{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,5,4]],"date-time":"2026-05-04T08:53:33Z","timestamp":1777884813053,"version":"3.51.4"},"reference-count":15,"publisher":"SAGE Publications","issue":"1","license":[{"start":{"date-parts":[[2013,1,1]],"date-time":"2013-01-01T00:00:00Z","timestamp":1356998400000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["Pediatr Dev Pathol"],"published-print":{"date-parts":[[2013,1]]},"abstract":"<jats:p>Genitourinary tract malformations causing hydrops fetalis are rare. The authors report a case of a female delivered at 32 weeks gestational age following a prenatal diagnosis of an abdominopelvic cystic mass with hydrops fetalis. The neonate was persistently hypoxic with unstable cardiovascular status and survived only 7 days. At autopsy, a cystic malformation replaced the vagina and uterus, associated with lower vaginal atresia and anorectal agenesis. The cyst had interfered with the normal process of M\u00fcllerian duct fusion, leading to a longitudinal vaginal septum and bifurcation of endocervix, with absent uterus and fallopian tubes. The urinary bladder was compressed by the cyst, resulting in bilateral hydronephrosis. The cyst impeded the inferior vena caval and umbilical venous circulations and impinged upon the thoracic cavity with resultant pulmonary hypoplasia. This malformation, which might be termed \u201ccystic dysplasia\u201d of the vagina, represents an extreme form of hydrometrocolpos that resulted in hydrops fetalis.<\/jats:p>","DOI":"10.2350\/12-07-1223-cr.1","type":"journal-article","created":{"date-parts":[[2012,10,31]],"date-time":"2012-10-31T15:11:32Z","timestamp":1351696292000},"page":"39-44","update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":3,"title":["Cystic Malformation of Lower Female Genital Tract Resulting in Hydrops Fetalis: A Case Report"],"prefix":"10.1177","volume":"16","author":[{"given":"Mana","family":"Taweevisit","sequence":"first","affiliation":[{"name":"Department of Pathology, Faculty of Medicine, Chulalongkorn University, 1873 King Rama IV Street, Pathumwan, Bangkok, 10330 Thailand"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Saknan","family":"Manotaya","sequence":"additional","affiliation":[{"name":"Department of Obstetrics and Gynecology, Faculty of Medicine, Chulalongkorn University, 1873 King Rama IV Street, Pathumwan, Bangkok, 10330 Thailand"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Paul Scott","family":"Thorner","sequence":"additional","affiliation":[{"name":"Department of Pathology, Faculty of Medicine, Chulalongkorn University, 1873 King Rama IV Street, Pathumwan, Bangkok, 10330 Thailand"},{"name":"Department of Pathology and Laboratory Medicine, Hospital for Sick Children and University of Toronto, Toronto M5G1X8, Canada"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"179","published-online":{"date-parts":[[2015,1,1]]},"reference":[{"key":"bibr1-12-07-1223-CR.1","first-page":"333","volume-title":"Potter's Pathology of the Fetus, Infant and Child","author":"Machin GA","year":"2007","edition":"2"},{"key":"bibr2-12-07-1223-CR.1","first-page":"635","volume":"106","author":"Moerman P","year":"1982","journal-title":"Arch Pathol Lab Med"},{"key":"bibr3-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1007\/s00383-010-2685-3"},{"key":"bibr4-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1016\/0002-9378(91)90234-I"},{"key":"bibr5-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1002\/uog.2584"},{"key":"bibr6-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1016\/j.jpag.2009.02.009"},{"key":"bibr7-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1016\/j.jpag.2008.02.008"},{"key":"bibr8-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1046\/j.1341-8076.2002.00021.x"},{"key":"bibr9-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1186\/1750-1172-2-13"},{"key":"bibr10-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1016\/j.anndiagpath.2006.08.003"},{"key":"bibr11-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1016\/0925-4773(93)90090-K"},{"key":"bibr12-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1089\/dna.1993.12.381"},{"key":"bibr13-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1242\/dev.121.12.4057"},{"key":"bibr14-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1007\/s00467-007-0466-6"},{"key":"bibr15-12-07-1223-CR.1","doi-asserted-by":"publisher","DOI":"10.1159\/000065017"}],"container-title":["Pediatric and Developmental Pathology"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.2350\/12-07-1223-CR.1","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/full-xml\/10.2350\/12-07-1223-CR.1","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.2350\/12-07-1223-CR.1","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,5,1]],"date-time":"2026-05-01T02:39:19Z","timestamp":1777603159000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.sagepub.com\/doi\/10.2350\/12-07-1223-CR.1"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2013,1]]},"references-count":15,"journal-issue":{"issue":"1","published-print":{"date-parts":[[2013,1]]}},"alternative-id":["10.2350\/12-07-1223-CR.1"],"URL":"https:\/\/doi.org\/10.2350\/12-07-1223-cr.1","relation":{},"ISSN":["1093-5266","1615-5742"],"issn-type":[{"value":"1093-5266","type":"print"},{"value":"1615-5742","type":"electronic"}],"subject":[],"published":{"date-parts":[[2013,1]]}}}