{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,15]],"date-time":"2026-08-15T05:00:25Z","timestamp":1786770025478,"version":"build-2736575974"},"reference-count":12,"publisher":"SAGE Publications","issue":"3","license":[{"start":{"date-parts":[[2018,8,2]],"date-time":"2018-08-02T00:00:00Z","timestamp":1533168000000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/journals.sagepub.com\/page\/policies\/text-and-data-mining-license"}],"content-domain":{"domain":["journals.sagepub.com"],"crossmark-restriction":true},"short-container-title":["Journal of Neuromuscular Diseases"],"published-print":{"date-parts":[[2018,8,2]]},"abstract":"<jats:sec>\n                    <jats:title>Background:<\/jats:title>\n                    <jats:p>Exertional myalgia and cramps of the limb and trunk muscles are typical in McArdle disease, but mastication and oral motor limitations have not been systematically investigated before.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Objective:<\/jats:title>\n                    <jats:p>Determine the reported prevalence and characteristics of limitations on oral motor activities, mastication, swallowing, and other oral motor activities in patients with McArdle disease.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Methods:<\/jats:title>\n                    <jats:p>An observational study was carried out in 28 patients using a standardised questionnaire on mastication and oral motor function.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Results:<\/jats:title>\n                    <jats:p>\n                      57% of the participants reported difficulties with mastication. Muscle cramps during mastication occurred in 57% of the patients. A feeling that food remains in the throat occurred in 32%. Adaptations during mastication were needed in 42% of the patients. Mastication difficulties, muscle cramps during mastication and mastication adjustments were inversely correlated with age (r\n                      <jats:sub>2<\/jats:sub>\n                      \u200a=\u200a\u2013 0.445, p\u200a&lt;\u200a0.05; r\n                      <jats:sub>2<\/jats:sub>\n                      \u200a=\u200a\u2013 0.509, p\u200a&lt;\u200a0.01; r\n                      <jats:sub>2<\/jats:sub>\n                      \u200a=\u200a\u2013 0.456, p\u200a&lt;\u200a0.05). Feeling of food remaining in throat, cramps during mastication and during other oral motor muscle activities, were correlated with disease severity (r\n                      <jats:sub>2<\/jats:sub>\n                      \u200a=\u200a0.476, p\u200a&lt;\u200a0.01; r\n                      <jats:sub>2<\/jats:sub>\n                      \u200a=\u200a0.463, p\u200a&lt;\u200a0.01; r\n                      <jats:sub>2<\/jats:sub>\n                      \u200a=\u200a0.461, p\u200a&lt;\u200a0.01; r\n                      <jats:sub>2<\/jats:sub>\n                      \u200a=\u200a0.432, p\u200a&lt;\u200a0.05).\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusions:<\/jats:title>\n                    <jats:p>In short, reported mastication difficulties are prevalent in people with McArdle disease, most frequently in younger people. Therefore, awareness of mastication and oral motor problems is required.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.3233\/jnd-180320","type":"journal-article","created":{"date-parts":[[2018,8,5]],"date-time":"2018-08-05T06:43:47Z","timestamp":1533451427000},"page":"353-357","update-policy":"https:\/\/doi.org\/10.1177\/sage-journals-update-policy","source":"Crossref","is-referenced-by-count":6,"title":["Mastication and Oral Motor Function in McArdle Disease: Patient Reported Complaints"],"prefix":"10.1177","volume":"5","author":[{"given":"C.V.","family":"Kouwenberg","sequence":"first","affiliation":[{"name":"Department of Neurology, Donders Institute for Brain, Cognition, and Behaviour, Radboud University Medical Centre, Nijmegen, The Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"N.C.","family":"Voermans","sequence":"additional","affiliation":[{"name":"Department of Neurology, Donders Institute for Brain, Cognition, and Behaviour, Radboud University Medical Centre, Nijmegen, The Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"R.","family":"Quinlivan","sequence":"additional","affiliation":[{"name":"MRC Centre for Neuromuscular Diseases and Department of Molecular Neuroscience, University College London Institute of Neurology and National Hospital for Neurology and Neurosurgery, Queen Square, London, UK"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"L.","family":"van den Engel-Hoek","sequence":"additional","affiliation":[{"name":"Department of Rehabilitation, Donders Institute for Brain, Cognition and Behaviour, Radboud University Medical Centre, Nijmegen, The Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"179","published-online":{"date-parts":[[2018,8,2]]},"reference":[{"issue":"12","key":"ref001","first-page":"CD007931","author":"Quinlivan R","year":"2012","journal-title":"Cochrane Database Syst Rev"},{"key":"ref002","doi-asserted-by":"publisher","DOI":"10.1002\/ana.10725"},{"key":"ref003","doi-asserted-by":"publisher","DOI":"10.1136\/jnnp.2009.195040"},{"issue":"1","key":"ref004","first-page":"13","volume":"10","author":"McArdle AB","year":"1951","journal-title":"Clin Sci"},{"key":"ref005","doi-asserted-by":"publisher","DOI":"10.1016\/S1079-2104(96)80043-6"},{"key":"ref006","doi-asserted-by":"publisher","DOI":"10.1136\/jnnp.36.2.217"},{"key":"ref007","unstructured":"EUROMAC registry of patients with McArdle disease and other rare glycogenolytic disorders with exercise intolerance. 2013 [cited 2017 05.04.17]; Available from: www.euromacregistry.eu."},{"key":"ref008","doi-asserted-by":"publisher","DOI":"10.1212\/WNL.0b013e3181c34aa6"},{"key":"ref009","doi-asserted-by":"publisher","DOI":"10.1002\/ana.10499"},{"key":"ref010","volume-title":"GeneReviews(R)","author":"Martin MA","year":"1993"},{"key":"ref011","doi-asserted-by":"publisher","DOI":"10.1177\/154405910508400902"},{"key":"ref012","doi-asserted-by":"publisher","DOI":"10.1152\/ajpregu.00489.2015"}],"container-title":["Journal of Neuromuscular Diseases"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.3233\/JND-180320","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/full-xml\/10.3233\/JND-180320","content-type":"application\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/journals.sagepub.com\/doi\/pdf\/10.3233\/JND-180320","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,4,29]],"date-time":"2026-04-29T23:53:32Z","timestamp":1777506812000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.sagepub.com\/doi\/10.3233\/JND-180320"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2018,8,2]]},"references-count":12,"journal-issue":{"issue":"3","published-print":{"date-parts":[[2018,8,2]]}},"alternative-id":["10.3233\/JND-180320"],"URL":"https:\/\/doi.org\/10.3233\/jnd-180320","relation":{},"ISSN":["2214-3599","2214-3602"],"issn-type":[{"value":"2214-3599","type":"print"},{"value":"2214-3602","type":"electronic"}],"subject":[],"published":{"date-parts":[[2018,8,2]]}}}