author":"Billing","year":"2004","journal-title":"Acta Radiologica."},{"issue":"7","key":"bib22-20250717","doi-asserted-by":"crossref","first-page":"1000","DOI":"10.2106\/00004623-198668070-00006","article-title":"The association of femoral retroversion with slipped capital femoral epiphysis","volume":"68","author":"Gelberman","year":"1986","journal-title":"J Bone Joint Surg Am."},{"issue":"5","key":"bib23-20250717","doi-asserted-by":"crossref","first-page":"947","DOI":"10.1097\/CORR.0000000000001611","article-title":"How common is femoral retroversion and how is it affected by different measurement methods in unilateral slipped capital femoral epiphysis?","volume":"479","author":"Schmaranzer","year":"2021","journal-title":"Clin Orthop Relat Res."},{"issue":"1","key":"bib24-20250717","doi-asserted-by":"crossref","first-page":"92","DOI":"10.1302\/0301-620X.90B1.19502","article-title":"Changing incidence of slipped capital femoral epiphysis: a relationship with obesity?","volume":"90","author":"Murray","year":"2008","journal-title":"J Bone Joint Surg Br."}],"container-title":["JBJS Case Connector"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.25.00143","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T13:31:05Z","timestamp":1787751065000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.ovid.com\/10.2106\/JBJS.CC.25.00143"}},"subtitle":["A Case Report"],"short-title":[],"issued":{"date-parts":[[2025,7]]},"references-count":24,"journal-issue":{"issue":"3","published-online":{"date-parts":[[2025]]}},"URL":"https:\/\/doi.org\/10.2106\/jbjs.cc.25.00143","relation":{},"ISSN":["2160-3251"],"issn-type":[{"value":"2160-3251","type":"electronic"}],"subject":[],"published":{"date-parts":[[2025,7]]}}}