{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,26]],"date-time":"2026-08-26T14:28:15Z","timestamp":1787754495402,"version":"build-2784847793"},"reference-count":17,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"2","content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["JBJS Case Connector"],"published-print":{"date-parts":[[2015,5,13]]},"abstract":"<jats:sec>\n                    <jats:title>Case:<\/jats:title>\n                    <jats:p>A forty-three-year-old male patient complained of difficulty walking due to severe hip and knee pain and stiffness, which had persisted for twenty years. He was found to have multifocal melorheostosis involving the axial skeleton and the entire left lower limb, along with complex vascular and lymphatic malformations corresponding to the sclerotomes related to the skeletal anomalies. Total hip and knee arthroplasties were performed. He was eventually free of pain during walking, and joint motion of the hip and knee was substantially improved after surgery.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>Hip and knee pain and contracture resulting from multifocal melorheostosis were successfully treated with total hip and knee arthroplasty.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.2106\/jbjs.cc.n.00159","type":"journal-article","created":{"date-parts":[[2015,5,13]],"date-time":"2015-05-13T22:42:19Z","timestamp":1431556939000},"page":"e40","source":"Crossref","is-referenced-by-count":7,"title":["Vascular Malformations Corresponding to Sclerotomes in Multifocal Melorheostosis: Painful Hip and Knee Contractures Treated with Total Joint Arthroplasty"],"prefix":"10.2106","volume":"5","author":[{"given":"Sung-Jin","family":"Shin","sequence":"first","affiliation":[{"name":"Department of Orthopaedic Surgery, Jeju National University Hospital, Aran 13gil 15, Jeju-si, Jeju, 690-767, South Korea. E-mail address for S.-J. Shin:. E-mail address for U. Nam:"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Uk","family":"Nam","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Jeju National University Hospital, Aran 13gil 15, Jeju-si, Jeju, 690-767, South Korea. E-mail address for S.-J. Shin:. E-mail address for U. Nam:"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Sang-Rim","family":"Kim","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Jeju National University School of Medicine, Ara 1dong, 102 Jejudaehakno, Jeju-si, Jeju, 690-756, South Korea. E-mail address for S.-R. Kim:. E-mail address for K.-W. Nam:"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Hee Joong","family":"Kim","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Seoul National University Hospital, 101 Daehakro, Jongno-gu, Seoul, 110-744, South Korea. E-mail address:"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Dimitris","family":"Dimitriou","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Massachusetts General Hospital, Harvard Medical School, 55 Fruit Street, Boston, MA 02114. E-mail address for D. Dimitriou:. E-mail address for G. Li:. E-mail address for Y.-M. Kwon:. E-mail address for H. Rubash:"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Guoan","family":"Li","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Massachusetts General Hospital, Harvard Medical School, 55 Fruit Street, Boston, MA 02114. E-mail address for D. Dimitriou:. E-mail address for G. Li:. E-mail address for Y.-M. Kwon:. E-mail address for H. Rubash:"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Young-Min","family":"Kwon","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Massachusetts General Hospital, Harvard Medical School, 55 Fruit Street, Boston, MA 02114. E-mail address for D. Dimitriou:. E-mail address for G. Li:. E-mail address for Y.-M. Kwon:. E-mail address for H. Rubash:"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Harry","family":"Rubash","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Massachusetts General Hospital, Harvard Medical School, 55 Fruit Street, Boston, MA 02114. E-mail address for D. Dimitriou:. E-mail address for G. Li:. E-mail address for Y.-M. Kwon:. E-mail address for H. Rubash:"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Kwang Woo","family":"Nam","sequence":"additional","affiliation":[{"name":"Department of Orthopaedic Surgery, Jeju National University School of Medicine, Ara 1dong, 102 Jejudaehakno, Jeju-si, Jeju, 690-756, South Korea. E-mail address for S.