{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:29:36Z","timestamp":1787754576905,"version":"build-2784847793"},"reference-count":12,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"3","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>We describe lower extremity management of a 14-year-old adolescent boy and 13-year-old adolescent girl with amyoplasia type of arthrogryposis who underwent bilateral knee disarticulation for recurrent knee flexion contracture and persistent pain. Both patients reported improvements in gross motor mobility and demonstrated enhanced scores across all Patient-Reported Outcomes Measurement Information System (PROMIS) domains. They both recommend this procedure to other similarly affected patients and affirm they would undergo the procedure again.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>Amputation in the amyoplasia population should not be viewed as a treatment failure but rather as a reasonable and predictable alternative in appropriately selected candidates.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.25.00173","type":"journal-article","created":{"date-parts":[[2025,7,10]],"date-time":"2025-07-10T18:01:53Z","timestamp":1752170513000},"update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Knee Disarticulation in Amyoplasia: A Quality-of-Life Salvage Intervention"],"prefix":"10.2106","volume":"15","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-3569-2513","authenticated-orcid":false,"given":"Lauren C.","family":"Hyer","sequence":"first","affiliation":[{"name":"Shriners Children's\u00ae\u2014Greenville, Greenville, South Carolina"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0009-0002-7128-0225","authenticated-orcid":false,"given":"Emily A.","family":"Lewis","sequence":"additional","affiliation":[{"name":"Prisma Health Department of Orthopedic Surgery, Greenville South Carolina"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-4048-3882","authenticated-orcid":false,"given":"Emily R.","family":"Shull","sequence":"additional","affiliation":[{"name":"Shriners Children's\u00ae\u2014Greenville, Greenville, South Carolina"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-0207-8322","authenticated-orcid":false,"given":"David E.","family":"Westberry","sequence":"additional","affiliation":[{"name":"Shriners Children's\u00ae\u2014Greenville, Greenville, South Carolina"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2025,7]]},"reference":[{"issue":"3","key":"bib1-20250710","doi-asserted-by":"crossref","first-page":"280","DOI":"10.1002\/ajmg.c.31739","article-title":"Arthrogryposis multiplex congenita definition: update using an international consensus-based approach","volume":"181","author":"Cachecho","year":"2019","journal-title":"Am J Med Genet C Semin Med Genet."},{"issue":"8","key":"bib2-20250710","doi-asserted-by":"crossref","first-page":"464","DOI":"10.1016\/j.ejmg.2014.03.008","article-title":"Arthrogryposis (multiple congenital contractures): diagnostic approach to etiology, 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Cases"],"short-title":[],"issued":{"date-parts":[[2025,7]]},"references-count":12,"journal-issue":{"issue":"3","published-online":{"date-parts":[[2025]]}},"URL":"https:\/\/doi.org\/10.2106\/jbjs.cc.25.00173","relation":{},"ISSN":["2160-3251"],"issn-type":[{"value":"2160-3251","type":"electronic"}],"subject":[],"published":{"date-parts":[[2025,7]]}}}