{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:28:32Z","timestamp":1787754512513,"version":"build-2784847793"},"reference-count":15,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"1","content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>A 27-year-old man presented with an 8-year history of chronic right gluteal and posterior thigh pain, worsened by sitting and unresponsive to conservative treatment. Imaging revealed widespread melorheostosis and osteopoikilosis of the right lower extremity, with 2 gluteal soft tissue masses compressing the sciatic nerve. The masses were excised using a dual surgical approach, achieving successful sciatic nerve decompression. Postoperatively, the patient regained normal sitting and sleeping tolerance, with complete pain relief maintained over a 15-month follow-up.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>Melorheostosis, a rare sclerosing bone disorder sometimes associated with osteopoikilosis, may require surgery when large lesions cause nerve compression.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.25.00546","type":"journal-article","created":{"date-parts":[[2026,1,8]],"date-time":"2026-01-08T19:00:33Z","timestamp":1767898833000},"update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":0,"title":["Combined Melorheostosis and Osteopoikilosis: Uncommon Presentation with Sciatic Nerve Neuropathy"],"prefix":"10.2106","volume":"16","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-9319-8148","authenticated-orcid":false,"given":"Ismail Tawfeek","family":"Badr","sequence":"first","affiliation":[{"name":"Department of Orthopaedic Surgery, Menoufia University Faculty of Medicine, Shebin-El-Kom, Menoufia, Egypt"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-8047-9159","authenticated-orcid":false,"given":"Mohamed Kamal","family":"Mesregah","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Menoufia University Faculty of Medicine, Shebin-El-Kom, Menoufia, Egypt"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-7047-0903","authenticated-orcid":false,"given":"Sanjiv","family":"Rampal","sequence":"additional","affiliation":[{"name":"Department of Orthopedic and Traumatology, School of Medicine, International Medical University, Kuala Lumpur, Malaysia"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-4490-500X","authenticated-orcid":false,"given":"Mahmoud Mohamed","family":"Moawad","sequence":"additional","affiliation":[{"name":"Department of Radiology, Menoufia University Faculty of Medicine, Shebin-El-Kom, Menoufia, Egypt"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-3409-2295","authenticated-orcid":false,"given":"Bahaa Zakarya","family":"Hasan","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Menoufia University Faculty of Medicine, Shebin-El-Kom, Menoufia, Egypt"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","published-online":{"date-parts":[[2026,1]]},"reference":[{"key":"bib1-20260108","doi-asserted-by":"crossref","first-page":"2050313X20940564","DOI":"10.1177\/2050313X20940564","article-title":"The dripping candle wax sign of melorheostosis","volume":"8","author":"Hoang","year":"2020","journal-title":"SAGE Open Med Case Rep."},{"issue":"5","key":"bib2-20260108","doi-asserted-by":"crossref","first-page":"869","DOI":"10.3390\/medicina59050869","article-title":"Melorheostosis: a review of the literature and a case report","volume":"59","author":"Iordache","year":"2023","journal-title":"Medicina (Kaunas)."},{"issue":"5","key":"bib3-20260108","doi-asserted-by":"crossref","first-page":"530","DOI":"10.1007\/s00223-019-00543-y","article-title":"Melorheostosis and osteopoikilosis: a review of clinical features and pathogenesis","volume":"104","author":"Wordsworth","year":"2019","journal-title":"Calcif Tissue Int."},{"issue":"4","key":"bib4-20260108","doi-asserted-by":"crossref","first-page":"335","DOI":"10.1007\/s11914-017-0375-y","article-title":"Melorheostosis: a rare sclerosing bone dysplasia","volume":"15","author":"Kotwal","year":"2017","journal-title":"Curr Osteoporos 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