-R. Kim:. E-mail address for K.-W. Nam:"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"276","reference":[{"issue":"8","key":"bib1-20230712","doi-asserted-by":"crossref","first-page":"593","DOI":"10.1016\/j.crad.2010.02.004","article-title":"Classical and unusual imaging appearances of melorheostosis","volume":"65","author":"Suresh","year":"2010","journal-title":"Clin Radiol."},{"issue":"6 Pt 2","key":"bib2-20230712","doi-asserted-by":"crossref","first-page":"717","DOI":"10.3109\/17453677908991300","article-title":"Para-articular ossifications associated with melorheostosis L\u00e9ri","volume":"50","author":"Dissing","year":"1979","journal-title":"Acta Orthop Scand."},{"issue":"8","key":"bib3-20230712","doi-asserted-by":"crossref","first-page":"504","DOI":"10.1097\/01.rlu.0000227548.69732.c7","article-title":"Multifocal melorheostosis","volume":"31","author":"McCay","year":"2006","journal-title":"Clin Nucl Med."},{"issue":"2","key":"bib4-20230712","doi-asserted-by":"crossref","first-page":"166","DOI":"10.1159\/000247127","article-title":"Melorheostosis with associated minimal change nephrotic syndrome, mesenteric fibromatosis and capillary haemangiomas","volume":"188","author":"Roger","year":"1994","journal-title":"Dermatology."},{"issue":"2","key":"bib5-20230712","doi-asserted-by":"crossref","first-page":"57","DOI":"10.1007\/BF00349329","article-title":"Melorheostosis and the sclerotomes: a radiological correlation","volume":"4","author":"Murray","year":"1979","journal-title":"Skeletal Radiol."},{"issue":"11","key":"bib6-20230712","doi-asserted-by":"crossref","first-page":"633","DOI":"10.1007\/s002560050449","article-title":"Sclerotome distribution of melorheostosis and multicentric fibromatosis","volume":"27","author":"Rhys","year":"1998","journal-title":"Skeletal Radiol."},{"issue":"1","key":"bib7-20230712","doi-asserted-by":"crossref","first-page":"41","DOI":"10.1007\/BF00367380","article-title":"Melorheostosis of the axial skeleton with associated fibrolipomatous lesions","volume":"9","author":"Garver","year":"1982","journal-title":"Skeletal Radiol."},{"key":"bib8-20230712","doi-asserted-by":"crossref","DOI":"10.1136\/bcr-2013-009820","article-title":"Successful treatment of pain in melorheostosis with zoledronate, with improvement on bone scintigraphy","author":"Slimani","year":"2013","journal-title":"BMJ Case Rep."},{"key":"bib9-20230712","doi-asserted-by":"crossref","DOI":"10.1136\/bcr.04.2009.1757","article-title":"Melorheostosis and its treatment with intravenous zoledronic acid","author":"Hollick","year":"2010","journal-title":"BMJ Case Rep."},{"issue":"4","key":"bib10-20230712","doi-asserted-by":"crossref","first-page":"415","DOI":"10.1302\/0301-620X.61B4.500749","article-title":"Melorheostosis in children. Clinical features and natural history","volume":"61","author":"Younge","year":"1979","journal-title":"J Bone Joint Surg Br."},{"issue":"12","key":"bib11-20230712","doi-asserted-by":"crossref","first-page":"709","DOI":"10.1007\/s00256-002-0576-y","article-title":"Atypical form of active melorheostosis and its treatment with bisphosphonate","volume":"31","author":"Don\u00e1th","year":"2002","journal-title":"Skeletal Radiol."},{"issue":"1","key":"bib12-20230712","doi-asserted-by":"crossref","first-page":"83","DOI":"10.1080\/17461550500066808","article-title":"Melorheostosis\u2014an unusual cause of amputation","volume":"29","author":"Graham","year":"2005","journal-title":"Prosthet Orthot Int."},{"issue":"2","key":"bib13-20230712","doi-asserted-by":"crossref","first-page":"589","DOI":"10.1016\/j.knee.2012.11.004","article-title":"Severe valgus deformity of the knee with permanent patellar dislocation associated with melorheostosis: a case report and review of the literature","volume":"21","author":"Kitta","year":"2014","journal-title":"Knee."},{"issue":"2","key":"bib14-20230712","doi-asserted-by":"crossref","first-page":"264","DOI":"10.1007\/s00167-010-1156-7","article-title":"Arthroscopically assisted knee contracture release secondary to melorheostosis: a case report","volume":"19","author":"Claramunt","year":"2011","journal-title":"Knee Surg Sports Traumatol Arthrosc."},{"issue":"5","key":"bib15-20230712","doi-asserted-by":"crossref","first-page":"1106","DOI":"10.2106\/JBJS.G.00961","article-title":"Successful elbow contracture release secondary to melorheostosis. 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