{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,2,6]],"date-time":"2026-02-06T04:46:08Z","timestamp":1770353168770,"version":"3.49.0"},"reference-count":90,"publisher":"Journal of Neurosurgery Publishing Group (JNSPG)","issue":"17","license":[{"start":{"date-parts":[[2023,4,24]],"date-time":"2023-04-24T00:00:00Z","timestamp":1682294400000},"content-version":"unspecified","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2023,4,24]]},"abstract":"<jats:sec>\n                    <jats:title>BACKGROUND<\/jats:title>\n                    <jats:p>Limited dorsal myeloschisis (LDM) and intramedullary infantile hemangioma rarely coexist in the spinal cord.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>OBSERVATIONS<\/jats:title>\n                    <jats:p>The authors describe the case of a 3-month-old girl who, despite lacking neurological symptoms or signs, had a cigarette burn-like mark at the lumbosacral area and skin dimpling in the gluteal area. Magnetic resonance imaging showed a low-set conus due to a thickened filum and an abnormal subcutaneous stalk connected to the conus medullaris. In combination with the skin lesions, these findings strongly implied nonsaccular-type LDM. An intramedullary mass in the conus medullaris was also shown on magnetic resonance imaging and was homogenously enhanced with isointensity on T1- and T2-weighted images. We prophylactically untethered the spinal cord and partially removed the intramedullary mass, which had no clear borders, for a safe surgical dissection. Histologically, the intramedullary mass was an infantile hemangioma, and the subcutaneous stalk was a lesion associated with LDM. The patient remained neurologically intact after surgery, and then 2 years later, there was spontaneous regression of the residual tumor.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>LESSONS<\/jats:title>\n                    <jats:p>Although rare, nonsaccular type LDM may appear concurrently with intramedullary infantile hemangioma at the conus medullaris. The authors present a possible mechanism behind this concurrent presentation in the same area.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.3171\/case22359","type":"journal-article","created":{"date-parts":[[2023,4,25]],"date-time":"2023-04-25T12:04:06Z","timestamp":1682424246000},"source":"Crossref","is-referenced-by-count":0,"title":["Limited dorsal myeloschisis associated with intramedullary infantile hemangioma in the conus medullaris: illustrative case"],"prefix":"10.3171","volume":"5","author":[{"given":"Yoko","family":"Nakanishi","sequence":"first","affiliation":[{"name":"Departments of Pediatric Neurosurgery, and"},{"name":"Department of Neurological Surgery, Wakayama Medical University, Wakayama, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Noritsugu","family":"Kunihiro","sequence":"additional","affiliation":[{"name":"Departments of Pediatric Neurosurgery, and"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ryoko","family":"Umaba","sequence":"additional","affiliation":[{"name":"Departments of Pediatric Neurosurgery, and"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Yasuhiro","family":"Matsusaka","sequence":"additional","affiliation":[{"name":"Departments of Pediatric Neurosurgery, and"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Takeshi","family":"Inoue","sequence":"additional","affiliation":[{"name":"Pathology, Osaka City General Hospital, Osaka, Japan; and"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Hiroaki","family":"Sakamoto","sequence":"additional","affiliation":[{"name":"Departments of Pediatric Neurosurgery, and"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"1754","reference":[{"issue":"6","key":"b1","series-title":"Neurosurgery","first-page":"1555","article-title":"Limited dorsal myeloschisis: a distinctive clinicopathological entity","volume":"67","author":"Pang D","year":"2010","unstructured":"Pang D, Zovickian J, Oviedo A, Moes GS. 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