{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,23]],"date-time":"2026-08-23T18:02:45Z","timestamp":1787508165675,"version":"build-2736575974"},"reference-count":90,"publisher":"Journal of Neurosurgery Publishing Group (JNSPG)","issue":"23","license":[{"start":{"date-parts":[[2025,6,9]],"date-time":"2025-06-09T00:00:00Z","timestamp":1749427200000},"content-version":"unspecified","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by-nc-nd\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["J Cosmet Laser Ther"],"published-print":{"date-parts":[[2025,6,9]]},"abstract":"<jats:sec>\n                    <jats:title>BACKGROUND<\/jats:title>\n                    <jats:p>Anterior sacral meningoceles (ASMs) are rare spinal lesions that may be associated with Currarino syndrome, a condition defined by the triad of anorectal malformations, sacral anomalies, and a presacral mass. While Currarino syndrome and caudal duplication syndrome are distinct entities, their coexistence is exceptionally rare, with only 2 reported cases\u2014none involving an ASM. The authors present a unique case of an ASM in a patient with Currarino syndrome and features of caudal duplication anomaly.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>OBSERVATIONS<\/jats:title>\n                    <jats:p>The patient presented with chronic low back pain, paresthesia in the lateral right thigh, and worsening renal function due to hydronephrosis of her solitary left kidney. Imaging revealed a large ASM compressing the left ureter, resulting in severe hydronephrosis and elevated creatinine levels. Surgical intervention included sacral laminectomy, spinal cord untethering, sectioning of the filum terminale, and disconnection of the fistulous connection between the spinal cord and the sacral meningocele. Postoperatively, her renal function improved, and her headache, paresthesia, and back pain significantly resolved.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>LESSONS<\/jats:title>\n                    <jats:p>This case underscores the rare coexistence of Currarino syndrome and caudal duplication anomaly, providing valuable insights into the management of an ASM in this setting.<\/jats:p>\n                    <jats:p>\n                      <jats:ext-link xmlns:xlink=\"http:\/\/www.w3.org\/1999\/xlink\" ext-link-type=\"uri\" xlink:href=\"https:\/\/thejns.org\/doi\/10.3171\/CASE2572\">https:\/\/thejns.org\/doi\/10.3171\/CASE2572<\/jats:ext-link>\n                    <\/jats:p>\n                  <\/jats:sec>","DOI":"10.3171\/case2572","type":"journal-article","created":{"date-parts":[[2025,6,9]],"date-time":"2025-06-09T19:49:23Z","timestamp":1749498563000},"source":"Crossref","is-referenced-by-count":4,"title":["Neurosurgical management of a giant anterior sacral meningocele in a patient with combined Currarino syndrome and caudal duplication anomaly: illustrative case"],"prefix":"10.3171","volume":"9","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-2879-3607","authenticated-orcid":true,"given":"Khushi H.","family":"Shah","sequence":"first","affiliation":[{"name":"Department of Neurological Surgery, University of Miami Miller School of Medicine, Miami, Florida"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-2207-9034","authenticated-orcid":true,"given":"Seth S.","family":"Tigchelaar","sequence":"additional","affiliation":[{"name":"Department of Neurological Surgery, University of Miami Miller School of Medicine, Miami, Florida"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-3249-9657","authenticated-orcid":true,"given":"Adham M.","family":"Khalafallah","sequence":"additional","affiliation":[{"name":"Department of Neurological Surgery, University of Miami Miller School of Medicine, Miami, Florida"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-0713-8497","authenticated-orcid":true,"given":"Allan D.","family":"Levi","sequence":"additional","affiliation":[{"name":"Department of Neurological Surgery, University of Miami Miller School of Medicine, Miami, Florida"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"1754","reference":[{"key":"bib1","series-title":"World Neurosurg","first-page":"522","article-title":"Successful management of a giant anterior sacral meningocele associated with low-dysplastic spondylolisthesis from a single posterior approach: case report","volume":"129","author":"Vanek","year":"2019","unstructured":"Vanek PBenes V.Successful management of a giant anterior sacral meningocele associated with low-dysplastic spondylolisthesis from a single posterior approach: case report. World Neurosurg. 2019;129:522-525."},{"key":"bib2","series-title":"World Neurosurg","first-page":"815.e5","article-title":"Recurrent abortion and tethered cord syndrome caused by anterior sacral meningocele: a report of a rare case with a review of the literature","volume":"101","author":"Gupta","year":"2017","unstructured":"Gupta SChunnilal JMehrotra MMehrotra ASrivastava AKDas KK.Recurrent abortion and tethered cord syndrome caused by anterior sacral meningocele: a report of a rare case with a review of the literature. World Neurosurg. 2017;101:815.e5-815.e7."},{"issue":"1","key":"bib3","series-title":"Orphanet J Rare Dis","article-title":"Currarino syndrome: a comprehensive genetic review of a rare congenital disorder","volume":"16","author":"Dworschak","year":"2021","unstructured":"Dworschak GCReutter HMLudwig M.Currarino syndrome: a comprehensive genetic review of a rare congenital disorder. Orphanet J Rare Dis. 2021;16(1):167."},{"issue":"2","key":"bib4","series-title":"AJR Am J Roentgenol","first-page":"395","article-title":"Triad of anorectal, sacral, and presacral anomalies","volume":"137","author":"Currarino","year":"1981","unstructured":"Currarino GColn DVotteler T.Triad of anorectal, sacral, and presacral anomalies. AJR Am J Roentgenol. 1981;137(2):395-398."},{"issue":"1","key":"bib5","series-title":"Ann Surg Treat Res","first-page":"49","article-title":"Currarino triad with M\u00fcllerian duct anomaly in mother and daughter without MNX1 gene mutation","volume":"90","author":"Kim","year":"2016","unstructured":"Kim SHPaek SHKim HYJung SEPark KW.Currarino triad with M\u00fcllerian duct anomaly in mother and daughter without MNX1 gene mutation. 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