{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,10,21]],"date-time":"2026-10-21T00:38:34Z","timestamp":1792543114233,"version":"4.5.0"},"reference-count":14,"publisher":"Journal of Neurosurgery Publishing Group (JNSPG)","issue":"16","license":[{"start":{"date-parts":[[2026,10,19]],"date-time":"2026-10-19T00:00:00Z","timestamp":1792368000000},"content-version":"unspecified","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by-nc-nd\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["J Neurosurg Case Lessons"],"published-print":{"date-parts":[[2026,10,19]]},"abstract":"<jats:sec>\n                    <jats:title>BACKGROUND<\/jats:title>\n                    <jats:p>Persistent primitive trigeminal artery (PTA) and its related variants\u2014the PTA family\u2014are rare vascular anomalies that can cause trigeminal neuralgia through atypical neurovascular compression patterns, requiring careful anatomical evaluation. The authors describe a rare case of recurrent trigeminal neuralgia caused by an anomalous cerebellar artery arising from a PTA and further complicated by a long-standing Teflon granuloma.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>OBSERVATIONS<\/jats:title>\n                    <jats:p>A 79-year-old man developed recurrent trigeminal neuralgia 19 years after microvascular decompression. Imaging revealed an anomalous anterior inferior cerebellar artery (AICA) arising from a PTA and compressing the trigeminal nerve, along with a Teflon granuloma obscuring the vessel\u2019s course. Three-dimensional multimodal reconstruction clarified the neurovascular conflict. During surgery, dense adhesions due to the granuloma were encountered, and maximal granuloma removal enabled successful transposition of the anomalous AICA.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>LESSONS<\/jats:title>\n                    <jats:p>PTA family anomalies can produce trigeminal neuralgia through atypical patterns of neurovascular compression. In complex or recurrent cases, preoperative 3D reconstruction imaging can enhance understanding of aberrant vascular anatomy. Maximal safe removal of a Teflon granuloma is crucial to create sufficient space and facilitate adequate decompression of the offending vessel.<\/jats:p>\n                    <jats:p>\n                      <jats:ext-link xmlns:xlink=\"http:\/\/www.w3.org\/1999\/xlink\" ext-link-type=\"uri\" xlink:href=\"https:\/\/thejns.org\/doi\/10.3171\/CASE2699\">https:\/\/thejns.org\/doi\/10.3171\/CASE2699<\/jats:ext-link>\n                    <\/jats:p>\n                  <\/jats:sec>","DOI":"10.3171\/case2699","type":"journal-article","created":{"date-parts":[[2026,10,14]],"date-time":"2026-10-14T00:00:59Z","timestamp":1791936059000},"source":"Crossref","is-referenced-by-count":0,"title":["Recurrent trigeminal neuralgia caused by an anomalous cerebellar artery arising from the persistent primitive trigeminal artery: illustrative case"],"prefix":"10.3171","volume":"12","author":[{"ORCID":"https:\/\/orcid.org\/0009-0006-2391-726X","authenticated-orcid":true,"given":"Hiroki","family":"Narita","sequence":"first","affiliation":[{"name":"Department of Neurosurgery, Kameda Medical Center, Kamogawa, Chiba"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-0769-2252","authenticated-orcid":true,"given":"Nobuyuki","family":"Watanabe","sequence":"additional","affiliation":[{"name":"Department of Neurosurgery, Kameda Medical Center, Kamogawa, Chiba"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-9251-7378","authenticated-orcid":true,"given":"Kentaro","family":"Watanabe","sequence":"additional","affiliation":[{"name":"Department of Neurosurgery, Jikei University School of Medicine, Minato-ku, Tokyo, Japan"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Ryoto","family":"Wachi","sequence":"additional","affiliation":[{"name":"Department of Neurosurgery, Kameda Medical Center, Kamogawa, Chiba"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-2160-253X","authenticated-orcid":true,"given":"Kohei","family":"Ishikawa","sequence":"additional","affiliation":[{"name":"Department of Neurosurgery, Jikei University School of Medicine, Minato-ku, Tokyo, Japan"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-4358-5868","authenticated-orcid":true,"given":"Michihiro","family":"Tanaka","sequence":"additional","affiliation":[{"name":"Department of Neurosurgery, Kameda Medical Center, Kamogawa, Chiba"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-3490-385X","authenticated-orcid":true,"given":"Yuichi","family":"Murayama","sequence":"additional","affiliation":[{"name":"Department of Neurosurgery, Jikei University School of Medicine, Minato-ku, Tokyo, Japan"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"1754","reference":[{"issue":"5","key":"bib1","series-title":"Acta Radiol (Stockh)","first-page":"329","article-title":"Patent primitive trigeminal artery studied by cerebral angiography","volume":"51","author":"Saltzman","year":"1959","unstructured":"Saltzman GF.Patent primitive trigeminal artery studied by cerebral angiography. Acta Radiol (Stockh). 1959;51(5):329-336. doi:10.3109\/00016925909171103"},{"issue":"2","key":"bib2","series-title":"Neurosurgery","first-page":"428","article-title":"Persistent trigeminal artery: a unique anatomic specimen\u2014analysis and therapeutic implications","volume":"47","author":"Suttner","year":"2000","unstructured":"Suttner NMura JTedeschi HPersistent trigeminal artery: a unique anatomic specimen\u2014analysis and therapeutic implications. Neurosurgery. 2000;47(2):428-433. doi:10.1097\/00006123-200008000-00030"},{"issue":"11","key":"bib3","series-title":"Eur Radiol","first-page":"1801","article-title":"Persistent trigeminal artery variants detected by MR angiography","volume":"10","author":"Uchino","year":"2000","unstructured":"Uchino AKato ATakase YKudo S.Persistent trigeminal artery variants detected by MR angiography. Eur Radiol. 2000;10(11):1801-1804. doi:10.1007\/s003300000443"},{"issue":"3","key":"bib4","series-title":"Surg Radiol Anat","first-page":"271","article-title":"Persistent trigeminal artery and its variants on MR angiography","volume":"34","author":"Uchino","year":"2012","unstructured":"Uchino ASaito NOkada YPersistent trigeminal artery and its variants on MR angiography. Surg Radiol Anat. 2012;34(3):271-276. doi:10.1007\/s00276-011-0848-0"},{"issue":"6","key":"bib5","series-title":"Interv Neuroradiol","first-page":"635","article-title":"Persistent trigeminal artery and its variants","volume":"25","author":"Komiyama","year":"2019","unstructured":"Komiyama M.Persistent trigeminal artery and its variants. 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Acta Neurochir Suppl. 2022;135:165-170."},{"issue":"1","key":"bib14","series-title":"Head Face Med","first-page":"56","article-title":"A novel 3D multimodal fusion imaging surgical guidance in microvascular decompression for primary trigeminal neuralgia and hemifacial spasm","volume":"20","author":"Hou","year":"2024","unstructured":"Hou XXu RXTang JYin C.A novel 3D multimodal fusion imaging surgical guidance in microvascular decompression for primary trigeminal neuralgia and hemifacial spasm. Head Face Med. 2024;20(1):56. doi:10.1186\/s13005-024-00442-0"}],"container-title":["Journal of Neurosurgery: Case Lessons"],"original-title":[],"link":[{"URL":"https:\/\/thejns.org\/view\/journals\/j-neurosurg-case-lessons\/12\/16\/article-CASE2699.xml","content-type":"text\/html","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/thejns.org\/downloadpdf\/journals\/j-neurosurg-case-lessons\/12\/16\/article-CASE2699.xml","content-type":"text\/html","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/thejns.org\/downloadpdf\/journals\/j-neurosurg-case-lessons\/12\/16\/article-CASE2699.xml","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,10,21]],"date-time":"2026-10-21T00:01:05Z","timestamp":1792540865000},"score":1,"resource":{"primary":{"URL":"https:\/\/thejns.org\/view\/journals\/j-neurosurg-case-lessons\/12\/16\/article-CASE2699.xml"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2026,10,19]]},"references-count":14,"journal-issue":{"issue":"16"},"URL":"https:\/\/doi.org\/10.3171\/case2699","relation":{},"ISSN":["2694-1902"],"issn-type":[{"value":"2694-1902","type":"electronic"}],"subject":[],"published":{"date-parts":[[2026,10,19]]}}}